Blastic Plasmacytoid Dendritic Cell Neoplasm Mimicking Erythema Nodosum: A Case Report

Blastic plasmacytoid dendritic cell neoplasm (BPDCN), previously known as blastic natural killer cell lymphoma, is a rare, difficult-to-diagnose, and aggressive hematologic malignancy. Skin lesions are the initial presentation of BPDCN in 64% to 77% of cases, characterized by brown to purple nodular...

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Main Authors: Marino Hirata, Nozomu Yoshino, Maya Takazawa, Hisashi Oshiro, Shinichi Kako, Hitoshi Sugawara
Format: Article
Language:English
Published: American College of Physicians 2023-02-01
Series:Annals of Internal Medicine: Clinical Cases
Online Access:https://www.acpjournals.org/doi/10.7326/aimcc.2022.0920
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author Marino Hirata
Nozomu Yoshino
Maya Takazawa
Hisashi Oshiro
Shinichi Kako
Hitoshi Sugawara
author_facet Marino Hirata
Nozomu Yoshino
Maya Takazawa
Hisashi Oshiro
Shinichi Kako
Hitoshi Sugawara
author_sort Marino Hirata
collection DOAJ
description Blastic plasmacytoid dendritic cell neoplasm (BPDCN), previously known as blastic natural killer cell lymphoma, is a rare, difficult-to-diagnose, and aggressive hematologic malignancy. Skin lesions are the initial presentation of BPDCN in 64% to 77% of cases, characterized by brown to purple nodular or bruised macular lesions in solitary or multiple locations. Here, we report the case of a 57-year-old man who initially presented with refractory erythema nodosum symptoms, including fever, arthritis, and painful erythema, and was finally diagnosed with BPDCN after a second skin biopsy. This case illustrates that skin lesions caused by BPDCN mimic ordinary erythema nodosum.
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issn 2767-7664
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publishDate 2023-02-01
publisher American College of Physicians
record_format Article
series Annals of Internal Medicine: Clinical Cases
spelling doaj-art-6ff878b320914132a8f6944d1c8d2b9e2025-08-20T02:12:58ZengAmerican College of PhysiciansAnnals of Internal Medicine: Clinical Cases2767-76642023-02-012210.7326/aimcc.2022.0920Blastic Plasmacytoid Dendritic Cell Neoplasm Mimicking Erythema Nodosum: A Case ReportMarino Hirata0Nozomu Yoshino1Maya Takazawa2Hisashi Oshiro3Shinichi Kako4Hitoshi Sugawara51Saitama Medical Center, Jichi Medical University, Saitama City, Japan1Saitama Medical Center, Jichi Medical University, Saitama City, Japan1Saitama Medical Center, Jichi Medical University, Saitama City, Japan1Saitama Medical Center, Jichi Medical University, Saitama City, Japan1Saitama Medical Center, Jichi Medical University, Saitama City, Japan1Saitama Medical Center, Jichi Medical University, Saitama City, JapanBlastic plasmacytoid dendritic cell neoplasm (BPDCN), previously known as blastic natural killer cell lymphoma, is a rare, difficult-to-diagnose, and aggressive hematologic malignancy. Skin lesions are the initial presentation of BPDCN in 64% to 77% of cases, characterized by brown to purple nodular or bruised macular lesions in solitary or multiple locations. Here, we report the case of a 57-year-old man who initially presented with refractory erythema nodosum symptoms, including fever, arthritis, and painful erythema, and was finally diagnosed with BPDCN after a second skin biopsy. This case illustrates that skin lesions caused by BPDCN mimic ordinary erythema nodosum.https://www.acpjournals.org/doi/10.7326/aimcc.2022.0920
spellingShingle Marino Hirata
Nozomu Yoshino
Maya Takazawa
Hisashi Oshiro
Shinichi Kako
Hitoshi Sugawara
Blastic Plasmacytoid Dendritic Cell Neoplasm Mimicking Erythema Nodosum: A Case Report
Annals of Internal Medicine: Clinical Cases
title Blastic Plasmacytoid Dendritic Cell Neoplasm Mimicking Erythema Nodosum: A Case Report
title_full Blastic Plasmacytoid Dendritic Cell Neoplasm Mimicking Erythema Nodosum: A Case Report
title_fullStr Blastic Plasmacytoid Dendritic Cell Neoplasm Mimicking Erythema Nodosum: A Case Report
title_full_unstemmed Blastic Plasmacytoid Dendritic Cell Neoplasm Mimicking Erythema Nodosum: A Case Report
title_short Blastic Plasmacytoid Dendritic Cell Neoplasm Mimicking Erythema Nodosum: A Case Report
title_sort blastic plasmacytoid dendritic cell neoplasm mimicking erythema nodosum a case report
url https://www.acpjournals.org/doi/10.7326/aimcc.2022.0920
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