Comprehensive overview of the current state and impact of cohort studies in newborn screening

Inborn errors of metabolism (IEM) are a rare and complex group of inherited disorders, typically observed in infants as autosomal recessive or, less commonly, as X-linked recessive conditions. Newborn screening (NBS) for IEMs can significantly improve prognosis and quality of life through early diag...

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Main Authors: Priyanka Sangale, Atul Khadse, Charushila Bhangale
Format: Article
Language:English
Published: Wolters Kluwer Medknow Publications 2024-07-01
Series:MGM Journal of Medical Sciences
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Online Access:https://journals.lww.com/mgmj/fulltext/2024/11030/comprehensive_overview_of_the_current_state_and.21.aspx
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author Priyanka Sangale
Atul Khadse
Charushila Bhangale
author_facet Priyanka Sangale
Atul Khadse
Charushila Bhangale
author_sort Priyanka Sangale
collection DOAJ
description Inborn errors of metabolism (IEM) are a rare and complex group of inherited disorders, typically observed in infants as autosomal recessive or, less commonly, as X-linked recessive conditions. Newborn screening (NBS) for IEMs can significantly improve prognosis and quality of life through early diagnosis and intervention, marking a significant public health achievement. NBS programs vary by country, but generally include tests for a range of metabolic errors, endocrine disorders, primary immunodeficiency disorders, congenital deafness, congenital heart defects, and cystic fibrosis. Integrating mass spectrometry (MS/MS), genetic sequencing, and emerging technologies such as next-generation sequencing into NBS programs represents a substantial advancement in the field of healthcare. These technologies enable early detection, intervention, and the possibility of personalized treatments through gene therapies. Such advancements are poised to shape the future of NBS, potentially enhancing healthcare outcomes for newborns on a global scale. Neonatal screening is the most well-known and widely implemented proactive and preventative pediatric public health initiative worldwide. It encompasses a comprehensive education system, screening, diagnostic confirmation, management, follow-up, and counseling. This article reviews recent advances in newborn metabolic screening, drawing on the results of various clinical trials and pilot studies.
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spelling doaj-art-7c9b25c1b9f04bdf84da3bbd6163b3262025-08-20T02:49:52ZengWolters Kluwer Medknow PublicationsMGM Journal of Medical Sciences2347-79622024-07-0111353354210.4103/mgmj.mgmj_202_24Comprehensive overview of the current state and impact of cohort studies in newborn screeningPriyanka SangaleAtul KhadseCharushila BhangaleInborn errors of metabolism (IEM) are a rare and complex group of inherited disorders, typically observed in infants as autosomal recessive or, less commonly, as X-linked recessive conditions. Newborn screening (NBS) for IEMs can significantly improve prognosis and quality of life through early diagnosis and intervention, marking a significant public health achievement. NBS programs vary by country, but generally include tests for a range of metabolic errors, endocrine disorders, primary immunodeficiency disorders, congenital deafness, congenital heart defects, and cystic fibrosis. Integrating mass spectrometry (MS/MS), genetic sequencing, and emerging technologies such as next-generation sequencing into NBS programs represents a substantial advancement in the field of healthcare. These technologies enable early detection, intervention, and the possibility of personalized treatments through gene therapies. Such advancements are poised to shape the future of NBS, potentially enhancing healthcare outcomes for newborns on a global scale. Neonatal screening is the most well-known and widely implemented proactive and preventative pediatric public health initiative worldwide. It encompasses a comprehensive education system, screening, diagnostic confirmation, management, follow-up, and counseling. This article reviews recent advances in newborn metabolic screening, drawing on the results of various clinical trials and pilot studies.https://journals.lww.com/mgmj/fulltext/2024/11030/comprehensive_overview_of_the_current_state_and.21.aspxclinical trial study; inborn errors of metabolism; newborn screening; omics approach; pilot study; public health program
spellingShingle Priyanka Sangale
Atul Khadse
Charushila Bhangale
Comprehensive overview of the current state and impact of cohort studies in newborn screening
MGM Journal of Medical Sciences
clinical trial study; inborn errors of metabolism; newborn screening; omics approach; pilot study; public health program
title Comprehensive overview of the current state and impact of cohort studies in newborn screening
title_full Comprehensive overview of the current state and impact of cohort studies in newborn screening
title_fullStr Comprehensive overview of the current state and impact of cohort studies in newborn screening
title_full_unstemmed Comprehensive overview of the current state and impact of cohort studies in newborn screening
title_short Comprehensive overview of the current state and impact of cohort studies in newborn screening
title_sort comprehensive overview of the current state and impact of cohort studies in newborn screening
topic clinical trial study; inborn errors of metabolism; newborn screening; omics approach; pilot study; public health program
url https://journals.lww.com/mgmj/fulltext/2024/11030/comprehensive_overview_of_the_current_state_and.21.aspx
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AT atulkhadse comprehensiveoverviewofthecurrentstateandimpactofcohortstudiesinnewbornscreening
AT charushilabhangale comprehensiveoverviewofthecurrentstateandimpactofcohortstudiesinnewbornscreening