Clival fibrous dysplasia in which short interval disease progression posed a diagnostic challenge in a skeletally mature patient: a case report

Abstract Background Fibrous dysplasia is an uncommon bone disorder in which medullary bone is replaced by disorganized fibro-osseous tissue. Fibrous dysplasia typically exhibits slow growth that stabilizes with skeletal maturity. We report a case in which rapid progression of a clival lesion otherwi...

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Main Authors: Sujitra Tinnut, Nancy Pham, Jayakar Nayak, Juan C. Fernandez-Miranda, Hannes Vogel, Nancy Fischbein
Format: Article
Language:English
Published: BMC 2025-02-01
Series:Journal of Medical Case Reports
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Online Access:https://doi.org/10.1186/s13256-025-05104-6
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author Sujitra Tinnut
Nancy Pham
Jayakar Nayak
Juan C. Fernandez-Miranda
Hannes Vogel
Nancy Fischbein
author_facet Sujitra Tinnut
Nancy Pham
Jayakar Nayak
Juan C. Fernandez-Miranda
Hannes Vogel
Nancy Fischbein
author_sort Sujitra Tinnut
collection DOAJ
description Abstract Background Fibrous dysplasia is an uncommon bone disorder in which medullary bone is replaced by disorganized fibro-osseous tissue. Fibrous dysplasia typically exhibits slow growth that stabilizes with skeletal maturity. We report a case in which rapid progression of a clival lesion otherwise typical for fibrous dysplasia in an adult male led to concern for a malignant rather than a benign lesion. Case presentation A 38 year-old white male developed eye pain, and magnetic resonance imaging of the brain was interpreted as normal. A total of 2 years later, the patient again presented with eye pain, and a repeat magnetic resonance imaging study demonstrated interval development of a lesion replacing much of the clivus. Though the lesion appeared fairly typical of fibrous dysplasia, with magnetic resonance imaging and subsequent computed tomography revealing a well-defined and mildly expansile clival lesion, lesions of fibrous dysplasia do not typically appear in skeletally mature patients, and they are generally indolent. On the basis of concern for malignant degeneration or possibly an alternative diagnosis, as the patient had been referred to our center with a diagnosis of clival chordoma, the lesion was treated with endoscopic resection. The diagnosis of typical fibrous dysplasia was ultimately confirmed through histopathological, immunohistochemical, and genetic analysis. Conclusion This case demonstrates the potential for development and progression of benign fibrous dysplasia lesions beyond skeletal maturity, a phenomenon rarely reported in literature and not previously demonstrated in the clivus.
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spelling doaj-art-57e68d68da2548d8b45bf4b5a387ecaa2025-08-20T02:01:35ZengBMCJournal of Medical Case Reports1752-19472025-02-011911610.1186/s13256-025-05104-6Clival fibrous dysplasia in which short interval disease progression posed a diagnostic challenge in a skeletally mature patient: a case reportSujitra Tinnut0Nancy Pham1Jayakar Nayak2Juan C. Fernandez-Miranda3Hannes Vogel4Nancy Fischbein5Department of Radiology, Faculty of Medicine, Naresuan UniversityDepartment of Radiology, Stanford University School of MedicineDepartment of Otolaryngology-Head and Neck Surgery, Stanford University School of MedicineDepartment of Otolaryngology-Head and Neck Surgery, Stanford University School of MedicineDivision of Neuropathology, Department of Pathology, Stanford University School of MedicineDepartment of Radiology, Stanford University School of MedicineAbstract Background Fibrous dysplasia is an uncommon bone disorder in which medullary bone is replaced by disorganized fibro-osseous tissue. Fibrous dysplasia typically exhibits slow growth that stabilizes with skeletal maturity. We report a case in which rapid progression of a clival lesion otherwise typical for fibrous dysplasia in an adult male led to concern for a malignant rather than a benign lesion. Case presentation A 38 year-old white male developed eye pain, and magnetic resonance imaging of the brain was interpreted as normal. A total of 2 years later, the patient again presented with eye pain, and a repeat magnetic resonance imaging study demonstrated interval development of a lesion replacing much of the clivus. Though the lesion appeared fairly typical of fibrous dysplasia, with magnetic resonance imaging and subsequent computed tomography revealing a well-defined and mildly expansile clival lesion, lesions of fibrous dysplasia do not typically appear in skeletally mature patients, and they are generally indolent. On the basis of concern for malignant degeneration or possibly an alternative diagnosis, as the patient had been referred to our center with a diagnosis of clival chordoma, the lesion was treated with endoscopic resection. The diagnosis of typical fibrous dysplasia was ultimately confirmed through histopathological, immunohistochemical, and genetic analysis. Conclusion This case demonstrates the potential for development and progression of benign fibrous dysplasia lesions beyond skeletal maturity, a phenomenon rarely reported in literature and not previously demonstrated in the clivus.https://doi.org/10.1186/s13256-025-05104-6ClivusFibrous dysplasiaMRICase report
spellingShingle Sujitra Tinnut
Nancy Pham
Jayakar Nayak
Juan C. Fernandez-Miranda
Hannes Vogel
Nancy Fischbein
Clival fibrous dysplasia in which short interval disease progression posed a diagnostic challenge in a skeletally mature patient: a case report
Journal of Medical Case Reports
Clivus
Fibrous dysplasia
MRI
Case report
title Clival fibrous dysplasia in which short interval disease progression posed a diagnostic challenge in a skeletally mature patient: a case report
title_full Clival fibrous dysplasia in which short interval disease progression posed a diagnostic challenge in a skeletally mature patient: a case report
title_fullStr Clival fibrous dysplasia in which short interval disease progression posed a diagnostic challenge in a skeletally mature patient: a case report
title_full_unstemmed Clival fibrous dysplasia in which short interval disease progression posed a diagnostic challenge in a skeletally mature patient: a case report
title_short Clival fibrous dysplasia in which short interval disease progression posed a diagnostic challenge in a skeletally mature patient: a case report
title_sort clival fibrous dysplasia in which short interval disease progression posed a diagnostic challenge in a skeletally mature patient a case report
topic Clivus
Fibrous dysplasia
MRI
Case report
url https://doi.org/10.1186/s13256-025-05104-6
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