The Role of RPGR and Its Interacting Proteins in Ciliopathies

Ciliopathies encompass a group of genetic disorders characterized by defects in the formation, maintenance, or function of cilia. Retinitis pigmentosa (RP) is frequently one of the clinical features presented in diverse ciliopathies. RP is a heterogeneous group of inherited retinal disorders, chara...

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Main Authors: Sarita Rani Patnaik, Rakesh Kotapati Raghupathy, Xun Zhang, David Mansfield, Xinhua Shu
Format: Article
Language:English
Published: Wiley 2015-01-01
Series:Journal of Ophthalmology
Online Access:http://dx.doi.org/10.1155/2015/414781
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author Sarita Rani Patnaik
Rakesh Kotapati Raghupathy
Xun Zhang
David Mansfield
Xinhua Shu
author_facet Sarita Rani Patnaik
Rakesh Kotapati Raghupathy
Xun Zhang
David Mansfield
Xinhua Shu
author_sort Sarita Rani Patnaik
collection DOAJ
description Ciliopathies encompass a group of genetic disorders characterized by defects in the formation, maintenance, or function of cilia. Retinitis pigmentosa (RP) is frequently one of the clinical features presented in diverse ciliopathies. RP is a heterogeneous group of inherited retinal disorders, characterized by the death of photoreceptors and affecting more than one million individuals worldwide. The retinitis pigmentosa GTPase regulator (RPGR) gene is mutated in up to 20% of all RP patients. RPGR protein has different interacting partners to function in ciliary protein trafficking. In this review, we specifically focus on RPGR and its two interacting proteins: RPGRIP1 and RPGRIP1L. We summarize the function of the three proteins and highlight recent studies that provide insight into the cellular function of those proteins.
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institution OA Journals
issn 2090-004X
2090-0058
language English
publishDate 2015-01-01
publisher Wiley
record_format Article
series Journal of Ophthalmology
spelling doaj-art-869c9238c96a470598d8fe615afd49032025-08-20T02:08:46ZengWileyJournal of Ophthalmology2090-004X2090-00582015-01-01201510.1155/2015/414781414781The Role of RPGR and Its Interacting Proteins in CiliopathiesSarita Rani Patnaik0Rakesh Kotapati Raghupathy1Xun Zhang2David Mansfield3Xinhua Shu4Department of Life Sciences, Glasgow Caledonian University, Glasgow G4 0BA, UKDepartment of Life Sciences, Glasgow Caledonian University, Glasgow G4 0BA, UKDepartment of Life Sciences, Glasgow Caledonian University, Glasgow G4 0BA, UKInverclyde Royal Hospital, Greenock PA16 0XN, UKDepartment of Life Sciences, Glasgow Caledonian University, Glasgow G4 0BA, UKCiliopathies encompass a group of genetic disorders characterized by defects in the formation, maintenance, or function of cilia. Retinitis pigmentosa (RP) is frequently one of the clinical features presented in diverse ciliopathies. RP is a heterogeneous group of inherited retinal disorders, characterized by the death of photoreceptors and affecting more than one million individuals worldwide. The retinitis pigmentosa GTPase regulator (RPGR) gene is mutated in up to 20% of all RP patients. RPGR protein has different interacting partners to function in ciliary protein trafficking. In this review, we specifically focus on RPGR and its two interacting proteins: RPGRIP1 and RPGRIP1L. We summarize the function of the three proteins and highlight recent studies that provide insight into the cellular function of those proteins.http://dx.doi.org/10.1155/2015/414781
spellingShingle Sarita Rani Patnaik
Rakesh Kotapati Raghupathy
Xun Zhang
David Mansfield
Xinhua Shu
The Role of RPGR and Its Interacting Proteins in Ciliopathies
Journal of Ophthalmology
title The Role of RPGR and Its Interacting Proteins in Ciliopathies
title_full The Role of RPGR and Its Interacting Proteins in Ciliopathies
title_fullStr The Role of RPGR and Its Interacting Proteins in Ciliopathies
title_full_unstemmed The Role of RPGR and Its Interacting Proteins in Ciliopathies
title_short The Role of RPGR and Its Interacting Proteins in Ciliopathies
title_sort role of rpgr and its interacting proteins in ciliopathies
url http://dx.doi.org/10.1155/2015/414781
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