Characterizing T Cells in SCID Patients Presenting with Reactive or Residual T Lymphocytes

Introduction. Patients with severe combined immunodeficiency (SCID) may present with residual circulating T cells. While all cells are functionally deficient, resulting in high susceptibility to infections, only some of these cells are causing autoimmune symptoms. Methods. Here we compared T-cell fu...

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Main Authors: Atar Lev, Amos J. Simon, Luba Trakhtenbrot, Itamar Goldstein, Meital Nagar, Polina Stepensky, Gideon Rechavi, Ninette Amariglio, Raz Somech
Format: Article
Language:English
Published: Wiley 2012-01-01
Series:Clinical and Developmental Immunology
Online Access:http://dx.doi.org/10.1155/2012/261470
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author Atar Lev
Amos J. Simon
Luba Trakhtenbrot
Itamar Goldstein
Meital Nagar
Polina Stepensky
Gideon Rechavi
Ninette Amariglio
Raz Somech
author_facet Atar Lev
Amos J. Simon
Luba Trakhtenbrot
Itamar Goldstein
Meital Nagar
Polina Stepensky
Gideon Rechavi
Ninette Amariglio
Raz Somech
author_sort Atar Lev
collection DOAJ
description Introduction. Patients with severe combined immunodeficiency (SCID) may present with residual circulating T cells. While all cells are functionally deficient, resulting in high susceptibility to infections, only some of these cells are causing autoimmune symptoms. Methods. Here we compared T-cell functions including the number of circulating CD3+ T cells, in vitro responses to mitogens, T-cell receptor (TCR) repertoire, TCR excision circles (TREC) levels, and regulatory T cells (Tregs) enumeration in several immunodeficinecy subtypes, clinically presenting with nonreactive residual cells (MHC-II deficiency) or reactive cells. The latter includes patients with autoreactive clonal expanded T cell and patients with alloreactive transplacentally maternal T cells. Results. MHC-II deficient patients had slightly reduced T-cell function, normal TRECs, TCR repertoires, and normal Tregs enumeration. In contrast, patients with reactive T cells exhibited poor T-cell differentiation and activity. While the autoreactive cells displayed significantly reduced Tregs numbers, the alloreactive transplacentally acquired maternal lymphocytes had high functional Tregs. Conclusion. SCID patients presenting with circulating T cells show different patterns of T-cell activity and regulatory T cells enumeration that dictates the immunodeficient and autoimmune manifestations. We suggest that a high-tolerance capacity of the alloreactive transplacentally acquired maternal lymphocytes represents a toleration advantage, yet still associated with severe immunodeficiency.
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spelling doaj-art-40d4d0d0e6ff41589c8f71b5b69f31d52025-08-20T02:07:51ZengWileyClinical and Developmental Immunology1740-25221740-25302012-01-01201210.1155/2012/261470261470Characterizing T Cells in SCID Patients Presenting with Reactive or Residual T LymphocytesAtar Lev0Amos J. Simon1Luba Trakhtenbrot2Itamar Goldstein3Meital Nagar4Polina Stepensky5Gideon Rechavi6Ninette Amariglio7Raz Somech8Cancer Research Center, Chaim Sheba Medical Center, Sackler Faculty of Medicine, Tel Aviv University, 69978 Tel Aviv, IsraelCancer Research Center, Chaim Sheba Medical Center, Sackler Faculty of Medicine, Tel Aviv University, 69978 Tel Aviv, IsraelCancer Research Center, Chaim Sheba Medical Center, Sackler Faculty of Medicine, Tel Aviv University, 69978 Tel Aviv, IsraelCancer Research Center, Chaim Sheba Medical Center, Sackler Faculty of Medicine, Tel Aviv University, 69978 Tel Aviv, IsraelCancer Research Center, Chaim Sheba Medical Center, Sackler Faculty of Medicine, Tel Aviv University, 69978 Tel Aviv, IsraelDepartment of Pediatric Hematology-Oncology, Hadassah Medical Center, Hadassah Hebrew University, 91120 Jerusalem, IsraelCancer Research Center, Chaim Sheba Medical Center, Sackler Faculty of Medicine, Tel Aviv University, 69978 Tel Aviv, IsraelCancer Research Center, Chaim Sheba Medical Center, Sackler Faculty of Medicine, Tel Aviv University, 69978 Tel Aviv, IsraelCancer Research Center, Chaim Sheba Medical Center, Sackler Faculty of Medicine, Tel Aviv University, 69978 Tel Aviv, IsraelIntroduction. Patients with severe combined immunodeficiency (SCID) may present with residual circulating T cells. While all cells are functionally deficient, resulting in high susceptibility to infections, only some of these cells are causing autoimmune symptoms. Methods. Here we compared T-cell functions including the number of circulating CD3+ T cells, in vitro responses to mitogens, T-cell receptor (TCR) repertoire, TCR excision circles (TREC) levels, and regulatory T cells (Tregs) enumeration in several immunodeficinecy subtypes, clinically presenting with nonreactive residual cells (MHC-II deficiency) or reactive cells. The latter includes patients with autoreactive clonal expanded T cell and patients with alloreactive transplacentally maternal T cells. Results. MHC-II deficient patients had slightly reduced T-cell function, normal TRECs, TCR repertoires, and normal Tregs enumeration. In contrast, patients with reactive T cells exhibited poor T-cell differentiation and activity. While the autoreactive cells displayed significantly reduced Tregs numbers, the alloreactive transplacentally acquired maternal lymphocytes had high functional Tregs. Conclusion. SCID patients presenting with circulating T cells show different patterns of T-cell activity and regulatory T cells enumeration that dictates the immunodeficient and autoimmune manifestations. We suggest that a high-tolerance capacity of the alloreactive transplacentally acquired maternal lymphocytes represents a toleration advantage, yet still associated with severe immunodeficiency.http://dx.doi.org/10.1155/2012/261470
spellingShingle Atar Lev
Amos J. Simon
Luba Trakhtenbrot
Itamar Goldstein
Meital Nagar
Polina Stepensky
Gideon Rechavi
Ninette Amariglio
Raz Somech
Characterizing T Cells in SCID Patients Presenting with Reactive or Residual T Lymphocytes
Clinical and Developmental Immunology
title Characterizing T Cells in SCID Patients Presenting with Reactive or Residual T Lymphocytes
title_full Characterizing T Cells in SCID Patients Presenting with Reactive or Residual T Lymphocytes
title_fullStr Characterizing T Cells in SCID Patients Presenting with Reactive or Residual T Lymphocytes
title_full_unstemmed Characterizing T Cells in SCID Patients Presenting with Reactive or Residual T Lymphocytes
title_short Characterizing T Cells in SCID Patients Presenting with Reactive or Residual T Lymphocytes
title_sort characterizing t cells in scid patients presenting with reactive or residual t lymphocytes
url http://dx.doi.org/10.1155/2012/261470
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