Serous retinal detachment secondary to bilateral choroidal osteoma successfully treated with subscleral sclerectomy: A case report

Purpose: To report a case of bilateral choroidal osteoma successfully treated with subscleral sclerectomy for secondary serous retinal detachment (SRD). Observations: A 52-year-old Japanese woman first diagnosed with Vogt-Koyanagi-Harada disease and treated with steroids for 9 years was referred to...

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Main Authors: Satoko Fujimoto, Kazuichi Maruyama, Takuya Shunto, Kohji Nishida
Format: Article
Language:English
Published: Elsevier 2025-03-01
Series:American Journal of Ophthalmology Case Reports
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Online Access:http://www.sciencedirect.com/science/article/pii/S2451993625000027
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author Satoko Fujimoto
Kazuichi Maruyama
Takuya Shunto
Kohji Nishida
author_facet Satoko Fujimoto
Kazuichi Maruyama
Takuya Shunto
Kohji Nishida
author_sort Satoko Fujimoto
collection DOAJ
description Purpose: To report a case of bilateral choroidal osteoma successfully treated with subscleral sclerectomy for secondary serous retinal detachment (SRD). Observations: A 52-year-old Japanese woman first diagnosed with Vogt-Koyanagi-Harada disease and treated with steroids for 9 years was referred to our clinic. SRD in both eyes recurred frequently and was uncontrolled with adalimumab subcutaneous injections and oral cyclosporine, in addition to steroids. A yellowish-to-orange, slightly elevated subretinal lesion was observed superior to the macular and inferotemporal regions of the right eye and superior to the macular and temporal regions of the left eye without any inflammation. Swept-source optical coherence tomography (OCT) revealed SRD in the fovea and a mass under the retinal pigment epithelium (RPE) in the macular area of both eyes. Indocyanine green angiography (ICGA) demonstrated hypocyanescence corresponding to the mass area under the RPE, with dilation of the dominant vortex veins. Ultrasonography revealed a hyperechogenic mass in the posterior wall of both eyes with deeper acoustic shadows, and computed tomography (CT) detected calcifications in the posterior wall of both eyes. A bilateral choroidal osteoma was diagnosed, and the superior SRD of her left eye increased toward the fovea without any evidence of choroidal neovascularization during follow-up. Therefore, subscleral sclerectomy (4 × 4 mm2 sclerectomy under the scleral flap) was performed at three sites at the equators in the upper temporal, upper nasal, and lower temporal quadrants of her left eye. Immediately after surgery, SRD resolved dramatically. As the foveal SRD of her right eye also increased after two months, the same surgery was performed, and it worked successfully. Conclusions and Importance: Choroidal osteoma can cause severe SRD that cannot be controlled with medication. Although further studies are needed, subscleral sclerectomy may be an effective treatment for the resolution of subretinal fluid secondary to choroidal osteoma by improving choroidal circulation congestion.
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spelling doaj-art-8007beb9afe243638d0e3bb030b2da9e2025-08-20T03:01:07ZengElsevierAmerican Journal of Ophthalmology Case Reports2451-99362025-03-013710224910.1016/j.ajoc.2025.102249Serous retinal detachment secondary to bilateral choroidal osteoma successfully treated with subscleral sclerectomy: A case reportSatoko Fujimoto0Kazuichi Maruyama1Takuya Shunto2Kohji Nishida3Department of Ophthalmology, Osaka University Graduate School of Medicine, 2-2 Yamadaoka, Suita, Osaka, 565-0871, JapanDepartment of Ophthalmology, Osaka University Graduate School of Medicine, 2-2 Yamadaoka, Suita, Osaka, 565-0871, Japan; Department of Vision Informatics, Osaka University Graduate School of Medicine, 2-2 Yamadaoka, Suita, Osaka, 565-0871, Japan; Integrated Frontier Research for Medical Science Division, Institute for Open and Transdisciplinary Research Initiatives, Osaka University, 2-2 Yamadaoka, Suita, Osaka, 565-0871, Japan; Corresponding author. Department of Ophthalmology, Osaka University Graduate School of Medicine, 2-2 Yamadaoka, Suita, Osaka, 565-0871, Japan.Department of Ophthalmology, Osaka University Graduate School of Medicine, 2-2 Yamadaoka, Suita, Osaka, 565-0871, JapanDepartment of Ophthalmology, Osaka University Graduate School of Medicine, 2-2 Yamadaoka, Suita, Osaka, 565-0871, Japan; Integrated Frontier Research for Medical Science Division, Institute for Open and Transdisciplinary Research Initiatives, Osaka University, 2-2 Yamadaoka, Suita, Osaka, 565-0871, JapanPurpose: To report a case of bilateral choroidal osteoma successfully treated with subscleral sclerectomy for secondary serous retinal detachment (SRD). Observations: A 52-year-old Japanese woman first diagnosed with Vogt-Koyanagi-Harada disease and treated with steroids for 9 years was referred to our clinic. SRD in both eyes recurred frequently and was uncontrolled with adalimumab subcutaneous injections and oral cyclosporine, in addition to steroids. A yellowish-to-orange, slightly elevated subretinal lesion was observed superior to the macular and inferotemporal regions of the right eye and superior to the macular and temporal regions of the left eye without any inflammation. Swept-source optical coherence tomography (OCT) revealed SRD in the fovea and a mass under the retinal pigment epithelium (RPE) in the macular area of both eyes. Indocyanine green angiography (ICGA) demonstrated hypocyanescence corresponding to the mass area under the RPE, with dilation of the dominant vortex veins. Ultrasonography revealed a hyperechogenic mass in the posterior wall of both eyes with deeper acoustic shadows, and computed tomography (CT) detected calcifications in the posterior wall of both eyes. A bilateral choroidal osteoma was diagnosed, and the superior SRD of her left eye increased toward the fovea without any evidence of choroidal neovascularization during follow-up. Therefore, subscleral sclerectomy (4 × 4 mm2 sclerectomy under the scleral flap) was performed at three sites at the equators in the upper temporal, upper nasal, and lower temporal quadrants of her left eye. Immediately after surgery, SRD resolved dramatically. As the foveal SRD of her right eye also increased after two months, the same surgery was performed, and it worked successfully. Conclusions and Importance: Choroidal osteoma can cause severe SRD that cannot be controlled with medication. Although further studies are needed, subscleral sclerectomy may be an effective treatment for the resolution of subretinal fluid secondary to choroidal osteoma by improving choroidal circulation congestion.http://www.sciencedirect.com/science/article/pii/S2451993625000027Choroidal osteomaSerous retinal detachmentSubretinal fluidSclerectomySubscleral sclerectomyScleral window
spellingShingle Satoko Fujimoto
Kazuichi Maruyama
Takuya Shunto
Kohji Nishida
Serous retinal detachment secondary to bilateral choroidal osteoma successfully treated with subscleral sclerectomy: A case report
American Journal of Ophthalmology Case Reports
Choroidal osteoma
Serous retinal detachment
Subretinal fluid
Sclerectomy
Subscleral sclerectomy
Scleral window
title Serous retinal detachment secondary to bilateral choroidal osteoma successfully treated with subscleral sclerectomy: A case report
title_full Serous retinal detachment secondary to bilateral choroidal osteoma successfully treated with subscleral sclerectomy: A case report
title_fullStr Serous retinal detachment secondary to bilateral choroidal osteoma successfully treated with subscleral sclerectomy: A case report
title_full_unstemmed Serous retinal detachment secondary to bilateral choroidal osteoma successfully treated with subscleral sclerectomy: A case report
title_short Serous retinal detachment secondary to bilateral choroidal osteoma successfully treated with subscleral sclerectomy: A case report
title_sort serous retinal detachment secondary to bilateral choroidal osteoma successfully treated with subscleral sclerectomy a case report
topic Choroidal osteoma
Serous retinal detachment
Subretinal fluid
Sclerectomy
Subscleral sclerectomy
Scleral window
url http://www.sciencedirect.com/science/article/pii/S2451993625000027
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AT takuyashunto serousretinaldetachmentsecondarytobilateralchoroidalosteomasuccessfullytreatedwithsubscleralsclerectomyacasereport
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