Generation and validation of a novel multitarget small molecule in glioblastoma

Abstract The development of multitarget small molecules (MSMs) has emerged as a powerful strategy for the treatment of multifactorial diseases such as cancer. Glioblastoma is the most prevalent and malignant primary brain tumor in adults, which is characterized by poor prognosis and a high heterogen...

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Main Authors: Aizpea Artetxe-Zurutuza, Nerea Iturrioz-Rodriguez, Joseba Elizazu, Mireia Toledano-Pinedo, Alicia Porro-Pérez, Irati De Goñi, Alejandro Elua-Pinin, Linda Schäker-Hübner, Mikel Azkargorta, Felix Elortza, Isabel Iriepa, Francisco Lòpez-Muñoz, Veronica Moncho-Amor, Finn K. Hansen, Nicolás Sampron, Jose Luis Marco-Contelles, Ander Matheu
Format: Article
Language:English
Published: Nature Publishing Group 2025-04-01
Series:Cell Death and Disease
Online Access:https://doi.org/10.1038/s41419-025-07569-1
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author Aizpea Artetxe-Zurutuza
Nerea Iturrioz-Rodriguez
Joseba Elizazu
Mireia Toledano-Pinedo
Alicia Porro-Pérez
Irati De Goñi
Alejandro Elua-Pinin
Linda Schäker-Hübner
Mikel Azkargorta
Felix Elortza
Isabel Iriepa
Francisco Lòpez-Muñoz
Veronica Moncho-Amor
Finn K. Hansen
Nicolás Sampron
Jose Luis Marco-Contelles
Ander Matheu
author_facet Aizpea Artetxe-Zurutuza
Nerea Iturrioz-Rodriguez
Joseba Elizazu
Mireia Toledano-Pinedo
Alicia Porro-Pérez
Irati De Goñi
Alejandro Elua-Pinin
Linda Schäker-Hübner
Mikel Azkargorta
Felix Elortza
Isabel Iriepa
Francisco Lòpez-Muñoz
Veronica Moncho-Amor
Finn K. Hansen
Nicolás Sampron
Jose Luis Marco-Contelles
Ander Matheu
author_sort Aizpea Artetxe-Zurutuza
collection DOAJ
description Abstract The development of multitarget small molecules (MSMs) has emerged as a powerful strategy for the treatment of multifactorial diseases such as cancer. Glioblastoma is the most prevalent and malignant primary brain tumor in adults, which is characterized by poor prognosis and a high heterogeneity. Current standards of treatment present limited effectiveness, as patients develop therapy resistance and recur. In this work, we synthesized and characterized a novel multi-target molecule (named DDI199 or contilistat), which is a polyfunctionalized indole derivative developed by juxtaposing selected pharmacophoric moieties of the parent compounds Contilisant and Vorinostat (SAHA) to act as multifunctional ligands that inhibit histone deacetylases (HDACs), monoamine oxidases (MAOs) and cholinesterases (ChEs), and modulate histamine H3 (H3R) and Sigma 1 Receptor (S1R) receptors. DDI199 exerts high cytotoxic activity in conventional glioblastoma cell lines and patient-derived glioma stem cells in vitro. Importantly, it significantly reduces tumor growth in vivo, both alone and in combination with temozolomide (TMZ). The comparison with SAHA showed higher target specificity and antitumor activity of the new molecule. Transcriptomic and proteomic analyses of patient-derived glioma stem cells revealed a deregulation in cell cycle, DNA remodeling and neurotransmission activity by the treatment with DDI199. In conclusion, our data reveal the efficacy of a novel MSM in glioblastoma pre-clinical setting.
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spelling doaj-art-5bef5594cdc14d1587cf3918eaef54942025-08-20T03:08:12ZengNature Publishing GroupCell Death and Disease2041-48892025-04-0116111410.1038/s41419-025-07569-1Generation and validation of a novel multitarget small molecule in glioblastomaAizpea Artetxe-Zurutuza0Nerea Iturrioz-Rodriguez1Joseba Elizazu2Mireia Toledano-Pinedo3Alicia Porro-Pérez4Irati De Goñi5Alejandro Elua-Pinin6Linda Schäker-Hübner7Mikel Azkargorta8Felix Elortza9Isabel Iriepa10Francisco Lòpez-Muñoz11Veronica Moncho-Amor12Finn K. Hansen13Nicolás Sampron14Jose Luis Marco-Contelles15Ander Matheu16Cellular Oncology group, Biogipuzkoa (Biodonostia) Health Research InstituteCellular Oncology group, Biogipuzkoa (Biodonostia) Health Research InstituteCellular Oncology group, Biogipuzkoa (Biodonostia) Health Research InstituteLaboratory of Medicinal Chemistry (Institute of General Organic Chemistry, CSIC)Laboratory of Medicinal Chemistry (Institute of General Organic Chemistry, CSIC)Cellular Oncology group, Biogipuzkoa (Biodonostia) Health Research InstituteCellular Oncology group, Biogipuzkoa (Biodonostia) Health Research InstituteDepartment of Pharmaceutical and Cell Biological Chemistry, Pharmaceutical Institute, University of BonnProteomics Platform, CIC bioGUNE, Basque Research and Technology Alliance (BRTA), CIBERehdProteomics Platform, CIC bioGUNE, Basque Research and Technology Alliance (BRTA), CIBERehdAlcala University, Department of Organic and Inorganic Chemistry, Andrés M. del Río Chemistry Research Institute (IQAR); and DISCOBAC group, Castilla-La Mancha Health Research Institute (IDISCAM)Faculty of Health Sciences–HM Hospitals, Camilo José Cela University; HM Hospitals Health Research Institute; Neuropsychopharmacology Unit, “Hospital 12 de Octubre” Research InstituteCellular Oncology group, Biogipuzkoa (Biodonostia) Health Research InstituteDepartment of Pharmaceutical and Cell Biological Chemistry, Pharmaceutical Institute, University of BonnCellular Oncology group, Biogipuzkoa (Biodonostia) Health Research InstituteLaboratory of Medicinal Chemistry (Institute of General Organic Chemistry, CSIC)Cellular Oncology group, Biogipuzkoa (Biodonostia) Health Research InstituteAbstract The development of multitarget small molecules (MSMs) has emerged as a powerful strategy for the treatment of multifactorial diseases such as cancer. Glioblastoma is the most prevalent and malignant primary brain tumor in adults, which is characterized by poor prognosis and a high heterogeneity. Current standards of treatment present limited effectiveness, as patients develop therapy resistance and recur. In this work, we synthesized and characterized a novel multi-target molecule (named DDI199 or contilistat), which is a polyfunctionalized indole derivative developed by juxtaposing selected pharmacophoric moieties of the parent compounds Contilisant and Vorinostat (SAHA) to act as multifunctional ligands that inhibit histone deacetylases (HDACs), monoamine oxidases (MAOs) and cholinesterases (ChEs), and modulate histamine H3 (H3R) and Sigma 1 Receptor (S1R) receptors. DDI199 exerts high cytotoxic activity in conventional glioblastoma cell lines and patient-derived glioma stem cells in vitro. Importantly, it significantly reduces tumor growth in vivo, both alone and in combination with temozolomide (TMZ). The comparison with SAHA showed higher target specificity and antitumor activity of the new molecule. Transcriptomic and proteomic analyses of patient-derived glioma stem cells revealed a deregulation in cell cycle, DNA remodeling and neurotransmission activity by the treatment with DDI199. In conclusion, our data reveal the efficacy of a novel MSM in glioblastoma pre-clinical setting.https://doi.org/10.1038/s41419-025-07569-1
spellingShingle Aizpea Artetxe-Zurutuza
Nerea Iturrioz-Rodriguez
Joseba Elizazu
Mireia Toledano-Pinedo
Alicia Porro-Pérez
Irati De Goñi
Alejandro Elua-Pinin
Linda Schäker-Hübner
Mikel Azkargorta
Felix Elortza
Isabel Iriepa
Francisco Lòpez-Muñoz
Veronica Moncho-Amor
Finn K. Hansen
Nicolás Sampron
Jose Luis Marco-Contelles
Ander Matheu
Generation and validation of a novel multitarget small molecule in glioblastoma
Cell Death and Disease
title Generation and validation of a novel multitarget small molecule in glioblastoma
title_full Generation and validation of a novel multitarget small molecule in glioblastoma
title_fullStr Generation and validation of a novel multitarget small molecule in glioblastoma
title_full_unstemmed Generation and validation of a novel multitarget small molecule in glioblastoma
title_short Generation and validation of a novel multitarget small molecule in glioblastoma
title_sort generation and validation of a novel multitarget small molecule in glioblastoma
url https://doi.org/10.1038/s41419-025-07569-1
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