Penile duplication (diphallia) with epispadias, neurogenic bladder, and lumbar vertebral Fusion: An exceptionally rare multisystem congenital association
We report a highly unusual case of penile duplication (diphallia) accompanied by epispadias, neurogenic bladder with markedly reduced compliance, and lumbar vertebral fusion. Comprehensive clinical, imaging, and urodynamic examinations delineated complex genitourinary and spinal anomalies necessitat...
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| Format: | Article |
| Language: | English |
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Elsevier
2025-09-01
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| Series: | Urology Case Reports |
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| Online Access: | http://www.sciencedirect.com/science/article/pii/S2214442025002402 |
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| author | Narjes Saberi Farid Rajaei Rizi Mohammad Nozari |
| author_facet | Narjes Saberi Farid Rajaei Rizi Mohammad Nozari |
| author_sort | Narjes Saberi |
| collection | DOAJ |
| description | We report a highly unusual case of penile duplication (diphallia) accompanied by epispadias, neurogenic bladder with markedly reduced compliance, and lumbar vertebral fusion. Comprehensive clinical, imaging, and urodynamic examinations delineated complex genitourinary and spinal anomalies necessitating multidisciplinary management. The discussion reviews embryological implications, compares existing literature, and addresses long-term follow-up considerations. This case underscores the clinical and academic importance of individualized evaluation and tailored intervention for exceedingly rare multisystem congenital malformations. |
| format | Article |
| id | doaj-art-41e53ec5b59c46cfab3d054be2e44773 |
| institution | Kabale University |
| issn | 2214-4420 |
| language | English |
| publishDate | 2025-09-01 |
| publisher | Elsevier |
| record_format | Article |
| series | Urology Case Reports |
| spelling | doaj-art-41e53ec5b59c46cfab3d054be2e447732025-08-24T05:12:46ZengElsevierUrology Case Reports2214-44202025-09-016210316910.1016/j.eucr.2025.103169Penile duplication (diphallia) with epispadias, neurogenic bladder, and lumbar vertebral Fusion: An exceptionally rare multisystem congenital associationNarjes Saberi0Farid Rajaei Rizi1Mohammad Nozari2Department of Urology, Isfahan Kidney Disease Research Center, Isfahan University of Medical Sciences, Isfahan, IranEndocrine and Metabolism Research Center, Isfahan University of Medical Sciences, Isfahan, Iran; Corresponding author. Endocrine and Metabolism Research Center, Khorram St., Isfahan, Iran.Department of Urology, Al-Zahra Hospital, Isfahan University of Medical Sciences, Isfahan, IranWe report a highly unusual case of penile duplication (diphallia) accompanied by epispadias, neurogenic bladder with markedly reduced compliance, and lumbar vertebral fusion. Comprehensive clinical, imaging, and urodynamic examinations delineated complex genitourinary and spinal anomalies necessitating multidisciplinary management. The discussion reviews embryological implications, compares existing literature, and addresses long-term follow-up considerations. This case underscores the clinical and academic importance of individualized evaluation and tailored intervention for exceedingly rare multisystem congenital malformations.http://www.sciencedirect.com/science/article/pii/S2214442025002402Penile duplicationEpispadiasNeurogenic bladderVertebral fusionCase report |
| spellingShingle | Narjes Saberi Farid Rajaei Rizi Mohammad Nozari Penile duplication (diphallia) with epispadias, neurogenic bladder, and lumbar vertebral Fusion: An exceptionally rare multisystem congenital association Urology Case Reports Penile duplication Epispadias Neurogenic bladder Vertebral fusion Case report |
| title | Penile duplication (diphallia) with epispadias, neurogenic bladder, and lumbar vertebral Fusion: An exceptionally rare multisystem congenital association |
| title_full | Penile duplication (diphallia) with epispadias, neurogenic bladder, and lumbar vertebral Fusion: An exceptionally rare multisystem congenital association |
| title_fullStr | Penile duplication (diphallia) with epispadias, neurogenic bladder, and lumbar vertebral Fusion: An exceptionally rare multisystem congenital association |
| title_full_unstemmed | Penile duplication (diphallia) with epispadias, neurogenic bladder, and lumbar vertebral Fusion: An exceptionally rare multisystem congenital association |
| title_short | Penile duplication (diphallia) with epispadias, neurogenic bladder, and lumbar vertebral Fusion: An exceptionally rare multisystem congenital association |
| title_sort | penile duplication diphallia with epispadias neurogenic bladder and lumbar vertebral fusion an exceptionally rare multisystem congenital association |
| topic | Penile duplication Epispadias Neurogenic bladder Vertebral fusion Case report |
| url | http://www.sciencedirect.com/science/article/pii/S2214442025002402 |
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