Testicular Adrenal Rest Tumors in Patients with Congenital Adrenal Hyperplasia: A Case Series

Objective: Testicular adrenal rest tumors (TARTs) are the main etiology of infertility in congenital adrenal hyperplasia (CAH). The aim of this study is to determine the patients diagnosed with TART and to evaluate the risk factors associated with the development of the disease. Methods: Clinical...

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Main Authors: Didem Yildirimçakar, Selda Ayça Altincik, Murat Öcal, Bayram Özhan
Format: Article
Language:English
Published: Aydın Pediatric Society 2020-06-01
Series:Trends in Pediatrics
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Online Access:https://trendspediatrics.com/article/view/11
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author Didem Yildirimçakar
Selda Ayça Altincik
Murat Öcal
Bayram Özhan
author_facet Didem Yildirimçakar
Selda Ayça Altincik
Murat Öcal
Bayram Özhan
author_sort Didem Yildirimçakar
collection DOAJ
description Objective: Testicular adrenal rest tumors (TARTs) are the main etiology of infertility in congenital adrenal hyperplasia (CAH). The aim of this study is to determine the patients diagnosed with TART and to evaluate the risk factors associated with the development of the disease. Methods: Clinical characteristics of 31 patients with CAH including 19 male, and 12 female patients who were followed up in our clinic were retrospectively reviewed regarding the presence of TART. Differences between clinical and laboratory findings of patients with and without TART were examined. Six male patients with TART were included in the study. Clinical characteristics such as pubertal stage, treatment doses, laboratory findings were evaluated. Changes in size of TARTs were examined with ultrasound follow-ups at six month- intervals. Results: The prevalence of TARTs was 31.5 % (6/19 male). Precocious puberty was higher in patients with TART than without TART. The mean age of the patients was 9.1±2.4 (range: 5.2-12.4) years at the time of diagnosis with TART. Five patients with TART were inadequately controlled. Four patients had a history of precocious puberty. Tumor progression was detected in 4 of 6 patients. In three patients with tumor progression, serum 17-hydroxy progesterone (17-OHP) values increased during follow-up, probably due to non-compliance with treatment. Conclusion: Scrotal ultrasound monitoring should be performed in all male patients with CAH in early childhood irrespective of disease control.
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spelling doaj-art-87111a40499d45b5bb4de79ef793cdcd2025-08-20T03:12:24ZengAydın Pediatric SocietyTrends in Pediatrics2792-04292020-06-011210.5222/TP.2020.87587Testicular Adrenal Rest Tumors in Patients with Congenital Adrenal Hyperplasia: A Case SeriesDidem Yildirimçakar0https://orcid.org/0000-0002-9408-713XSelda Ayça Altincik1https://orcid.org/0000-0002-4101-9299Murat Öcal2https://orcid.org/0000-0001-7190-075XBayram Özhan3https://orcid.org/0000-0003-4842-9976Department of Pediatric Endocrinology, Pamukkale University, Denizli,TurkeyDepartment of Pediatric Endocrinology, Pamukkale University, Denizli,TurkeyDepartment of Pediatric Endocrinology, Pamukkale University, Denizli,TurkeyDepartment of Pediatric Endocrinology, Pamukkale University, Denizli,Turkey Objective: Testicular adrenal rest tumors (TARTs) are the main etiology of infertility in congenital adrenal hyperplasia (CAH). The aim of this study is to determine the patients diagnosed with TART and to evaluate the risk factors associated with the development of the disease. Methods: Clinical characteristics of 31 patients with CAH including 19 male, and 12 female patients who were followed up in our clinic were retrospectively reviewed regarding the presence of TART. Differences between clinical and laboratory findings of patients with and without TART were examined. Six male patients with TART were included in the study. Clinical characteristics such as pubertal stage, treatment doses, laboratory findings were evaluated. Changes in size of TARTs were examined with ultrasound follow-ups at six month- intervals. Results: The prevalence of TARTs was 31.5 % (6/19 male). Precocious puberty was higher in patients with TART than without TART. The mean age of the patients was 9.1±2.4 (range: 5.2-12.4) years at the time of diagnosis with TART. Five patients with TART were inadequately controlled. Four patients had a history of precocious puberty. Tumor progression was detected in 4 of 6 patients. In three patients with tumor progression, serum 17-hydroxy progesterone (17-OHP) values increased during follow-up, probably due to non-compliance with treatment. Conclusion: Scrotal ultrasound monitoring should be performed in all male patients with CAH in early childhood irrespective of disease control. https://trendspediatrics.com/article/view/11CAHTARTtesticular tumor
spellingShingle Didem Yildirimçakar
Selda Ayça Altincik
Murat Öcal
Bayram Özhan
Testicular Adrenal Rest Tumors in Patients with Congenital Adrenal Hyperplasia: A Case Series
Trends in Pediatrics
CAH
TART
testicular tumor
title Testicular Adrenal Rest Tumors in Patients with Congenital Adrenal Hyperplasia: A Case Series
title_full Testicular Adrenal Rest Tumors in Patients with Congenital Adrenal Hyperplasia: A Case Series
title_fullStr Testicular Adrenal Rest Tumors in Patients with Congenital Adrenal Hyperplasia: A Case Series
title_full_unstemmed Testicular Adrenal Rest Tumors in Patients with Congenital Adrenal Hyperplasia: A Case Series
title_short Testicular Adrenal Rest Tumors in Patients with Congenital Adrenal Hyperplasia: A Case Series
title_sort testicular adrenal rest tumors in patients with congenital adrenal hyperplasia a case series
topic CAH
TART
testicular tumor
url https://trendspediatrics.com/article/view/11
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AT muratocal testicularadrenalresttumorsinpatientswithcongenitaladrenalhyperplasiaacaseseries
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