A decade of insight: Understanding primary Leiomyosarcoma of the bone

Purpose: To investigate the clinical, radiological, histopathological features, survival outcomes, and prognostic factors of the rare primary leiomyosarcoma of bone (PBLMS). Methods: This was a retrospective study conducted between the year 2012–2022. 16 patients had biopsy-proven PBLMS out of 632 p...

Full description

Saved in:
Bibliographic Details
Main Authors: Himanshu Rohela, Anila Sharma, Vaibhav Sahu, Sunil Pasricha, Ullas Batra, Kundan Singh Chufal, Akshay Tiwari, Manish Pruthi, Gurudutt Gupta, Anurag Mehta
Format: Article
Language:English
Published: Elsevier 2025-04-01
Series:Journal of Orthopaedic Reports
Subjects:
Online Access:http://www.sciencedirect.com/science/article/pii/S2773157X25000086
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1849421693385179136
author Himanshu Rohela
Anila Sharma
Vaibhav Sahu
Sunil Pasricha
Ullas Batra
Kundan Singh Chufal
Akshay Tiwari
Manish Pruthi
Gurudutt Gupta
Anurag Mehta
author_facet Himanshu Rohela
Anila Sharma
Vaibhav Sahu
Sunil Pasricha
Ullas Batra
Kundan Singh Chufal
Akshay Tiwari
Manish Pruthi
Gurudutt Gupta
Anurag Mehta
author_sort Himanshu Rohela
collection DOAJ
description Purpose: To investigate the clinical, radiological, histopathological features, survival outcomes, and prognostic factors of the rare primary leiomyosarcoma of bone (PBLMS). Methods: This was a retrospective study conducted between the year 2012–2022. 16 patients had biopsy-proven PBLMS out of 632 primary bone sarcomas. Data was collected on patient details, tumor characteristics, treatment, and outcomes. Results: The study included 12 males and 4 females with a median age of 26.5 years. Common sites were femur (62 %), tibia (32 %), and humerus (6 %). Pathological fractures occurred in 19 %. Surgery was the primary treatment-limb salvage in 87.5 %, amputation in 12.5 % of the patients. Neo-adjuvant chemotherapy was given in 3 patients. Adjuvant chemotherapy and radiotherapy were given in 10 and 2 patients, respectively. One patient had local recurrence. Five patients developed distant metastasis. The 5-year OS and EFS rates were 62.5 % and 58.5 %, respectively. Higher tumor grade, local recurrence, and distant metastasis adversely impacted OS (p value < 0.05). Positive margins, pathological fracture, and distant metastasis negatively affected local recurrence. Conclusions: PBLMS is an aggressive sarcoma with high metastatic potential. Early detection and complete surgical resection with negative margins are crucial. The benefit of chemotherapy and radiotherapy remains unclear. Distant metastasis was the most significant adverse prognostic factor for overall survival.
format Article
id doaj-art-6067bfa33c334322aa3fad9d76af7749
institution Kabale University
issn 2773-157X
language English
publishDate 2025-04-01
publisher Elsevier
record_format Article
series Journal of Orthopaedic Reports
spelling doaj-art-6067bfa33c334322aa3fad9d76af77492025-08-20T03:31:24ZengElsevierJournal of Orthopaedic Reports2773-157X2025-04-014110055610.1016/j.jorep.2025.100556A decade of insight: Understanding primary Leiomyosarcoma of the boneHimanshu Rohela0Anila Sharma1Vaibhav Sahu2Sunil Pasricha3Ullas Batra4Kundan Singh Chufal5Akshay Tiwari6Manish Pruthi7Gurudutt Gupta8Anurag Mehta9Department of Musculoskeletal Surgical Oncology, Rajiv Gandhi Cancer Institute &amp; Research Centre, New Delhi, IndiaDepartment of Pathology, Rajiv Gandhi Cancer Institute &amp; Research Centre, New Delhi, IndiaDepartment of Musculoskeletal Surgical Oncology, Rajiv Gandhi Cancer Institute &amp; Research Centre, New Delhi, India; Corresponding author. Department of Musculoskeletal Surgical Oncology, Rajiv Gandhi Cancer Institute &amp; Research Centre, Sir Chotu Ram Marg, Rohini Institutional Area, Sector 5 Rohini, 110085, New Delhi, India.Department of Pathology, Rajiv Gandhi Cancer Institute &amp; Research Centre, New Delhi, IndiaDepartment of Medical Oncology, Rajiv Gandhi Cancer Institute &amp; Research Centre, New Delhi, IndiaDepartment of Radiation Oncology, Rajiv Gandhi Cancer Institute &amp; Research Centre, New Delhi, IndiaDepartment of Musculoskeletal Surgical Oncology, Max Institute of Cancer Care, New Delhi, IndiaDepartment of Musculoskeletal Surgical Oncology, Tata Memorial Hospital, Mumbai, IndiaDepartment of Pathology, Rajiv Gandhi Cancer Institute &amp; Research Centre, New Delhi, IndiaDepartment of Pathology, Rajiv Gandhi Cancer Institute &amp; Research Centre, New Delhi, IndiaPurpose: To investigate the clinical, radiological, histopathological features, survival outcomes, and prognostic factors of the rare primary leiomyosarcoma of bone (PBLMS). Methods: This was a retrospective study conducted between the year 2012–2022. 16 patients had biopsy-proven PBLMS out of 632 primary bone sarcomas. Data was collected on patient details, tumor characteristics, treatment, and outcomes. Results: The study included 12 males and 4 females with a median age of 26.5 years. Common sites were femur (62 %), tibia (32 %), and humerus (6 %). Pathological fractures occurred in 19 %. Surgery was the primary treatment-limb salvage in 87.5 %, amputation in 12.5 % of the patients. Neo-adjuvant chemotherapy was given in 3 patients. Adjuvant chemotherapy and radiotherapy were given in 10 and 2 patients, respectively. One patient had local recurrence. Five patients developed distant metastasis. The 5-year OS and EFS rates were 62.5 % and 58.5 %, respectively. Higher tumor grade, local recurrence, and distant metastasis adversely impacted OS (p value < 0.05). Positive margins, pathological fracture, and distant metastasis negatively affected local recurrence. Conclusions: PBLMS is an aggressive sarcoma with high metastatic potential. Early detection and complete surgical resection with negative margins are crucial. The benefit of chemotherapy and radiotherapy remains unclear. Distant metastasis was the most significant adverse prognostic factor for overall survival.http://www.sciencedirect.com/science/article/pii/S2773157X25000086LeiomyosarcomaBone sarcomaSurvivalChemotherapyRadiotherapy
spellingShingle Himanshu Rohela
Anila Sharma
Vaibhav Sahu
Sunil Pasricha
Ullas Batra
Kundan Singh Chufal
Akshay Tiwari
Manish Pruthi
Gurudutt Gupta
Anurag Mehta
A decade of insight: Understanding primary Leiomyosarcoma of the bone
Journal of Orthopaedic Reports
Leiomyosarcoma
Bone sarcoma
Survival
Chemotherapy
Radiotherapy
title A decade of insight: Understanding primary Leiomyosarcoma of the bone
title_full A decade of insight: Understanding primary Leiomyosarcoma of the bone
title_fullStr A decade of insight: Understanding primary Leiomyosarcoma of the bone
title_full_unstemmed A decade of insight: Understanding primary Leiomyosarcoma of the bone
title_short A decade of insight: Understanding primary Leiomyosarcoma of the bone
title_sort decade of insight understanding primary leiomyosarcoma of the bone
topic Leiomyosarcoma
Bone sarcoma
Survival
Chemotherapy
Radiotherapy
url http://www.sciencedirect.com/science/article/pii/S2773157X25000086
work_keys_str_mv AT himanshurohela adecadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT anilasharma adecadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT vaibhavsahu adecadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT sunilpasricha adecadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT ullasbatra adecadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT kundansinghchufal adecadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT akshaytiwari adecadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT manishpruthi adecadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT guruduttgupta adecadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT anuragmehta adecadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT himanshurohela decadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT anilasharma decadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT vaibhavsahu decadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT sunilpasricha decadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT ullasbatra decadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT kundansinghchufal decadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT akshaytiwari decadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT manishpruthi decadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT guruduttgupta decadeofinsightunderstandingprimaryleiomyosarcomaofthebone
AT anuragmehta decadeofinsightunderstandingprimaryleiomyosarcomaofthebone