Ablation of Prion Protein in Wild Type Human Amyloid Precursor Protein (APP) Transgenic Mice Does Not Alter The Proteolysis of APP, Levels of Amyloid-β or Pathologic Phenotype.

The cellular prion protein (PrPC) has been proposed to play an important role in the pathogenesis of Alzheimer's disease. In cellular models PrPC inhibited the action of the β-secretase BACE1 on wild type amyloid precursor protein resulting in a reduction in amyloid-β (Aβ) peptides. Here we hav...

Full description

Saved in:
Bibliographic Details
Main Authors: Isobel J Whitehouse, Deborah Brown, Herbert Baybutt, Abigail B Diack, Katherine A B Kellett, Pedro Piccardo, Jean C Manson, Nigel M Hooper
Format: Article
Language:English
Published: Public Library of Science (PLoS) 2016-01-01
Series:PLoS ONE
Online Access:https://journals.plos.org/plosone/article/file?id=10.1371/journal.pone.0159119&type=printable
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1850232484616208384
author Isobel J Whitehouse
Deborah Brown
Herbert Baybutt
Abigail B Diack
Katherine A B Kellett
Pedro Piccardo
Jean C Manson
Nigel M Hooper
author_facet Isobel J Whitehouse
Deborah Brown
Herbert Baybutt
Abigail B Diack
Katherine A B Kellett
Pedro Piccardo
Jean C Manson
Nigel M Hooper
author_sort Isobel J Whitehouse
collection DOAJ
description The cellular prion protein (PrPC) has been proposed to play an important role in the pathogenesis of Alzheimer's disease. In cellular models PrPC inhibited the action of the β-secretase BACE1 on wild type amyloid precursor protein resulting in a reduction in amyloid-β (Aβ) peptides. Here we have assessed the effect of genetic ablation of PrPC in transgenic mice expressing human wild type amyloid precursor protein (line I5). Deletion of PrPC had no effect on the α- and β-secretase proteolysis of the amyloid precursor protein (APP) nor on the amount of Aβ38, Aβ40 or Aβ42 in the brains of the mice. In addition, ablation of PrPC did not alter Aβ deposition or histopathology phenotype in this transgenic model. Thus using this transgenic model we could not provide evidence to support the hypothesis that PrPC regulates Aβ production.
format Article
id doaj-art-661eb766a5da451a8aa047e01b1089fe
institution OA Journals
issn 1932-6203
language English
publishDate 2016-01-01
publisher Public Library of Science (PLoS)
record_format Article
series PLoS ONE
spelling doaj-art-661eb766a5da451a8aa047e01b1089fe2025-08-20T02:03:12ZengPublic Library of Science (PLoS)PLoS ONE1932-62032016-01-01117e015911910.1371/journal.pone.0159119Ablation of Prion Protein in Wild Type Human Amyloid Precursor Protein (APP) Transgenic Mice Does Not Alter The Proteolysis of APP, Levels of Amyloid-β or Pathologic Phenotype.Isobel J WhitehouseDeborah BrownHerbert BaybuttAbigail B DiackKatherine A B KellettPedro PiccardoJean C MansonNigel M HooperThe cellular prion protein (PrPC) has been proposed to play an important role in the pathogenesis of Alzheimer's disease. In cellular models PrPC inhibited the action of the β-secretase BACE1 on wild type amyloid precursor protein resulting in a reduction in amyloid-β (Aβ) peptides. Here we have assessed the effect of genetic ablation of PrPC in transgenic mice expressing human wild type amyloid precursor protein (line I5). Deletion of PrPC had no effect on the α- and β-secretase proteolysis of the amyloid precursor protein (APP) nor on the amount of Aβ38, Aβ40 or Aβ42 in the brains of the mice. In addition, ablation of PrPC did not alter Aβ deposition or histopathology phenotype in this transgenic model. Thus using this transgenic model we could not provide evidence to support the hypothesis that PrPC regulates Aβ production.https://journals.plos.org/plosone/article/file?id=10.1371/journal.pone.0159119&type=printable
spellingShingle Isobel J Whitehouse
Deborah Brown
Herbert Baybutt
Abigail B Diack
Katherine A B Kellett
Pedro Piccardo
Jean C Manson
Nigel M Hooper
Ablation of Prion Protein in Wild Type Human Amyloid Precursor Protein (APP) Transgenic Mice Does Not Alter The Proteolysis of APP, Levels of Amyloid-β or Pathologic Phenotype.
PLoS ONE
title Ablation of Prion Protein in Wild Type Human Amyloid Precursor Protein (APP) Transgenic Mice Does Not Alter The Proteolysis of APP, Levels of Amyloid-β or Pathologic Phenotype.
title_full Ablation of Prion Protein in Wild Type Human Amyloid Precursor Protein (APP) Transgenic Mice Does Not Alter The Proteolysis of APP, Levels of Amyloid-β or Pathologic Phenotype.
title_fullStr Ablation of Prion Protein in Wild Type Human Amyloid Precursor Protein (APP) Transgenic Mice Does Not Alter The Proteolysis of APP, Levels of Amyloid-β or Pathologic Phenotype.
title_full_unstemmed Ablation of Prion Protein in Wild Type Human Amyloid Precursor Protein (APP) Transgenic Mice Does Not Alter The Proteolysis of APP, Levels of Amyloid-β or Pathologic Phenotype.
title_short Ablation of Prion Protein in Wild Type Human Amyloid Precursor Protein (APP) Transgenic Mice Does Not Alter The Proteolysis of APP, Levels of Amyloid-β or Pathologic Phenotype.
title_sort ablation of prion protein in wild type human amyloid precursor protein app transgenic mice does not alter the proteolysis of app levels of amyloid β or pathologic phenotype
url https://journals.plos.org/plosone/article/file?id=10.1371/journal.pone.0159119&type=printable
work_keys_str_mv AT isobeljwhitehouse ablationofprionproteininwildtypehumanamyloidprecursorproteinapptransgenicmicedoesnotaltertheproteolysisofapplevelsofamyloidborpathologicphenotype
AT deborahbrown ablationofprionproteininwildtypehumanamyloidprecursorproteinapptransgenicmicedoesnotaltertheproteolysisofapplevelsofamyloidborpathologicphenotype
AT herbertbaybutt ablationofprionproteininwildtypehumanamyloidprecursorproteinapptransgenicmicedoesnotaltertheproteolysisofapplevelsofamyloidborpathologicphenotype
AT abigailbdiack ablationofprionproteininwildtypehumanamyloidprecursorproteinapptransgenicmicedoesnotaltertheproteolysisofapplevelsofamyloidborpathologicphenotype
AT katherineabkellett ablationofprionproteininwildtypehumanamyloidprecursorproteinapptransgenicmicedoesnotaltertheproteolysisofapplevelsofamyloidborpathologicphenotype
AT pedropiccardo ablationofprionproteininwildtypehumanamyloidprecursorproteinapptransgenicmicedoesnotaltertheproteolysisofapplevelsofamyloidborpathologicphenotype
AT jeancmanson ablationofprionproteininwildtypehumanamyloidprecursorproteinapptransgenicmicedoesnotaltertheproteolysisofapplevelsofamyloidborpathologicphenotype
AT nigelmhooper ablationofprionproteininwildtypehumanamyloidprecursorproteinapptransgenicmicedoesnotaltertheproteolysisofapplevelsofamyloidborpathologicphenotype