Natural variants suppress mutations in hundreds of essential genes

Abstract The consequence of a mutation can be influenced by the context in which it operates. For example, loss of gene function may be tolerated in one genetic background, and lethal in another. The extent to which mutant phenotypes are malleable, the architecture of modifiers and the identities of...

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Main Authors: Leopold Parts, Amandine Batté, Maykel Lopes, Michael W Yuen, Meredith Laver, Bryan‐Joseph San Luis, Jia‐Xing Yue, Carles Pons, Elise Eray, Patrick Aloy, Gianni Liti, Jolanda van Leeuwen
Format: Article
Language:English
Published: Springer Nature 2021-05-01
Series:Molecular Systems Biology
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Online Access:https://doi.org/10.15252/msb.202010138
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author Leopold Parts
Amandine Batté
Maykel Lopes
Michael W Yuen
Meredith Laver
Bryan‐Joseph San Luis
Jia‐Xing Yue
Carles Pons
Elise Eray
Patrick Aloy
Gianni Liti
Jolanda van Leeuwen
author_facet Leopold Parts
Amandine Batté
Maykel Lopes
Michael W Yuen
Meredith Laver
Bryan‐Joseph San Luis
Jia‐Xing Yue
Carles Pons
Elise Eray
Patrick Aloy
Gianni Liti
Jolanda van Leeuwen
author_sort Leopold Parts
collection DOAJ
description Abstract The consequence of a mutation can be influenced by the context in which it operates. For example, loss of gene function may be tolerated in one genetic background, and lethal in another. The extent to which mutant phenotypes are malleable, the architecture of modifiers and the identities of causal genes remain largely unknown. Here, we measure the fitness effects of ~ 1,100 temperature‐sensitive alleles of yeast essential genes in the context of variation from ten different natural genetic backgrounds and map the modifiers for 19 combinations. Altogether, fitness defects for 149 of the 580 tested genes (26%) could be suppressed by genetic variation in at least one yeast strain. Suppression was generally driven by gain‐of‐function of a single, strong modifier gene, and involved both genes encoding complex or pathway partners suppressing specific temperature‐sensitive alleles, as well as general modifiers altering the effect of many alleles. The emerging frequency of suppression and range of possible mechanisms suggest that a substantial fraction of monogenic diseases could be managed by modulating other gene products.
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issn 1744-4292
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publishDate 2021-05-01
publisher Springer Nature
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series Molecular Systems Biology
spelling doaj-art-547226e6c7ef427cb48bed2dc376bb172025-08-20T02:35:44ZengSpringer NatureMolecular Systems Biology1744-42922021-05-0117511610.15252/msb.202010138Natural variants suppress mutations in hundreds of essential genesLeopold Parts0Amandine Batté1Maykel Lopes2Michael W Yuen3Meredith Laver4Bryan‐Joseph San Luis5Jia‐Xing Yue6Carles Pons7Elise Eray8Patrick Aloy9Gianni Liti10Jolanda van Leeuwen11Donnelly Centre for Cellular and Biomolecular Research, University of TorontoCenter for Integrative Genomics, University of LausanneCenter for Integrative Genomics, University of LausanneDonnelly Centre for Cellular and Biomolecular Research, University of TorontoDonnelly Centre for Cellular and Biomolecular Research, University of TorontoDonnelly Centre for Cellular and Biomolecular Research, University of TorontoUniversity of Côte d’Azur, CNRS, INSERM, IRCANInstitute for Research in Biomedicine (IRB Barcelona), The Barcelona Institute for Science and TechnologyCenter for Integrative Genomics, University of LausanneInstitute for Research in Biomedicine (IRB Barcelona), The Barcelona Institute for Science and TechnologyUniversity of Côte d’Azur, CNRS, INSERM, IRCANCenter for Integrative Genomics, University of LausanneAbstract The consequence of a mutation can be influenced by the context in which it operates. For example, loss of gene function may be tolerated in one genetic background, and lethal in another. The extent to which mutant phenotypes are malleable, the architecture of modifiers and the identities of causal genes remain largely unknown. Here, we measure the fitness effects of ~ 1,100 temperature‐sensitive alleles of yeast essential genes in the context of variation from ten different natural genetic backgrounds and map the modifiers for 19 combinations. Altogether, fitness defects for 149 of the 580 tested genes (26%) could be suppressed by genetic variation in at least one yeast strain. Suppression was generally driven by gain‐of‐function of a single, strong modifier gene, and involved both genes encoding complex or pathway partners suppressing specific temperature‐sensitive alleles, as well as general modifiers altering the effect of many alleles. The emerging frequency of suppression and range of possible mechanisms suggest that a substantial fraction of monogenic diseases could be managed by modulating other gene products.https://doi.org/10.15252/msb.202010138compensatory evolutiongenetic interactionsgenetic modifiersgenetic suppressionnatural variation
spellingShingle Leopold Parts
Amandine Batté
Maykel Lopes
Michael W Yuen
Meredith Laver
Bryan‐Joseph San Luis
Jia‐Xing Yue
Carles Pons
Elise Eray
Patrick Aloy
Gianni Liti
Jolanda van Leeuwen
Natural variants suppress mutations in hundreds of essential genes
Molecular Systems Biology
compensatory evolution
genetic interactions
genetic modifiers
genetic suppression
natural variation
title Natural variants suppress mutations in hundreds of essential genes
title_full Natural variants suppress mutations in hundreds of essential genes
title_fullStr Natural variants suppress mutations in hundreds of essential genes
title_full_unstemmed Natural variants suppress mutations in hundreds of essential genes
title_short Natural variants suppress mutations in hundreds of essential genes
title_sort natural variants suppress mutations in hundreds of essential genes
topic compensatory evolution
genetic interactions
genetic modifiers
genetic suppression
natural variation
url https://doi.org/10.15252/msb.202010138
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