A Case of Granulomatous Interstitial Nephritis Associated with <i>Mycobacterium chimaera</i> Disseminated Infection

<i>Mycobacterium chimaera</i> infections are becoming increasingly frequent in patients with a history of cardiac surgery. We herein report a case of a patient admitted to the Nephrology Unit of Padua University Hospital with deteriorating kidney function, pancytopenia, hypercalcemia, an...

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Main Authors: Martina Cacciapuoti, Maria Mazzitelli, Elena Naso, Maria Loreta De Giorgi, Giovanni Samassa, Valentina Di Vico, Serena Marinello, Lucia Federica Stefanelli, Lorenzo Calò, Annamaria Cattelan, Federico Nalesso
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Language:English
Published: MDPI AG 2025-04-01
Series:Microorganisms
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Online Access:https://www.mdpi.com/2076-2607/13/5/1019
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author Martina Cacciapuoti
Maria Mazzitelli
Elena Naso
Maria Loreta De Giorgi
Giovanni Samassa
Valentina Di Vico
Serena Marinello
Lucia Federica Stefanelli
Lorenzo Calò
Annamaria Cattelan
Federico Nalesso
author_facet Martina Cacciapuoti
Maria Mazzitelli
Elena Naso
Maria Loreta De Giorgi
Giovanni Samassa
Valentina Di Vico
Serena Marinello
Lucia Federica Stefanelli
Lorenzo Calò
Annamaria Cattelan
Federico Nalesso
author_sort Martina Cacciapuoti
collection DOAJ
description <i>Mycobacterium chimaera</i> infections are becoming increasingly frequent in patients with a history of cardiac surgery. We herein report a case of a patient admitted to the Nephrology Unit of Padua University Hospital with deteriorating kidney function, pancytopenia, hypercalcemia, and respiratory symptoms that emerged seven years after they underwent heart surgery for prosthetic aortic valve replacement. A kidney biopsy revealed non-caseating necrotizing granulomatous interstitial nephritis, which was initially diagnosed as idiopathic granulomatous interstitial nephritis. The patient was treated with intravenous corticosteroids since no active infections, including mycobacterial infections, were detected. The negativity of the <i>Mycobacterium</i> molecular test following the kidney biopsy delayed the diagnosis of a <i>Mycobacterium chimaera</i> disseminated infection with endocarditis, myositis, cerebral, and kidney involvement, as blood cultures were available only after six weeks. The patient was started on antimicrobial therapy with azithromycin, moxifloxacin, rifampicin, and ethambutol while prednisone was tapered down, leading to an improvement in kidney function, blood count, and blood calcium level. Our case suggests that a <i>Mycobacterium chimaera</i> infection should be considered for patients with a history of cardiac surgery and granulomatous interstitial nephritis even in the absence of mycobacteria in a kidney biopsy.
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spelling doaj-art-4d83eae89c0e427ea97d83466db0da9c2025-08-20T03:14:36ZengMDPI AGMicroorganisms2076-26072025-04-01135101910.3390/microorganisms13051019A Case of Granulomatous Interstitial Nephritis Associated with <i>Mycobacterium chimaera</i> Disseminated InfectionMartina Cacciapuoti0Maria Mazzitelli1Elena Naso2Maria Loreta De Giorgi3Giovanni Samassa4Valentina Di Vico5Serena Marinello6Lucia Federica Stefanelli7Lorenzo Calò8Annamaria Cattelan9Federico Nalesso10Nephrology, Dialysis and Transplantation Unit, University Hospital of Padova, 35128 Padova, ItalyInfectious and Tropical Disease Unit, University Hospital of Padova, 35128 Padova, ItalyNephrology, Dialysis and Transplantation Unit, University Hospital of Padova, 35128 Padova, ItalyNephrology, Dialysis and Transplantation Unit, University Hospital of Padova, 35128 Padova, ItalyNephrology, Dialysis and Transplantation Unit, University Hospital of Padova, 35128 Padova, ItalyNephrology, Dialysis and Transplantation Unit, University Hospital of Padova, 35128 Padova, ItalyInfectious and Tropical Disease Unit, University Hospital of Padova, 35128 Padova, ItalyNephrology, Dialysis and Transplantation Unit, University Hospital of Padova, 35128 Padova, ItalyNephrology, Dialysis and Transplantation Unit, University Hospital of Padova, 35128 Padova, ItalyInfectious and Tropical Disease Unit, University Hospital of Padova, 35128 Padova, ItalyNephrology, Dialysis and Transplantation Unit, University Hospital of Padova, 35128 Padova, Italy<i>Mycobacterium chimaera</i> infections are becoming increasingly frequent in patients with a history of cardiac surgery. We herein report a case of a patient admitted to the Nephrology Unit of Padua University Hospital with deteriorating kidney function, pancytopenia, hypercalcemia, and respiratory symptoms that emerged seven years after they underwent heart surgery for prosthetic aortic valve replacement. A kidney biopsy revealed non-caseating necrotizing granulomatous interstitial nephritis, which was initially diagnosed as idiopathic granulomatous interstitial nephritis. The patient was treated with intravenous corticosteroids since no active infections, including mycobacterial infections, were detected. The negativity of the <i>Mycobacterium</i> molecular test following the kidney biopsy delayed the diagnosis of a <i>Mycobacterium chimaera</i> disseminated infection with endocarditis, myositis, cerebral, and kidney involvement, as blood cultures were available only after six weeks. The patient was started on antimicrobial therapy with azithromycin, moxifloxacin, rifampicin, and ethambutol while prednisone was tapered down, leading to an improvement in kidney function, blood count, and blood calcium level. Our case suggests that a <i>Mycobacterium chimaera</i> infection should be considered for patients with a history of cardiac surgery and granulomatous interstitial nephritis even in the absence of mycobacteria in a kidney biopsy.https://www.mdpi.com/2076-2607/13/5/1019<i>Mycobacterium chimaera</i>disseminated infectiongranulomatous interstitial nephritiscardiac surgery
spellingShingle Martina Cacciapuoti
Maria Mazzitelli
Elena Naso
Maria Loreta De Giorgi
Giovanni Samassa
Valentina Di Vico
Serena Marinello
Lucia Federica Stefanelli
Lorenzo Calò
Annamaria Cattelan
Federico Nalesso
A Case of Granulomatous Interstitial Nephritis Associated with <i>Mycobacterium chimaera</i> Disseminated Infection
Microorganisms
<i>Mycobacterium chimaera</i>
disseminated infection
granulomatous interstitial nephritis
cardiac surgery
title A Case of Granulomatous Interstitial Nephritis Associated with <i>Mycobacterium chimaera</i> Disseminated Infection
title_full A Case of Granulomatous Interstitial Nephritis Associated with <i>Mycobacterium chimaera</i> Disseminated Infection
title_fullStr A Case of Granulomatous Interstitial Nephritis Associated with <i>Mycobacterium chimaera</i> Disseminated Infection
title_full_unstemmed A Case of Granulomatous Interstitial Nephritis Associated with <i>Mycobacterium chimaera</i> Disseminated Infection
title_short A Case of Granulomatous Interstitial Nephritis Associated with <i>Mycobacterium chimaera</i> Disseminated Infection
title_sort case of granulomatous interstitial nephritis associated with i mycobacterium chimaera i disseminated infection
topic <i>Mycobacterium chimaera</i>
disseminated infection
granulomatous interstitial nephritis
cardiac surgery
url https://www.mdpi.com/2076-2607/13/5/1019
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