Early Death in Two Patients with Acute Promyelocytic Leukemia Presenting the bcr3 Isoform, FLT3-ITD Mutation, and Elevated WT1 Level

Despite major advances in the treatment of acute promyelocytic leukemia (APL), the problem of early death (ED) remains unsolved. Alongside the currently known clinical and hematological risk factors, prognostic significance has been attributed to internal tandem duplication mutations of the fms-like...

Full description

Saved in:
Bibliographic Details
Main Authors: Marianna Greco, Giovanni Caocci, Antonio Ledda, Adriana Vacca, Marcella Arras, Ivana Celeghini, Giorgio La Nasa
Format: Article
Language:English
Published: Wiley 2013-01-01
Series:Case Reports in Hematology
Online Access:http://dx.doi.org/10.1155/2013/896394
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1849412939819253760
author Marianna Greco
Giovanni Caocci
Antonio Ledda
Adriana Vacca
Marcella Arras
Ivana Celeghini
Giorgio La Nasa
author_facet Marianna Greco
Giovanni Caocci
Antonio Ledda
Adriana Vacca
Marcella Arras
Ivana Celeghini
Giorgio La Nasa
author_sort Marianna Greco
collection DOAJ
description Despite major advances in the treatment of acute promyelocytic leukemia (APL), the problem of early death (ED) remains unsolved. Alongside the currently known clinical and hematological risk factors, prognostic significance has been attributed to internal tandem duplication mutations of the fms-like tyrosine kinase-3 (FLT3-ITD), hypogranular variant morphology, and the bcr-3 isoform of PML-RARα. We describe premature death of two patients with the hypogranular variant of APL who presented remarkably high expression levels of Wilms' tumor gene (WT1). Our results point to WT1 as an important prognostic factor of ED that needs to be promptly evaluated in all newly diagnosed cases of APL.
format Article
id doaj-art-65e1565a4ebe4357b941798828eacac6
institution Kabale University
issn 2090-6560
2090-6579
language English
publishDate 2013-01-01
publisher Wiley
record_format Article
series Case Reports in Hematology
spelling doaj-art-65e1565a4ebe4357b941798828eacac62025-08-20T03:34:17ZengWileyCase Reports in Hematology2090-65602090-65792013-01-01201310.1155/2013/896394896394Early Death in Two Patients with Acute Promyelocytic Leukemia Presenting the bcr3 Isoform, FLT3-ITD Mutation, and Elevated WT1 LevelMarianna Greco0Giovanni Caocci1Antonio Ledda2Adriana Vacca3Marcella Arras4Ivana Celeghini5Giorgio La Nasa6Hematology Unit and Bone Marrow Transplantation Center, “R. Binaghi” Hospital, Via Is Guadazzonis 3, 09126 Cagliari, ItalyHematology Unit and Bone Marrow Transplantation Center, “R. Binaghi” Hospital, Via Is Guadazzonis 3, 09126 Cagliari, ItalyHematology Unit and Bone Marrow Transplantation Center, “R. Binaghi” Hospital, Via Is Guadazzonis 3, 09126 Cagliari, ItalyHematology Unit and Bone Marrow Transplantation Center, “R. Binaghi” Hospital, Via Is Guadazzonis 3, 09126 Cagliari, ItalyHematology Unit and Bone Marrow Transplantation Center, “R. Binaghi” Hospital, Via Is Guadazzonis 3, 09126 Cagliari, ItalyHematology Unit and Bone Marrow Transplantation Center, “R. Binaghi” Hospital, Via Is Guadazzonis 3, 09126 Cagliari, ItalyHematology Unit and Bone Marrow Transplantation Center, “R. Binaghi” Hospital, Via Is Guadazzonis 3, 09126 Cagliari, ItalyDespite major advances in the treatment of acute promyelocytic leukemia (APL), the problem of early death (ED) remains unsolved. Alongside the currently known clinical and hematological risk factors, prognostic significance has been attributed to internal tandem duplication mutations of the fms-like tyrosine kinase-3 (FLT3-ITD), hypogranular variant morphology, and the bcr-3 isoform of PML-RARα. We describe premature death of two patients with the hypogranular variant of APL who presented remarkably high expression levels of Wilms' tumor gene (WT1). Our results point to WT1 as an important prognostic factor of ED that needs to be promptly evaluated in all newly diagnosed cases of APL.http://dx.doi.org/10.1155/2013/896394
spellingShingle Marianna Greco
Giovanni Caocci
Antonio Ledda
Adriana Vacca
Marcella Arras
Ivana Celeghini
Giorgio La Nasa
Early Death in Two Patients with Acute Promyelocytic Leukemia Presenting the bcr3 Isoform, FLT3-ITD Mutation, and Elevated WT1 Level
Case Reports in Hematology
title Early Death in Two Patients with Acute Promyelocytic Leukemia Presenting the bcr3 Isoform, FLT3-ITD Mutation, and Elevated WT1 Level
title_full Early Death in Two Patients with Acute Promyelocytic Leukemia Presenting the bcr3 Isoform, FLT3-ITD Mutation, and Elevated WT1 Level
title_fullStr Early Death in Two Patients with Acute Promyelocytic Leukemia Presenting the bcr3 Isoform, FLT3-ITD Mutation, and Elevated WT1 Level
title_full_unstemmed Early Death in Two Patients with Acute Promyelocytic Leukemia Presenting the bcr3 Isoform, FLT3-ITD Mutation, and Elevated WT1 Level
title_short Early Death in Two Patients with Acute Promyelocytic Leukemia Presenting the bcr3 Isoform, FLT3-ITD Mutation, and Elevated WT1 Level
title_sort early death in two patients with acute promyelocytic leukemia presenting the bcr3 isoform flt3 itd mutation and elevated wt1 level
url http://dx.doi.org/10.1155/2013/896394
work_keys_str_mv AT mariannagreco earlydeathintwopatientswithacutepromyelocyticleukemiapresentingthebcr3isoformflt3itdmutationandelevatedwt1level
AT giovannicaocci earlydeathintwopatientswithacutepromyelocyticleukemiapresentingthebcr3isoformflt3itdmutationandelevatedwt1level
AT antonioledda earlydeathintwopatientswithacutepromyelocyticleukemiapresentingthebcr3isoformflt3itdmutationandelevatedwt1level
AT adrianavacca earlydeathintwopatientswithacutepromyelocyticleukemiapresentingthebcr3isoformflt3itdmutationandelevatedwt1level
AT marcellaarras earlydeathintwopatientswithacutepromyelocyticleukemiapresentingthebcr3isoformflt3itdmutationandelevatedwt1level
AT ivanaceleghini earlydeathintwopatientswithacutepromyelocyticleukemiapresentingthebcr3isoformflt3itdmutationandelevatedwt1level
AT giorgiolanasa earlydeathintwopatientswithacutepromyelocyticleukemiapresentingthebcr3isoformflt3itdmutationandelevatedwt1level