SCAN: a nanopore-based, cost effective decision-supporting tool for mass screening of aneuploidies

Abstract In developed countries, Newborn Screening (NBS) programs aim to detect treatable yet clinically silent disorders. The selection of disorders to be included in NBS considers severity, treatment availability, prevalence, and analysis cost. However, numerous genetic disorders remain excluded f...

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Main Authors: Anne Kristine Schack, M. Carmen Garrido-Navas, David Galevski, Gjorgji Madjarov, Lukasz Krych
Format: Article
Language:English
Published: BMC 2024-11-01
Series:Human Genomics
Online Access:https://doi.org/10.1186/s40246-024-00690-w
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author Anne Kristine Schack
M. Carmen Garrido-Navas
David Galevski
Gjorgji Madjarov
Lukasz Krych
author_facet Anne Kristine Schack
M. Carmen Garrido-Navas
David Galevski
Gjorgji Madjarov
Lukasz Krych
author_sort Anne Kristine Schack
collection DOAJ
description Abstract In developed countries, Newborn Screening (NBS) programs aim to detect treatable yet clinically silent disorders. The selection of disorders to be included in NBS considers severity, treatment availability, prevalence, and analysis cost. However, numerous genetic disorders remain excluded from routine testing due to high expenses and specialized equipment requirements. Here we present SCAN, a novel, non-invasive, and cost-effective decision-support tool utilizing nanopore sequencing for estimating proportions of chromosomes responsible for the most common aneuploidies. SCAN combines DNA enrichment (amplification), barcoding, nanopore sequencing, and machine learning predictive modeling. In a proof-of-concept study for Klinefelter Syndrome, SCAN achieved 100% sensitivity, specificity, and accuracy, becoming the world’s first IVD-certified genetic test utilising nanopore sequencing. Further model training shows promise in expanding this assay to detect other chromosomal aneuploidies included in the protocol.
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institution Kabale University
issn 1479-7364
language English
publishDate 2024-11-01
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series Human Genomics
spelling doaj-art-59be9e53d0784492ad95bc3cd4757e6c2024-11-24T12:35:29ZengBMCHuman Genomics1479-73642024-11-011811710.1186/s40246-024-00690-wSCAN: a nanopore-based, cost effective decision-supporting tool for mass screening of aneuploidiesAnne Kristine Schack0M. Carmen Garrido-Navas1David Galevski2Gjorgji Madjarov3Lukasz Krych4gMendel ApSCONGEN, Genetic Counselling ServicesFaculty of Computer Science and Engineering, University Ss Cyril and MethodiusFaculty of Computer Science and Engineering, University Ss Cyril and MethodiusFood Microbiology and Fermentation, University of CopenhagenAbstract In developed countries, Newborn Screening (NBS) programs aim to detect treatable yet clinically silent disorders. The selection of disorders to be included in NBS considers severity, treatment availability, prevalence, and analysis cost. However, numerous genetic disorders remain excluded from routine testing due to high expenses and specialized equipment requirements. Here we present SCAN, a novel, non-invasive, and cost-effective decision-support tool utilizing nanopore sequencing for estimating proportions of chromosomes responsible for the most common aneuploidies. SCAN combines DNA enrichment (amplification), barcoding, nanopore sequencing, and machine learning predictive modeling. In a proof-of-concept study for Klinefelter Syndrome, SCAN achieved 100% sensitivity, specificity, and accuracy, becoming the world’s first IVD-certified genetic test utilising nanopore sequencing. Further model training shows promise in expanding this assay to detect other chromosomal aneuploidies included in the protocol.https://doi.org/10.1186/s40246-024-00690-w
spellingShingle Anne Kristine Schack
M. Carmen Garrido-Navas
David Galevski
Gjorgji Madjarov
Lukasz Krych
SCAN: a nanopore-based, cost effective decision-supporting tool for mass screening of aneuploidies
Human Genomics
title SCAN: a nanopore-based, cost effective decision-supporting tool for mass screening of aneuploidies
title_full SCAN: a nanopore-based, cost effective decision-supporting tool for mass screening of aneuploidies
title_fullStr SCAN: a nanopore-based, cost effective decision-supporting tool for mass screening of aneuploidies
title_full_unstemmed SCAN: a nanopore-based, cost effective decision-supporting tool for mass screening of aneuploidies
title_short SCAN: a nanopore-based, cost effective decision-supporting tool for mass screening of aneuploidies
title_sort scan a nanopore based cost effective decision supporting tool for mass screening of aneuploidies
url https://doi.org/10.1186/s40246-024-00690-w
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