A case report about focal status epilepticus as first presentation in Alzheimer’s disease: finding the culprit

Abstract Background Neuronal hyperexcitability has been proposed to play a key role in Alzheimer’s disease (AD). Understanding the relation between this enhanced excitability and AD pathology could provide a window for therapeutic interventions. However epileptiform activity is often subclinical, hi...

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Main Authors: Astrid Devulder, Greet Vanderlinden, Evy Cleeren, Valerie Goovaerts, Tom Theys, Koen Van Laere, Wim Van Paesschen
Format: Article
Language:English
Published: BMC 2024-12-01
Series:BMC Neurology
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Online Access:https://doi.org/10.1186/s12883-024-03979-4
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author Astrid Devulder
Greet Vanderlinden
Evy Cleeren
Valerie Goovaerts
Tom Theys
Koen Van Laere
Wim Van Paesschen
author_facet Astrid Devulder
Greet Vanderlinden
Evy Cleeren
Valerie Goovaerts
Tom Theys
Koen Van Laere
Wim Van Paesschen
author_sort Astrid Devulder
collection DOAJ
description Abstract Background Neuronal hyperexcitability has been proposed to play a key role in Alzheimer’s disease (AD). Understanding the relation between this enhanced excitability and AD pathology could provide a window for therapeutic interventions. However epileptiform activity is often subclinical, hidden on scalp EEG and very challenging to assess with current diagnostic modalities. Case presentation A woman in her sixties presented with acute confusion. Despite a normal scalp electroencephalogram (EEG), magnetic resonance imaging (MRI) showed cytotoxic edema of the right mesial temporal lobe and hippocampal hypermetabolism was present on ([18F]-fluoro-2-deoxyglucose positron emission tomography (PET). Bilateral foramen ovale (FO) electrodes were placed to directly record mesial temporal activity and revealed continuous mesial temporal epileptic activity, while scalp EEG remained normal. After recovery, a new diagnosis of AD was established on cerebrospinal fluid. The lateralization of the epileptiform activity was congruent with the predominant side of tau pathology in the mesial temporal cortex on 18F-MK6240 PET. On follow-up MRI, two and five months later, the right hippocampus became atrophic. Conclusion This case highlights the significant role of neuronal hyperexcitability in early AD pathogenesis and how shared mechanisms between AD and epilepsy can complicate clinical management.
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issn 1471-2377
language English
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spelling doaj-art-65298b95016e4e008cfe1d666896eca42025-08-20T01:57:16ZengBMCBMC Neurology1471-23772024-12-012411510.1186/s12883-024-03979-4A case report about focal status epilepticus as first presentation in Alzheimer’s disease: finding the culpritAstrid Devulder0Greet Vanderlinden1Evy Cleeren2Valerie Goovaerts3Tom Theys4Koen Van Laere5Wim Van Paesschen6Laboratory for Epilepsy ResearchNuclear Medicine and Molecular Imaging, Department of Imaging and PathologyDepartment of Neurology, University Hospitals LeuvenDepartment of Neurology, University Hospitals LeuvenResearch Group Experimental Neurosurgery and NeuroanatomyNuclear Medicine and Molecular Imaging, Department of Imaging and PathologyLaboratory for Epilepsy ResearchAbstract Background Neuronal hyperexcitability has been proposed to play a key role in Alzheimer’s disease (AD). Understanding the relation between this enhanced excitability and AD pathology could provide a window for therapeutic interventions. However epileptiform activity is often subclinical, hidden on scalp EEG and very challenging to assess with current diagnostic modalities. Case presentation A woman in her sixties presented with acute confusion. Despite a normal scalp electroencephalogram (EEG), magnetic resonance imaging (MRI) showed cytotoxic edema of the right mesial temporal lobe and hippocampal hypermetabolism was present on ([18F]-fluoro-2-deoxyglucose positron emission tomography (PET). Bilateral foramen ovale (FO) electrodes were placed to directly record mesial temporal activity and revealed continuous mesial temporal epileptic activity, while scalp EEG remained normal. After recovery, a new diagnosis of AD was established on cerebrospinal fluid. The lateralization of the epileptiform activity was congruent with the predominant side of tau pathology in the mesial temporal cortex on 18F-MK6240 PET. On follow-up MRI, two and five months later, the right hippocampus became atrophic. Conclusion This case highlights the significant role of neuronal hyperexcitability in early AD pathogenesis and how shared mechanisms between AD and epilepsy can complicate clinical management.https://doi.org/10.1186/s12883-024-03979-4Alzheimer’s diseaseCase reportHippocampal atrophyTau pathologyTemporal lobe epilepsy
spellingShingle Astrid Devulder
Greet Vanderlinden
Evy Cleeren
Valerie Goovaerts
Tom Theys
Koen Van Laere
Wim Van Paesschen
A case report about focal status epilepticus as first presentation in Alzheimer’s disease: finding the culprit
BMC Neurology
Alzheimer’s disease
Case report
Hippocampal atrophy
Tau pathology
Temporal lobe epilepsy
title A case report about focal status epilepticus as first presentation in Alzheimer’s disease: finding the culprit
title_full A case report about focal status epilepticus as first presentation in Alzheimer’s disease: finding the culprit
title_fullStr A case report about focal status epilepticus as first presentation in Alzheimer’s disease: finding the culprit
title_full_unstemmed A case report about focal status epilepticus as first presentation in Alzheimer’s disease: finding the culprit
title_short A case report about focal status epilepticus as first presentation in Alzheimer’s disease: finding the culprit
title_sort case report about focal status epilepticus as first presentation in alzheimer s disease finding the culprit
topic Alzheimer’s disease
Case report
Hippocampal atrophy
Tau pathology
Temporal lobe epilepsy
url https://doi.org/10.1186/s12883-024-03979-4
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