Exploring the early drivers of pain in Parkinson’s disease

Abstract Pain is a common and complex non-motor symptom in people with Parkinson’s disease (PWP). Little is known about the genetic drivers of pain in PWP, and progress in its study has been challenging. Here, we conducted two genome-wide association studies (GWAS) to identify genetic variants assoc...

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Main Authors: Shiying Liu, Douglas D. Gunzler, Steven A. Gunzler, Dana C. Crawford, Farren B. S. Briggs
Format: Article
Language:English
Published: Nature Portfolio 2025-02-01
Series:Scientific Reports
Online Access:https://doi.org/10.1038/s41598-025-90678-w
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author Shiying Liu
Douglas D. Gunzler
Steven A. Gunzler
Dana C. Crawford
Farren B. S. Briggs
author_facet Shiying Liu
Douglas D. Gunzler
Steven A. Gunzler
Dana C. Crawford
Farren B. S. Briggs
author_sort Shiying Liu
collection DOAJ
description Abstract Pain is a common and complex non-motor symptom in people with Parkinson’s disease (PWP). Little is known about the genetic drivers of pain in PWP, and progress in its study has been challenging. Here, we conducted two genome-wide association studies (GWAS) to identify genetic variants associated with pain experienced during the earliest stages of Parkinson’s disease. The study population consisted of 4,159 PWP of European ancestry who were mapped to five previously-described, longitudinal pain trajectories. In the first GWAS, the extreme pain trajectories (highest burden versus no significant pain over time) were compared, and in the second GWAS, a multinomial approach was undertaken. While no variant reached genome-wide significance, we identified promising associations, such as rs117108018 (ORGWAS−Extreme=8.96, pGWAS−Extreme=2.5 × 10− 7), a brain/nerve eQTL for L3MBTL3 and EPB41L2, and rs61881484 (pGWAS−Multinomial=2 × 10− 7), which intersects a transcription factor peak targeting CREB1, critical in sensory neuron synaptic plasticity and neuropathic pain regulation. Gene-based tests implicated CTNNB1 (pGWAS−Extreme=3.2 × 10− 5), KLK7 (pGWAS−Extreme=7 × 10− 5), and SLITRK3 (pGWAS−Multinomial=3.2 × 10− 5), which have been associated with neurodevelopment. At the pathway-level, there was an enrichment for genes involved in neurotransmitter regulation and opioid dependence. This study implicates neuropathic pain mechanisms as prominent drivers of elevated pain in PWP, suggests potential therapeutic genetic targets for further research.
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spelling doaj-art-487bb6c3f7994a6a87eaa144733d1cea2025-08-20T02:15:00ZengNature PortfolioScientific Reports2045-23222025-02-0115111110.1038/s41598-025-90678-wExploring the early drivers of pain in Parkinson’s diseaseShiying Liu0Douglas D. Gunzler1Steven A. Gunzler2Dana C. Crawford3Farren B. S. Briggs4Department of Population and Quantitative Health Sciences, Case Western Reserve UniversityDepartment of Population and Quantitative Health Sciences, Case Western Reserve UniversityNeurological Institute, University Hospitals Cleveland Medical Center and Case Western Reserve University School of MedicineDepartment of Population and Quantitative Health Sciences, Case Western Reserve UniversityDepartment of Public Health Sciences, University of Miami Miller School of MedicineAbstract Pain is a common and complex non-motor symptom in people with Parkinson’s disease (PWP). Little is known about the genetic drivers of pain in PWP, and progress in its study has been challenging. Here, we conducted two genome-wide association studies (GWAS) to identify genetic variants associated with pain experienced during the earliest stages of Parkinson’s disease. The study population consisted of 4,159 PWP of European ancestry who were mapped to five previously-described, longitudinal pain trajectories. In the first GWAS, the extreme pain trajectories (highest burden versus no significant pain over time) were compared, and in the second GWAS, a multinomial approach was undertaken. While no variant reached genome-wide significance, we identified promising associations, such as rs117108018 (ORGWAS−Extreme=8.96, pGWAS−Extreme=2.5 × 10− 7), a brain/nerve eQTL for L3MBTL3 and EPB41L2, and rs61881484 (pGWAS−Multinomial=2 × 10− 7), which intersects a transcription factor peak targeting CREB1, critical in sensory neuron synaptic plasticity and neuropathic pain regulation. Gene-based tests implicated CTNNB1 (pGWAS−Extreme=3.2 × 10− 5), KLK7 (pGWAS−Extreme=7 × 10− 5), and SLITRK3 (pGWAS−Multinomial=3.2 × 10− 5), which have been associated with neurodevelopment. At the pathway-level, there was an enrichment for genes involved in neurotransmitter regulation and opioid dependence. This study implicates neuropathic pain mechanisms as prominent drivers of elevated pain in PWP, suggests potential therapeutic genetic targets for further research.https://doi.org/10.1038/s41598-025-90678-w
spellingShingle Shiying Liu
Douglas D. Gunzler
Steven A. Gunzler
Dana C. Crawford
Farren B. S. Briggs
Exploring the early drivers of pain in Parkinson’s disease
Scientific Reports
title Exploring the early drivers of pain in Parkinson’s disease
title_full Exploring the early drivers of pain in Parkinson’s disease
title_fullStr Exploring the early drivers of pain in Parkinson’s disease
title_full_unstemmed Exploring the early drivers of pain in Parkinson’s disease
title_short Exploring the early drivers of pain in Parkinson’s disease
title_sort exploring the early drivers of pain in parkinson s disease
url https://doi.org/10.1038/s41598-025-90678-w
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