Genetic epilepsy caused by CDKL5 gene mutations as an example of epileptic encephalopathy and developmental encephalopathy: literature review and own observations

The disease caused by mutations in the CDKL5 gene (encoding cyclin-dependent kinase 5, CDK5) belongs to the group of early (infantile) epileptic encephalopathies caused by alterations in the genome. Currently, the disease is called “developmental encephalopathy and epileptic encephalopathy type 2”....

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Main Authors: K. Yu. Mukhin, O. A. Pylaeva, M. Yu. Bobylova, V. A. Chadaev
Format: Article
Language:Russian
Published: ABV-press 2021-07-01
Series:Русский журнал детской неврологии
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Online Access:https://rjdn.abvpress.ru/jour/article/view/360
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author K. Yu. Mukhin
O. A. Pylaeva
M. Yu. Bobylova
V. A. Chadaev
author_facet K. Yu. Mukhin
O. A. Pylaeva
M. Yu. Bobylova
V. A. Chadaev
author_sort K. Yu. Mukhin
collection DOAJ
description The disease caused by mutations in the CDKL5 gene (encoding cyclin-dependent kinase 5, CDK5) belongs to the group of early (infantile) epileptic encephalopathies caused by alterations in the genome. Currently, the disease is called “developmental encephalopathy and epileptic encephalopathy type 2”. This disorder is a complex combination of symptoms that develop due to deficiency or absence of the CDKL5 gene product, which is serine/threonine kinase. The CDKL5 gene is located on X chromosome; the disease has an X-linked dominant inheritance pattern. This literature review summarizes relevant studies analyzing the disease caused by CDKL5 gene mutations, including its genetic and epidemiological aspects, clinical manifestations, characteristics of epilepsy, principles of diagnosis, and therapeutic approaches. We present a case series of several patients with genetic disorders involving the CDKL5 gene.
format Article
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issn 2073-8803
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publishDate 2021-07-01
publisher ABV-press
record_format Article
series Русский журнал детской неврологии
spelling doaj-art-743aee6d9ca14825bedbb68a9a24867d2025-08-20T03:22:03ZrusABV-pressРусский журнал детской неврологии2073-88032412-91782021-07-01161-2104110.17650/2073-8803-2021-16-1-2-10-41240Genetic epilepsy caused by CDKL5 gene mutations as an example of epileptic encephalopathy and developmental encephalopathy: literature review and own observationsK. Yu. Mukhin0O. A. Pylaeva1M. Yu. Bobylova2V. A. Chadaev3Svt. Luka’s Institute of Child Neurology and Epilepsy; Svt. Luka’s Institute of Pediatric and Adult Neurology and EpilepsySvt. Luka’s Institute of Child Neurology and Epilepsy; Svt. Luka’s Institute of Pediatric and Adult Neurology and EpilepsySvt. Luka’s Institute of Child Neurology and Epilepsy; Svt. Luka’s Institute of Pediatric and Adult Neurology and EpilepsySvt. Luka’s Institute of Pediatric and Adult Neurology and EpilepsyThe disease caused by mutations in the CDKL5 gene (encoding cyclin-dependent kinase 5, CDK5) belongs to the group of early (infantile) epileptic encephalopathies caused by alterations in the genome. Currently, the disease is called “developmental encephalopathy and epileptic encephalopathy type 2”. This disorder is a complex combination of symptoms that develop due to deficiency or absence of the CDKL5 gene product, which is serine/threonine kinase. The CDKL5 gene is located on X chromosome; the disease has an X-linked dominant inheritance pattern. This literature review summarizes relevant studies analyzing the disease caused by CDKL5 gene mutations, including its genetic and epidemiological aspects, clinical manifestations, characteristics of epilepsy, principles of diagnosis, and therapeutic approaches. We present a case series of several patients with genetic disorders involving the CDKL5 gene.https://rjdn.abvpress.ru/jour/article/view/360epileptic encephalopathydevelopmental encephalopathyearly epileptic encephalopathycdkl5 geneepilepsyclinical manifestationsdiagnosistherapy
spellingShingle K. Yu. Mukhin
O. A. Pylaeva
M. Yu. Bobylova
V. A. Chadaev
Genetic epilepsy caused by CDKL5 gene mutations as an example of epileptic encephalopathy and developmental encephalopathy: literature review and own observations
Русский журнал детской неврологии
epileptic encephalopathy
developmental encephalopathy
early epileptic encephalopathy
cdkl5 gene
epilepsy
clinical manifestations
diagnosis
therapy
title Genetic epilepsy caused by CDKL5 gene mutations as an example of epileptic encephalopathy and developmental encephalopathy: literature review and own observations
title_full Genetic epilepsy caused by CDKL5 gene mutations as an example of epileptic encephalopathy and developmental encephalopathy: literature review and own observations
title_fullStr Genetic epilepsy caused by CDKL5 gene mutations as an example of epileptic encephalopathy and developmental encephalopathy: literature review and own observations
title_full_unstemmed Genetic epilepsy caused by CDKL5 gene mutations as an example of epileptic encephalopathy and developmental encephalopathy: literature review and own observations
title_short Genetic epilepsy caused by CDKL5 gene mutations as an example of epileptic encephalopathy and developmental encephalopathy: literature review and own observations
title_sort genetic epilepsy caused by cdkl5 gene mutations as an example of epileptic encephalopathy and developmental encephalopathy literature review and own observations
topic epileptic encephalopathy
developmental encephalopathy
early epileptic encephalopathy
cdkl5 gene
epilepsy
clinical manifestations
diagnosis
therapy
url https://rjdn.abvpress.ru/jour/article/view/360
work_keys_str_mv AT kyumukhin geneticepilepsycausedbycdkl5genemutationsasanexampleofepilepticencephalopathyanddevelopmentalencephalopathyliteraturereviewandownobservations
AT oapylaeva geneticepilepsycausedbycdkl5genemutationsasanexampleofepilepticencephalopathyanddevelopmentalencephalopathyliteraturereviewandownobservations
AT myubobylova geneticepilepsycausedbycdkl5genemutationsasanexampleofepilepticencephalopathyanddevelopmentalencephalopathyliteraturereviewandownobservations
AT vachadaev geneticepilepsycausedbycdkl5genemutationsasanexampleofepilepticencephalopathyanddevelopmentalencephalopathyliteraturereviewandownobservations