Anorectal malformations (ARM) and VACTERL association and severity of congenital heart diseases (CHD): Experience of 396 consecutive patients in a tertiary center

Objective: Congenital heart diseases (CHD) are the most frequently associated anomalies with anorectal malformations (ARM). Nevertheless, many specific aspects of CHD in ARM patients have yet to be studied. The aims of this study were to evaluate the prevalence and distribution of CHD in neonates-in...

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Main Authors: Patrizio Moras, Angelo Zarfati, Pietro Bagolan, Andrea Conforti, Alessandra Toscano, Barbara Daniela Iacobelli
Format: Article
Language:English
Published: Elsevier 2024-07-01
Series:Pediatrics and Neonatology
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Online Access:http://www.sciencedirect.com/science/article/pii/S1875957223002243
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author Patrizio Moras
Angelo Zarfati
Pietro Bagolan
Andrea Conforti
Alessandra Toscano
Barbara Daniela Iacobelli
author_facet Patrizio Moras
Angelo Zarfati
Pietro Bagolan
Andrea Conforti
Alessandra Toscano
Barbara Daniela Iacobelli
author_sort Patrizio Moras
collection DOAJ
description Objective: Congenital heart diseases (CHD) are the most frequently associated anomalies with anorectal malformations (ARM). Nevertheless, many specific aspects of CHD in ARM patients have yet to be studied. The aims of this study were to evaluate the prevalence and distribution of CHD in neonates-infants with ARM, and to explore whether the severity of ARM, and the presence of VACTERL association, had an impact on CHD rate, severity, and timing at first cardiac surgery. Study design: All consecutive newborn-infants with ARM managed in our tertiary center (January-1999; December-2021) were collected from a prospective database and retrospectively analyzed. Prevalence and distribution of CHD in ARM patients were assessed. Patients were divided into groups depending on ARM severity and presence of VACTERL association. Pairwise comparison for CHD prevalence, severity, and timing at first cardiac surgery was performed between groups. Results: Of 396 ARM patients identified, those with severe ARM showed a higher number of overall CHD compared to patients with non-severe ARM (36.7 % vs. 25.2 %, p = 0.032). VACTERL + patients had a significantly higher prevalence of CHD (73.4 % vs. 16.4 %; p <0.001) and major CHD (51.7 % vs. 26.9 %; p = 0.008) when compared with VACTERL-patients. Furthermore, VACTERL + patients underwent first cardiac surgery at a significantly younger age than VACTERL-patients (5.2 ± 15.2 months vs. 11.9 ± 6.3, p = 0.039). Conclusions: Patients with severe ARM had a higher number of CHD compared to patients with non-severe ARM. VATERL + patients had significantly more CHD and more severe CHD than VACTERL-patients. Early screening for CHD is strongly recommended in all newborns diagnosed with ARM before surgery. Level of evidence: III retrospective comparative study.
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spelling doaj-art-6cc5c1ccbaf1421ebd23d1f64cf675c82025-08-20T03:03:42ZengElsevierPediatrics and Neonatology1875-95722024-07-0165438138510.1016/j.pedneo.2023.08.011Anorectal malformations (ARM) and VACTERL association and severity of congenital heart diseases (CHD): Experience of 396 consecutive patients in a tertiary centerPatrizio Moras0Angelo Zarfati1Pietro Bagolan2Andrea Conforti3Alessandra Toscano4Barbara Daniela Iacobelli5Perinatal Cardiology Unit, Bambino Gesù Children's Hospital, IRCCS, Rome, ItalyNeonatal Surgery Unit, Bambino Gesù Children's Hospital, IRCCS, Rome, Italy; Department of Systems Medicine, University of Rome “Tor Vergata”, Rome, Italy; Corresponding author. Piazza Sant’Onofrio, 4 – 00165, Rome, Italy.Neonatal Surgery Unit, Bambino Gesù Children's Hospital, IRCCS, Rome, Italy; Department of Systems Medicine, University of Rome “Tor Vergata”, Rome, ItalyNeonatal Surgery Unit, Bambino Gesù Children's Hospital, IRCCS, Rome, ItalyPerinatal Cardiology Unit, Bambino Gesù Children's Hospital, IRCCS, Rome, ItalyNeonatal Surgery Unit, Bambino Gesù Children's Hospital, IRCCS, Rome, ItalyObjective: Congenital heart diseases (CHD) are the most frequently associated anomalies with anorectal malformations (ARM). Nevertheless, many specific aspects of CHD in ARM patients have yet to be studied. The aims of this study were to evaluate the prevalence and distribution of CHD in neonates-infants with ARM, and to explore whether the severity of ARM, and the presence of VACTERL association, had an impact on CHD rate, severity, and timing at first cardiac surgery. Study design: All consecutive newborn-infants with ARM managed in our tertiary center (January-1999; December-2021) were collected from a prospective database and retrospectively analyzed. Prevalence and distribution of CHD in ARM patients were assessed. Patients were divided into groups depending on ARM severity and presence of VACTERL association. Pairwise comparison for CHD prevalence, severity, and timing at first cardiac surgery was performed between groups. Results: Of 396 ARM patients identified, those with severe ARM showed a higher number of overall CHD compared to patients with non-severe ARM (36.7 % vs. 25.2 %, p = 0.032). VACTERL + patients had a significantly higher prevalence of CHD (73.4 % vs. 16.4 %; p <0.001) and major CHD (51.7 % vs. 26.9 %; p = 0.008) when compared with VACTERL-patients. Furthermore, VACTERL + patients underwent first cardiac surgery at a significantly younger age than VACTERL-patients (5.2 ± 15.2 months vs. 11.9 ± 6.3, p = 0.039). Conclusions: Patients with severe ARM had a higher number of CHD compared to patients with non-severe ARM. VATERL + patients had significantly more CHD and more severe CHD than VACTERL-patients. Early screening for CHD is strongly recommended in all newborns diagnosed with ARM before surgery. Level of evidence: III retrospective comparative study.http://www.sciencedirect.com/science/article/pii/S1875957223002243Anorectal malformationsARMVACTERLVACTERL associationCongenital heart diseaseCHD
spellingShingle Patrizio Moras
Angelo Zarfati
Pietro Bagolan
Andrea Conforti
Alessandra Toscano
Barbara Daniela Iacobelli
Anorectal malformations (ARM) and VACTERL association and severity of congenital heart diseases (CHD): Experience of 396 consecutive patients in a tertiary center
Pediatrics and Neonatology
Anorectal malformations
ARM
VACTERL
VACTERL association
Congenital heart disease
CHD
title Anorectal malformations (ARM) and VACTERL association and severity of congenital heart diseases (CHD): Experience of 396 consecutive patients in a tertiary center
title_full Anorectal malformations (ARM) and VACTERL association and severity of congenital heart diseases (CHD): Experience of 396 consecutive patients in a tertiary center
title_fullStr Anorectal malformations (ARM) and VACTERL association and severity of congenital heart diseases (CHD): Experience of 396 consecutive patients in a tertiary center
title_full_unstemmed Anorectal malformations (ARM) and VACTERL association and severity of congenital heart diseases (CHD): Experience of 396 consecutive patients in a tertiary center
title_short Anorectal malformations (ARM) and VACTERL association and severity of congenital heart diseases (CHD): Experience of 396 consecutive patients in a tertiary center
title_sort anorectal malformations arm and vacterl association and severity of congenital heart diseases chd experience of 396 consecutive patients in a tertiary center
topic Anorectal malformations
ARM
VACTERL
VACTERL association
Congenital heart disease
CHD
url http://www.sciencedirect.com/science/article/pii/S1875957223002243
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