A clinical case of neonatal diabetes caused by INS gene mutation

Neonatal diabetes mellitus (NDM) is a severe endocrine pathology diagnosed in children during the first months of life. It comprises rare (1:300 000–1:400 000 newborns) metabolic disorders with postnatal pancreatic β-cell dysfunction, manifested by hyperglycaemia and hypoinsulinae...

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Main Authors: Rosa A. Atanesyan, Tatyana A. Uglova, Tatyana M. Vdovina, Leonid Ya. Klimov, Marina U. Kostanova, Victoriya A. Kuryaninova, Marina V. Stoyan, Lilit S. Alaverdyan, Svetlana V. Dolbnya
Format: Article
Language:English
Published: Endocrinology Research Centre 2019-06-01
Series:Сахарный диабет
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Online Access:https://www.dia-endojournals.ru/jour/article/view/9876
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author Rosa A. Atanesyan
Tatyana A. Uglova
Tatyana M. Vdovina
Leonid Ya. Klimov
Marina U. Kostanova
Victoriya A. Kuryaninova
Marina V. Stoyan
Lilit S. Alaverdyan
Svetlana V. Dolbnya
author_facet Rosa A. Atanesyan
Tatyana A. Uglova
Tatyana M. Vdovina
Leonid Ya. Klimov
Marina U. Kostanova
Victoriya A. Kuryaninova
Marina V. Stoyan
Lilit S. Alaverdyan
Svetlana V. Dolbnya
author_sort Rosa A. Atanesyan
collection DOAJ
description Neonatal diabetes mellitus (NDM) is a severe endocrine pathology diagnosed in children during the first months of life. It comprises rare (1:300 000–1:400 000 newborns) metabolic disorders with postnatal pancreatic β-cell dysfunction, manifested by hyperglycaemia and hypoinsulinaemia. It is currently established that molecular genetic diagnosis of neonatal diabetes forms can influence treatment and prognosis. Interestingly, most identified mutations in the insulin gene are not inherited, but are sporadic. There is evidence that, in addition to heterozygous INS mutations, NDM can be caused by homozygous or compound-heterozygous mutations. The present article presents the clinical case of a girl with NDM associated with an INS gene mutation. INS gene mutations cause permanent diabetes and require children to undergo genetic examination, especially patients with type 1 diabetes in the absence of antibodies. Currently, there are no data that allow to determine a phenotypic and genotypic ‘portrait’ of NDM forms or to explain the factors determining their occurrence. Further studies of clinical cases of neonatal diabetes are therefore required to determine the characteristics of NDM subtypes with subsequent disease prognosis.
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publisher Endocrinology Research Centre
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series Сахарный диабет
spelling doaj-art-752e9da87603460985a3aaa39fa93caf2025-08-20T01:57:08ZengEndocrinology Research CentreСахарный диабет2072-03512072-03782019-06-0122217017610.14341/DM98768683A clinical case of neonatal diabetes caused by INS gene mutationRosa A. Atanesyan0Tatyana A. Uglova1Tatyana M. Vdovina2Leonid Ya. Klimov3Marina U. Kostanova4Victoriya A. Kuryaninova5Marina V. Stoyan6Lilit S. Alaverdyan7Svetlana V. Dolbnya8<p>Stavropol state medical University; Regional endocrinological dispensary</p><p>Municipal child's clinical hospital of a name of G. K. Filippsky</p><p>Stavropol state medical University</p><p>Stavropol state medical University</p><p>Stavropol state medical University</p><p>Stavropol state medical University; Municipal child's clinical hospital of a name of G. K. Filippsky</p><p>Stavropol state medical University; Municipal child's clinical hospital of a name of G. K. Filippsky</p><p>Stavropol state medical University</p><p>Stavropol state medical University</p>Neonatal diabetes mellitus (NDM) is a severe endocrine pathology diagnosed in children during the first months of life. It comprises rare (1:300 000&ndash;1:400 000 newborns) metabolic disorders with postnatal pancreatic &beta;-cell dysfunction, manifested by hyperglycaemia and hypoinsulinaemia. It is currently established that molecular genetic diagnosis of neonatal diabetes forms can influence treatment and prognosis. Interestingly, most identified mutations in the insulin gene are not inherited, but are sporadic. There is evidence that, in addition to heterozygous INS mutations, NDM can be caused by homozygous or compound-heterozygous mutations. The present article presents the clinical case of a girl with NDM associated with an INS gene mutation. INS gene mutations cause permanent diabetes and require children to undergo genetic examination, especially patients with type 1 diabetes in the absence of antibodies. Currently, there are no data that allow to determine a phenotypic and genotypic &lsquo;portrait&rsquo; of NDM forms or to explain the factors determining their occurrence. Further studies of clinical cases of neonatal diabetes are therefore required to determine the characteristics of NDM subtypes with subsequent disease prognosis.https://www.dia-endojournals.ru/jour/article/view/9876neonatal diabetespermanent formpump insulin therapy
spellingShingle Rosa A. Atanesyan
Tatyana A. Uglova
Tatyana M. Vdovina
Leonid Ya. Klimov
Marina U. Kostanova
Victoriya A. Kuryaninova
Marina V. Stoyan
Lilit S. Alaverdyan
Svetlana V. Dolbnya
A clinical case of neonatal diabetes caused by INS gene mutation
Сахарный диабет
neonatal diabetes
permanent form
pump insulin therapy
title A clinical case of neonatal diabetes caused by INS gene mutation
title_full A clinical case of neonatal diabetes caused by INS gene mutation
title_fullStr A clinical case of neonatal diabetes caused by INS gene mutation
title_full_unstemmed A clinical case of neonatal diabetes caused by INS gene mutation
title_short A clinical case of neonatal diabetes caused by INS gene mutation
title_sort clinical case of neonatal diabetes caused by ins gene mutation
topic neonatal diabetes
permanent form
pump insulin therapy
url https://www.dia-endojournals.ru/jour/article/view/9876
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