Novel Loop-Structure-Based CD19/CD22 Dual-Target CAR-T Therapy for High-Risk Diffuse Large B-Cell Lymphoma Presenting with Hemophagocytic Lymphohistiocytosis: A Case Report

Yuan Ye,1,* Shuhong Li,2,* Zhi Guo,1,* Lijun Zhao,2 Huanhuan Zhou,1 Nan Zhong,1 Mingxin He,1 Yu J Cao,2 Liqiong Liu1 1Department of Hematology, Affiliated Nanshan Hospital of Shenzhen University, Shenzhen, Guangdong, 518052, People’s Republic of China; 2State Key...

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Main Authors: Ye Y, Li S, Guo Z, Zhao L, Zhou H, Zhong N, He M, Cao YJ, Liu L
Format: Article
Language:English
Published: Dove Medical Press 2025-07-01
Series:Cancer Management and Research
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Online Access:https://www.dovepress.com/novel-loop-structure-based-cd19cd22-dual-target-car-t-therapy-for-high-peer-reviewed-fulltext-article-CMAR
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author Ye Y
Li S
Guo Z
Zhao L
Zhou H
Zhong N
He M
Cao YJ
Liu L
author_facet Ye Y
Li S
Guo Z
Zhao L
Zhou H
Zhong N
He M
Cao YJ
Liu L
author_sort Ye Y
collection DOAJ
description Yuan Ye,1,* Shuhong Li,2,* Zhi Guo,1,* Lijun Zhao,2 Huanhuan Zhou,1 Nan Zhong,1 Mingxin He,1 Yu J Cao,2 Liqiong Liu1 1Department of Hematology, Affiliated Nanshan Hospital of Shenzhen University, Shenzhen, Guangdong, 518052, People’s Republic of China; 2State Key Laboratory of Chemical Oncogenomics, Shenzhen Key Laboratory of Chemical Genomics, Peking University Shenzhen Graduate School, Shenzhen, Guangdong, 518055, People’s Republic of China*These authors contributed equally to this workCorrespondence: Liqiong Liu, Department of Hematology, Affiliated Nanshan Hospital of Shenzhen University, Shenzhen, Guangdong, 518052, People’s Republic of China, Email llqwsp@hotmail.com Yu J Cao, State Key Laboratory of Chemical Oncogenomics, Shenzhen Key Laboratory of Chemical Genomics, Peking University Shenzhen Graduate School, Shenzhen, Guangdong, 518055, People’s Republic of China, Email joshuacao@pku.edu.cnObjective: To investigate the efficacy and safety of novel loop-structure-based CD19/CD22 dual-target chimeric antigen receptor T-cell (CD19/CD22 BS LoopCAR-T) therapy in high-risk diffuse large B-cell lymphoma (DLBCL) presenting with hemophagocytic lymphohistiocytosis (HLH).Methods: We analyzed the clinical data of a high-risk DLBCL patient presenting with HLH treated with CD19/CD22 BS LoopCAR-T at the Affiliated Nanshan Hospital of Shenzhen University in December 2023.Results: The patient, a 59-year-old female, was diagnosed with myelodysplastic syndromes with multilineage dysplasia in October 2022. Following six cycles of azacitidine treatment, her bone marrow and hemogram returned to normal, and the disease was stable In August 2023, she presented with recurrent fever for over a month and was diagnosed with high-risk DLBCL stage IVB presenting with HLH. After receiving the HLH-1994 protocol followed by one cycle each of R-CHOP and R-DA-EPOCH regimens, the patient underwent infusion of CD19/CD22 BS LoopCAR-T cells at a dose of 1.73× 108 cells. She experienced a rapid response, developing grade 1 cytokine release syndrome (CRS) and no immune effector cell-associated HLH-like syndrome (IEC-HS), and achieved disease stabilization following aggressive treatment. Bone marrow and peripheral blood flow cytometry at one and three months post-CAR-T therapy showed complete remission (CR). PET-CT at three months post-CAR-T therapy also indicated CR. The patient was followed up until April 2025, and the disease-free survival time after CAR-T treatment exceeded 16 months.Conclusion: The novel CD19/CD22 BS LoopCAR-T therapy is safe and effective in treating high-risk DLBCL patients presenting with HLH.Keywords: hemophagocytic lymphohistiocytosis, diffuse large B-cell lymphoma, CD19/CD22 dual target, chimeric antigen receptor T cells
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spelling doaj-art-55ccc6c7c451442aa94dbbf1e75b63bd2025-08-20T03:13:32ZengDove Medical PressCancer Management and Research1179-13222025-07-01Volume 17Issue 113891398104837Novel Loop-Structure-Based CD19/CD22 Dual-Target CAR-T Therapy for High-Risk Diffuse Large B-Cell Lymphoma Presenting with Hemophagocytic Lymphohistiocytosis: A Case ReportYe YLi S0Guo Z1Zhao LZhou HZhong NHe MCao YJ2Liu LPeking UniversityDepartment of Hematology, The 6th Affiliated Hospital of Shenzhen University Health Science CenterChemical Biology and BiotechnologyYuan Ye,1,* Shuhong Li,2,* Zhi Guo,1,* Lijun Zhao,2 Huanhuan Zhou,1 Nan Zhong,1 Mingxin He,1 Yu J Cao,2 Liqiong Liu1 1Department of Hematology, Affiliated Nanshan Hospital of Shenzhen University, Shenzhen, Guangdong, 518052, People’s Republic of China; 2State Key Laboratory of Chemical Oncogenomics, Shenzhen Key Laboratory of Chemical Genomics, Peking University Shenzhen Graduate School, Shenzhen, Guangdong, 518055, People’s Republic of China*These authors contributed equally to this workCorrespondence: Liqiong Liu, Department of Hematology, Affiliated Nanshan Hospital of Shenzhen University, Shenzhen, Guangdong, 518052, People’s Republic of China, Email llqwsp@hotmail.com Yu J Cao, State Key Laboratory of Chemical Oncogenomics, Shenzhen Key Laboratory of Chemical Genomics, Peking University Shenzhen Graduate School, Shenzhen, Guangdong, 518055, People’s Republic of China, Email joshuacao@pku.edu.cnObjective: To investigate the efficacy and safety of novel loop-structure-based CD19/CD22 dual-target chimeric antigen receptor T-cell (CD19/CD22 BS LoopCAR-T) therapy in high-risk diffuse large B-cell lymphoma (DLBCL) presenting with hemophagocytic lymphohistiocytosis (HLH).Methods: We analyzed the clinical data of a high-risk DLBCL patient presenting with HLH treated with CD19/CD22 BS LoopCAR-T at the Affiliated Nanshan Hospital of Shenzhen University in December 2023.Results: The patient, a 59-year-old female, was diagnosed with myelodysplastic syndromes with multilineage dysplasia in October 2022. Following six cycles of azacitidine treatment, her bone marrow and hemogram returned to normal, and the disease was stable In August 2023, she presented with recurrent fever for over a month and was diagnosed with high-risk DLBCL stage IVB presenting with HLH. After receiving the HLH-1994 protocol followed by one cycle each of R-CHOP and R-DA-EPOCH regimens, the patient underwent infusion of CD19/CD22 BS LoopCAR-T cells at a dose of 1.73× 108 cells. She experienced a rapid response, developing grade 1 cytokine release syndrome (CRS) and no immune effector cell-associated HLH-like syndrome (IEC-HS), and achieved disease stabilization following aggressive treatment. Bone marrow and peripheral blood flow cytometry at one and three months post-CAR-T therapy showed complete remission (CR). PET-CT at three months post-CAR-T therapy also indicated CR. The patient was followed up until April 2025, and the disease-free survival time after CAR-T treatment exceeded 16 months.Conclusion: The novel CD19/CD22 BS LoopCAR-T therapy is safe and effective in treating high-risk DLBCL patients presenting with HLH.Keywords: hemophagocytic lymphohistiocytosis, diffuse large B-cell lymphoma, CD19/CD22 dual target, chimeric antigen receptor T cellshttps://www.dovepress.com/novel-loop-structure-based-cd19cd22-dual-target-car-t-therapy-for-high-peer-reviewed-fulltext-article-CMARHemophagocytic lymphohistiocytosisDiffuse large B-cell lymphomaCD19/CD22 dual targetChimeric antigen receptor T cells
spellingShingle Ye Y
Li S
Guo Z
Zhao L
Zhou H
Zhong N
He M
Cao YJ
Liu L
Novel Loop-Structure-Based CD19/CD22 Dual-Target CAR-T Therapy for High-Risk Diffuse Large B-Cell Lymphoma Presenting with Hemophagocytic Lymphohistiocytosis: A Case Report
Cancer Management and Research
Hemophagocytic lymphohistiocytosis
Diffuse large B-cell lymphoma
CD19/CD22 dual target
Chimeric antigen receptor T cells
title Novel Loop-Structure-Based CD19/CD22 Dual-Target CAR-T Therapy for High-Risk Diffuse Large B-Cell Lymphoma Presenting with Hemophagocytic Lymphohistiocytosis: A Case Report
title_full Novel Loop-Structure-Based CD19/CD22 Dual-Target CAR-T Therapy for High-Risk Diffuse Large B-Cell Lymphoma Presenting with Hemophagocytic Lymphohistiocytosis: A Case Report
title_fullStr Novel Loop-Structure-Based CD19/CD22 Dual-Target CAR-T Therapy for High-Risk Diffuse Large B-Cell Lymphoma Presenting with Hemophagocytic Lymphohistiocytosis: A Case Report
title_full_unstemmed Novel Loop-Structure-Based CD19/CD22 Dual-Target CAR-T Therapy for High-Risk Diffuse Large B-Cell Lymphoma Presenting with Hemophagocytic Lymphohistiocytosis: A Case Report
title_short Novel Loop-Structure-Based CD19/CD22 Dual-Target CAR-T Therapy for High-Risk Diffuse Large B-Cell Lymphoma Presenting with Hemophagocytic Lymphohistiocytosis: A Case Report
title_sort novel loop structure based cd19 cd22 dual target car t therapy for high risk diffuse large b cell lymphoma presenting with hemophagocytic lymphohistiocytosis a case report
topic Hemophagocytic lymphohistiocytosis
Diffuse large B-cell lymphoma
CD19/CD22 dual target
Chimeric antigen receptor T cells
url https://www.dovepress.com/novel-loop-structure-based-cd19cd22-dual-target-car-t-therapy-for-high-peer-reviewed-fulltext-article-CMAR
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