Ubr3, a Novel Modulator of Hh Signaling Affects the Degradation of Costal-2 and Kif7 through Poly-ubiquitination.

Hedgehog (Hh) signaling regulates multiple aspects of metazoan development and tissue homeostasis, and is constitutively active in numerous cancers. We identified Ubr3, an E3 ubiquitin ligase, as a novel, positive regulator of Hh signaling in Drosophila and vertebrates. Hh signaling regulates the Ub...

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Main Authors: Tongchao Li, Junkai Fan, Bernardo Blanco-Sánchez, Nikolaos Giagtzoglou, Guang Lin, Shinya Yamamoto, Manish Jaiswal, Kuchuan Chen, Jie Zhang, Wei Wei, Michael T Lewis, Andrew K Groves, Monte Westerfield, Jianhang Jia, Hugo J Bellen
Format: Article
Language:English
Published: Public Library of Science (PLoS) 2016-05-01
Series:PLoS Genetics
Online Access:https://journals.plos.org/plosgenetics/article/file?id=10.1371/journal.pgen.1006054&type=printable
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author Tongchao Li
Junkai Fan
Bernardo Blanco-Sánchez
Nikolaos Giagtzoglou
Guang Lin
Shinya Yamamoto
Manish Jaiswal
Kuchuan Chen
Jie Zhang
Wei Wei
Michael T Lewis
Andrew K Groves
Monte Westerfield
Jianhang Jia
Hugo J Bellen
author_facet Tongchao Li
Junkai Fan
Bernardo Blanco-Sánchez
Nikolaos Giagtzoglou
Guang Lin
Shinya Yamamoto
Manish Jaiswal
Kuchuan Chen
Jie Zhang
Wei Wei
Michael T Lewis
Andrew K Groves
Monte Westerfield
Jianhang Jia
Hugo J Bellen
author_sort Tongchao Li
collection DOAJ
description Hedgehog (Hh) signaling regulates multiple aspects of metazoan development and tissue homeostasis, and is constitutively active in numerous cancers. We identified Ubr3, an E3 ubiquitin ligase, as a novel, positive regulator of Hh signaling in Drosophila and vertebrates. Hh signaling regulates the Ubr3-mediated poly-ubiquitination and degradation of Cos2, a central component of Hh signaling. In developing Drosophila eye discs, loss of ubr3 leads to a delayed differentiation of photoreceptors and a reduction in Hh signaling. In zebrafish, loss of Ubr3 causes a decrease in Shh signaling in the developing eyes, somites, and sensory neurons. However, not all tissues that require Hh signaling are affected in zebrafish. Mouse UBR3 poly-ubiquitinates Kif7, the mammalian homologue of Cos2. Finally, loss of UBR3 up-regulates Kif7 protein levels and decreases Hh signaling in cultured cells. In summary, our work identifies Ubr3 as a novel, evolutionarily conserved modulator of Hh signaling that boosts Hh in some tissues.
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institution OA Journals
issn 1553-7390
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language English
publishDate 2016-05-01
publisher Public Library of Science (PLoS)
record_format Article
series PLoS Genetics
spelling doaj-art-4980a293e69a4e169d42d8dce10c8eec2025-08-20T02:15:40ZengPublic Library of Science (PLoS)PLoS Genetics1553-73901553-74042016-05-01125e100605410.1371/journal.pgen.1006054Ubr3, a Novel Modulator of Hh Signaling Affects the Degradation of Costal-2 and Kif7 through Poly-ubiquitination.Tongchao LiJunkai FanBernardo Blanco-SánchezNikolaos GiagtzoglouGuang LinShinya YamamotoManish JaiswalKuchuan ChenJie ZhangWei WeiMichael T LewisAndrew K GrovesMonte WesterfieldJianhang JiaHugo J BellenHedgehog (Hh) signaling regulates multiple aspects of metazoan development and tissue homeostasis, and is constitutively active in numerous cancers. We identified Ubr3, an E3 ubiquitin ligase, as a novel, positive regulator of Hh signaling in Drosophila and vertebrates. Hh signaling regulates the Ubr3-mediated poly-ubiquitination and degradation of Cos2, a central component of Hh signaling. In developing Drosophila eye discs, loss of ubr3 leads to a delayed differentiation of photoreceptors and a reduction in Hh signaling. In zebrafish, loss of Ubr3 causes a decrease in Shh signaling in the developing eyes, somites, and sensory neurons. However, not all tissues that require Hh signaling are affected in zebrafish. Mouse UBR3 poly-ubiquitinates Kif7, the mammalian homologue of Cos2. Finally, loss of UBR3 up-regulates Kif7 protein levels and decreases Hh signaling in cultured cells. In summary, our work identifies Ubr3 as a novel, evolutionarily conserved modulator of Hh signaling that boosts Hh in some tissues.https://journals.plos.org/plosgenetics/article/file?id=10.1371/journal.pgen.1006054&type=printable
spellingShingle Tongchao Li
Junkai Fan
Bernardo Blanco-Sánchez
Nikolaos Giagtzoglou
Guang Lin
Shinya Yamamoto
Manish Jaiswal
Kuchuan Chen
Jie Zhang
Wei Wei
Michael T Lewis
Andrew K Groves
Monte Westerfield
Jianhang Jia
Hugo J Bellen
Ubr3, a Novel Modulator of Hh Signaling Affects the Degradation of Costal-2 and Kif7 through Poly-ubiquitination.
PLoS Genetics
title Ubr3, a Novel Modulator of Hh Signaling Affects the Degradation of Costal-2 and Kif7 through Poly-ubiquitination.
title_full Ubr3, a Novel Modulator of Hh Signaling Affects the Degradation of Costal-2 and Kif7 through Poly-ubiquitination.
title_fullStr Ubr3, a Novel Modulator of Hh Signaling Affects the Degradation of Costal-2 and Kif7 through Poly-ubiquitination.
title_full_unstemmed Ubr3, a Novel Modulator of Hh Signaling Affects the Degradation of Costal-2 and Kif7 through Poly-ubiquitination.
title_short Ubr3, a Novel Modulator of Hh Signaling Affects the Degradation of Costal-2 and Kif7 through Poly-ubiquitination.
title_sort ubr3 a novel modulator of hh signaling affects the degradation of costal 2 and kif7 through poly ubiquitination
url https://journals.plos.org/plosgenetics/article/file?id=10.1371/journal.pgen.1006054&type=printable
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