Diagnosis of Hereditary Leiomyomatosis and Renal Cell Cancer After Subcapsular Renal Hematoma

ABSTRACT Introduction Hereditary leiomyomatosis and renal cell cancer (HLRCC) is a rare autosomal dominant genetic disorder. We report a case diagnosed with HLRCC following a subcapsular renal hematoma caused by a tumor. Case Presentation A 28‐year‐old woman with a history of uterine myomas presente...

Full description

Saved in:
Bibliographic Details
Main Authors: Kazuma Soya, Takeru Fujimoto, Daisuke Takahashi, Kana Kohashiguchi, Yusuke Takei, Yoshio Sugino, Hiroshi Iwamura
Format: Article
Language:English
Published: Wiley 2025-05-01
Series:IJU Case Reports
Subjects:
Online Access:https://doi.org/10.1002/iju5.70009
Tags: Add Tag
No Tags, Be the first to tag this record!
Description
Summary:ABSTRACT Introduction Hereditary leiomyomatosis and renal cell cancer (HLRCC) is a rare autosomal dominant genetic disorder. We report a case diagnosed with HLRCC following a subcapsular renal hematoma caused by a tumor. Case Presentation A 28‐year‐old woman with a history of uterine myomas presented with left back pain. Computed tomography revealed a renal mass with a subcapsular hematoma, and coil embolization was performed. The tumor had enlarged rapidly, and 18F‐fluorodeoxyglucose positron emission tomography/computed tomography revealed significant 18F‐fluorodeoxyglucose uptake, suggesting malignancy. Subsequently, robot‐assisted radical nephrectomy was performed. Histopathological examination confirmed papillary renal carcinoma (Stage pT2aN0M0). Fumarate hydratase immunostaining was negative, and a fumarate hydratase gene pathogenic germline variant confirmed the HLRCC diagnosis. No recurrence has been reported for 2 years since the surgery. Conclusion A combination of imaging tests using multiple modalities and close follow‐ups contributed to establishing an accurate diagnosis and providing early definitive treatment.
ISSN:2577-171X