Malignant Triton Tumors in Sisters with Clinical Neurofibromatosis Type 1

Malignant triton tumors (MTTs) are rare and aggressive sarcomas categorized as a subgroup of malignant peripheral nerve sheath tumors (MPNSTs). MTTs arise from Schwann cells of peripheral nerves or existing neurofibromas and have elements of rhabdomyoblastic differentiation. We report the occurrence...

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Main Authors: Basnet Alina, Jofre A. Sebastian, Capo Gerardo
Format: Article
Language:English
Published: Wiley 2015-01-01
Series:Case Reports in Oncological Medicine
Online Access:http://dx.doi.org/10.1155/2015/405351
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author Basnet Alina
Jofre A. Sebastian
Capo Gerardo
author_facet Basnet Alina
Jofre A. Sebastian
Capo Gerardo
author_sort Basnet Alina
collection DOAJ
description Malignant triton tumors (MTTs) are rare and aggressive sarcomas categorized as a subgroup of malignant peripheral nerve sheath tumors (MPNSTs). MTTs arise from Schwann cells of peripheral nerves or existing neurofibromas and have elements of rhabdomyoblastic differentiation. We report the occurrence of MTTs in two sisters. The first patient is a 36-year-old female who presented with left sided chest wall swelling. She also had clinical features consistent with neurofibromatosis type 1 (NF-1). Debulking of the mass showed high-grade malignant peripheral nerve sheath tumor with skeletal muscle differentiation (MTT). The patient was treated with ifosfamide and adriamycin along with radiation. Four years after treatment, she still has no evidence of disease recurrence. Her sister subsequently presented to us at the age of 42 with left sided lateral chest wall pain. Imaging showed a multicompartmental retroperitoneal cystic mass with left psoas involvement. The tumor was resected and, similarly to her sister, it showed high-grade malignant peripheral nerve sheath tumor with rhabdomyoblastic differentiation (MTT). The patient was started on chemotherapy and radiation as described above.
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spelling doaj-art-7d7f7ed7f037428d847ffbf0eb3673e52025-08-20T03:35:18ZengWileyCase Reports in Oncological Medicine2090-67062090-67142015-01-01201510.1155/2015/405351405351Malignant Triton Tumors in Sisters with Clinical Neurofibromatosis Type 1Basnet Alina0Jofre A. Sebastian1Capo Gerardo2Trinitas Regional Medical Center, Seton Hall University of Health and Medical Sciences, Elizabeth, NJ 67202, USATrinitas Regional Medical Center, Seton Hall University of Health and Medical Sciences, Elizabeth, NJ 67202, USATrinitas Regional Medical Center, Seton Hall University of Health and Medical Sciences, Elizabeth, NJ 67202, USAMalignant triton tumors (MTTs) are rare and aggressive sarcomas categorized as a subgroup of malignant peripheral nerve sheath tumors (MPNSTs). MTTs arise from Schwann cells of peripheral nerves or existing neurofibromas and have elements of rhabdomyoblastic differentiation. We report the occurrence of MTTs in two sisters. The first patient is a 36-year-old female who presented with left sided chest wall swelling. She also had clinical features consistent with neurofibromatosis type 1 (NF-1). Debulking of the mass showed high-grade malignant peripheral nerve sheath tumor with skeletal muscle differentiation (MTT). The patient was treated with ifosfamide and adriamycin along with radiation. Four years after treatment, she still has no evidence of disease recurrence. Her sister subsequently presented to us at the age of 42 with left sided lateral chest wall pain. Imaging showed a multicompartmental retroperitoneal cystic mass with left psoas involvement. The tumor was resected and, similarly to her sister, it showed high-grade malignant peripheral nerve sheath tumor with rhabdomyoblastic differentiation (MTT). The patient was started on chemotherapy and radiation as described above.http://dx.doi.org/10.1155/2015/405351
spellingShingle Basnet Alina
Jofre A. Sebastian
Capo Gerardo
Malignant Triton Tumors in Sisters with Clinical Neurofibromatosis Type 1
Case Reports in Oncological Medicine
title Malignant Triton Tumors in Sisters with Clinical Neurofibromatosis Type 1
title_full Malignant Triton Tumors in Sisters with Clinical Neurofibromatosis Type 1
title_fullStr Malignant Triton Tumors in Sisters with Clinical Neurofibromatosis Type 1
title_full_unstemmed Malignant Triton Tumors in Sisters with Clinical Neurofibromatosis Type 1
title_short Malignant Triton Tumors in Sisters with Clinical Neurofibromatosis Type 1
title_sort malignant triton tumors in sisters with clinical neurofibromatosis type 1
url http://dx.doi.org/10.1155/2015/405351
work_keys_str_mv AT basnetalina malignanttritontumorsinsisterswithclinicalneurofibromatosistype1
AT jofreasebastian malignanttritontumorsinsisterswithclinicalneurofibromatosistype1
AT capogerardo malignanttritontumorsinsisterswithclinicalneurofibromatosistype1