A case report of anal fistula-associated mucinous adenocarcinoma developing 3 years after treatment of perianal abscess

Abstract Background A long-standing (over 10 years) anal fistula is considered a fundamental cause of fistula-associated mucinous adenocarcinoma (FAMC). Perianal abscesses and anal fistulas are two sequential phases of the same anorectal infectious process. We experienced a case of FAMC which develo...

Full description

Saved in:
Bibliographic Details
Main Authors: Michihiro Koizumi, Akihisa Matsuda, Takeshi Yamada, Koji Morimoto, Itaru Kubota, Yawara Kubota, Shuzo Tamura, Kenta Tominaga, Takashi Sakatani, Hiroshi Yoshida
Format: Article
Language:English
Published: Japan Surgical Society 2023-09-01
Series:Surgical Case Reports
Subjects:
Online Access:https://doi.org/10.1186/s40792-023-01743-3
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1849416347425964032
author Michihiro Koizumi
Akihisa Matsuda
Takeshi Yamada
Koji Morimoto
Itaru Kubota
Yawara Kubota
Shuzo Tamura
Kenta Tominaga
Takashi Sakatani
Hiroshi Yoshida
author_facet Michihiro Koizumi
Akihisa Matsuda
Takeshi Yamada
Koji Morimoto
Itaru Kubota
Yawara Kubota
Shuzo Tamura
Kenta Tominaga
Takashi Sakatani
Hiroshi Yoshida
author_sort Michihiro Koizumi
collection DOAJ
description Abstract Background A long-standing (over 10 years) anal fistula is considered a fundamental cause of fistula-associated mucinous adenocarcinoma (FAMC). Perianal abscesses and anal fistulas are two sequential phases of the same anorectal infectious process. We experienced a case of FAMC which developed 3 years after the treatment of a perianal abscess. Case presentation A 68-year-old woman was admitted to our hospital because of progressive anal pain and a palpable tumor. She had a history of undergoing a drainage operation for a perianal abscess 3 years previously. A 15 × 15-mm tumor at the former drainage site was identified; transanal ultrasonography showed an intersphincteric fistula connecting to the tumor. A biopsy taken from the tumor demonstrated mucinous adenocarcinoma; the tumor was diagnosed as FAMC. Laparoscopic abdominoperineal resection was performed. Histopathology showed highly dysplastic cells lining the lumen of the anal fistula and poorly differentiated mucinous adenocarcinoma proliferating in the dermis and epidermis in the distal aspect of the fistula. Conclusions FAMC can develop within fewer than 3 years after the development of a perianal abscess and anal fistula.
format Article
id doaj-art-61c27de32bf0425d9fe0bd77969e30bd
institution Kabale University
issn 2198-7793
language English
publishDate 2023-09-01
publisher Japan Surgical Society
record_format Article
series Surgical Case Reports
spelling doaj-art-61c27de32bf0425d9fe0bd77969e30bd2025-08-20T03:33:13ZengJapan Surgical SocietySurgical Case Reports2198-77932023-09-01911510.1186/s40792-023-01743-3A case report of anal fistula-associated mucinous adenocarcinoma developing 3 years after treatment of perianal abscessMichihiro Koizumi0Akihisa Matsuda1Takeshi Yamada2Koji Morimoto3Itaru Kubota4Yawara Kubota5Shuzo Tamura6Kenta Tominaga7Takashi Sakatani8Hiroshi Yoshida9Nishiarai Coloproctology ClinicDepartment of Gastrointestinal and Hepato‐Biliary‐Pancreatic Surgery, Nippon Medical SchoolDepartment of Gastrointestinal and Hepato‐Biliary‐Pancreatic Surgery, Nippon Medical SchoolNishiarai Coloproctology ClinicNishiarai Coloproctology ClinicNishiarai Coloproctology ClinicNishiarai Coloproctology ClinicDepartment of Diagnostic Pathology, Nippon Medical SchoolDepartment of Diagnostic Pathology, Nippon Medical SchoolDepartment of Gastrointestinal and Hepato‐Biliary‐Pancreatic Surgery, Nippon Medical SchoolAbstract Background A long-standing (over 10 years) anal fistula is considered a fundamental cause of fistula-associated mucinous adenocarcinoma (FAMC). Perianal abscesses and anal fistulas are two sequential phases of the same anorectal infectious process. We experienced a case of FAMC which developed 3 years after the treatment of a perianal abscess. Case presentation A 68-year-old woman was admitted to our hospital because of progressive anal pain and a palpable tumor. She had a history of undergoing a drainage operation for a perianal abscess 3 years previously. A 15 × 15-mm tumor at the former drainage site was identified; transanal ultrasonography showed an intersphincteric fistula connecting to the tumor. A biopsy taken from the tumor demonstrated mucinous adenocarcinoma; the tumor was diagnosed as FAMC. Laparoscopic abdominoperineal resection was performed. Histopathology showed highly dysplastic cells lining the lumen of the anal fistula and poorly differentiated mucinous adenocarcinoma proliferating in the dermis and epidermis in the distal aspect of the fistula. Conclusions FAMC can develop within fewer than 3 years after the development of a perianal abscess and anal fistula.https://doi.org/10.1186/s40792-023-01743-3Fistula-associated mucinous adenocarcinomaAnal carcinomaAnal fistulaPerianal abscessCryptitisCryptoglandular infectious theory
spellingShingle Michihiro Koizumi
Akihisa Matsuda
Takeshi Yamada
Koji Morimoto
Itaru Kubota
Yawara Kubota
Shuzo Tamura
Kenta Tominaga
Takashi Sakatani
Hiroshi Yoshida
A case report of anal fistula-associated mucinous adenocarcinoma developing 3 years after treatment of perianal abscess
Surgical Case Reports
Fistula-associated mucinous adenocarcinoma
Anal carcinoma
Anal fistula
Perianal abscess
Cryptitis
Cryptoglandular infectious theory
title A case report of anal fistula-associated mucinous adenocarcinoma developing 3 years after treatment of perianal abscess
title_full A case report of anal fistula-associated mucinous adenocarcinoma developing 3 years after treatment of perianal abscess
title_fullStr A case report of anal fistula-associated mucinous adenocarcinoma developing 3 years after treatment of perianal abscess
title_full_unstemmed A case report of anal fistula-associated mucinous adenocarcinoma developing 3 years after treatment of perianal abscess
title_short A case report of anal fistula-associated mucinous adenocarcinoma developing 3 years after treatment of perianal abscess
title_sort case report of anal fistula associated mucinous adenocarcinoma developing 3 years after treatment of perianal abscess
topic Fistula-associated mucinous adenocarcinoma
Anal carcinoma
Anal fistula
Perianal abscess
Cryptitis
Cryptoglandular infectious theory
url https://doi.org/10.1186/s40792-023-01743-3
work_keys_str_mv AT michihirokoizumi acasereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT akihisamatsuda acasereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT takeshiyamada acasereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT kojimorimoto acasereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT itarukubota acasereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT yawarakubota acasereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT shuzotamura acasereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT kentatominaga acasereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT takashisakatani acasereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT hiroshiyoshida acasereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT michihirokoizumi casereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT akihisamatsuda casereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT takeshiyamada casereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT kojimorimoto casereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT itarukubota casereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT yawarakubota casereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT shuzotamura casereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT kentatominaga casereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT takashisakatani casereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess
AT hiroshiyoshida casereportofanalfistulaassociatedmucinousadenocarcinomadeveloping3yearsaftertreatmentofperianalabscess