Neuromyelitis Optica Spectrum Disorders Mimicking Wernicke’s Encephalopathy: A Difficult Differential Diagnosis

Neuromyelitis optica spectrum disorders (NMOSD) encompass a spectrum of immunomediated diseases presenting with diverse syndromes. Conversely, Wernicke’s encephalopathy denotes an acute neurological condition stemming from severe thiamine (Vitamin B1) deficiency. We report a unique case of NMOSD man...

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Main Authors: Hussein Algahtani, Bader Shirah, Fawzia Alahmri, Nawal Abdelghaffar, Saeed A. Alqahtani
Format: Article
Language:English
Published: Wolters Kluwer Medknow Publications 2025-01-01
Series:Acta Neurologica Taiwanica
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Online Access:https://journals.lww.com/10.4103/ANT.ANT_112_0071
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author Hussein Algahtani
Bader Shirah
Fawzia Alahmri
Nawal Abdelghaffar
Saeed A. Alqahtani
author_facet Hussein Algahtani
Bader Shirah
Fawzia Alahmri
Nawal Abdelghaffar
Saeed A. Alqahtani
author_sort Hussein Algahtani
collection DOAJ
description Neuromyelitis optica spectrum disorders (NMOSD) encompass a spectrum of immunomediated diseases presenting with diverse syndromes. Conversely, Wernicke’s encephalopathy denotes an acute neurological condition stemming from severe thiamine (Vitamin B1) deficiency. We report a unique case of NMOSD manifesting with clinical and radiological characteristics resembling Wernicke’s encephalopathy, exhibiting unresponsiveness to thiamine therapy and subsequent clinical deterioration. Our report highlights an atypical and rare presentation of NMOSD, initially confounded by changes on magnetic resonance imaging attributed to thiamine deficiency, delaying appropriate management during the early hospitalization period. While brain abnormalities are frequently documented in NMOSD, the occurrence of vertigo as an inaugural symptom is seldom reported. The patient demonstrated recovery following aggressive therapeutic interventions, including pulse steroids, plasma exchange, and rituximab therapy. Our case underscores the importance of considering NMOSD in patients displaying clinical and radiological features reminiscent of Wernicke’s encephalopathy, particularly when thiamine replacement fails to elicit a response. Clinicians must recognize this unusual presentation of NMOSD promptly and initiate aggressive therapeutic measures. Early diagnosis assumes critical significance to promptly commence aggressive immunomodulatory therapy.
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spelling doaj-art-632f4c5f2ea3474b94259cde9e65fae52025-08-20T03:25:59ZengWolters Kluwer Medknow PublicationsActa Neurologica Taiwanica1028-768X2025-01-01341434710.4103/ANT.ANT_112_0071Neuromyelitis Optica Spectrum Disorders Mimicking Wernicke’s Encephalopathy: A Difficult Differential DiagnosisHussein AlgahtaniBader ShirahFawzia AlahmriNawal AbdelghaffarSaeed A. AlqahtaniNeuromyelitis optica spectrum disorders (NMOSD) encompass a spectrum of immunomediated diseases presenting with diverse syndromes. Conversely, Wernicke’s encephalopathy denotes an acute neurological condition stemming from severe thiamine (Vitamin B1) deficiency. We report a unique case of NMOSD manifesting with clinical and radiological characteristics resembling Wernicke’s encephalopathy, exhibiting unresponsiveness to thiamine therapy and subsequent clinical deterioration. Our report highlights an atypical and rare presentation of NMOSD, initially confounded by changes on magnetic resonance imaging attributed to thiamine deficiency, delaying appropriate management during the early hospitalization period. While brain abnormalities are frequently documented in NMOSD, the occurrence of vertigo as an inaugural symptom is seldom reported. The patient demonstrated recovery following aggressive therapeutic interventions, including pulse steroids, plasma exchange, and rituximab therapy. Our case underscores the importance of considering NMOSD in patients displaying clinical and radiological features reminiscent of Wernicke’s encephalopathy, particularly when thiamine replacement fails to elicit a response. Clinicians must recognize this unusual presentation of NMOSD promptly and initiate aggressive therapeutic measures. Early diagnosis assumes critical significance to promptly commence aggressive immunomodulatory therapy.https://journals.lww.com/10.4103/ANT.ANT_112_0071case reportneuromyelitis optica spectrum disordersvertigowernicke’s encephalopathy
spellingShingle Hussein Algahtani
Bader Shirah
Fawzia Alahmri
Nawal Abdelghaffar
Saeed A. Alqahtani
Neuromyelitis Optica Spectrum Disorders Mimicking Wernicke’s Encephalopathy: A Difficult Differential Diagnosis
Acta Neurologica Taiwanica
case report
neuromyelitis optica spectrum disorders
vertigo
wernicke’s encephalopathy
title Neuromyelitis Optica Spectrum Disorders Mimicking Wernicke’s Encephalopathy: A Difficult Differential Diagnosis
title_full Neuromyelitis Optica Spectrum Disorders Mimicking Wernicke’s Encephalopathy: A Difficult Differential Diagnosis
title_fullStr Neuromyelitis Optica Spectrum Disorders Mimicking Wernicke’s Encephalopathy: A Difficult Differential Diagnosis
title_full_unstemmed Neuromyelitis Optica Spectrum Disorders Mimicking Wernicke’s Encephalopathy: A Difficult Differential Diagnosis
title_short Neuromyelitis Optica Spectrum Disorders Mimicking Wernicke’s Encephalopathy: A Difficult Differential Diagnosis
title_sort neuromyelitis optica spectrum disorders mimicking wernicke s encephalopathy a difficult differential diagnosis
topic case report
neuromyelitis optica spectrum disorders
vertigo
wernicke’s encephalopathy
url https://journals.lww.com/10.4103/ANT.ANT_112_0071
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AT fawziaalahmri neuromyelitisopticaspectrumdisordersmimickingwernickesencephalopathyadifficultdifferentialdiagnosis
AT nawalabdelghaffar neuromyelitisopticaspectrumdisordersmimickingwernickesencephalopathyadifficultdifferentialdiagnosis
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