MLKL deficiency elevates testosterone production in male mice independently of necroptotic functions

Abstract Mixed lineage kinase domain-like (MLKL) is a pseudokinase, best known for its role as the terminal effector of the necroptotic cell death pathway. MLKL-mediated necroptosis has long been linked to various age-related pathologies including neurodegeneration, atherosclerosis and male reproduc...

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Main Authors: Shene Chiou, Wayne Cawthorne, Thomas Soerianto, Vinzenz Hofferek, Komal M. Patel, Sarah E. Garnish, Emma C. Tovey Crutchfield, Cathrine Hall, Joanne M. Hildebrand, Malcolm J. McConville, Kate E. Lawlor, Edwin D. Hawkins, Andre L. Samson, James M. Murphy
Format: Article
Language:English
Published: Nature Publishing Group 2024-11-01
Series:Cell Death and Disease
Online Access:https://doi.org/10.1038/s41419-024-07242-z
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author Shene Chiou
Wayne Cawthorne
Thomas Soerianto
Vinzenz Hofferek
Komal M. Patel
Sarah E. Garnish
Emma C. Tovey Crutchfield
Cathrine Hall
Joanne M. Hildebrand
Malcolm J. McConville
Kate E. Lawlor
Edwin D. Hawkins
Andre L. Samson
James M. Murphy
author_facet Shene Chiou
Wayne Cawthorne
Thomas Soerianto
Vinzenz Hofferek
Komal M. Patel
Sarah E. Garnish
Emma C. Tovey Crutchfield
Cathrine Hall
Joanne M. Hildebrand
Malcolm J. McConville
Kate E. Lawlor
Edwin D. Hawkins
Andre L. Samson
James M. Murphy
author_sort Shene Chiou
collection DOAJ
description Abstract Mixed lineage kinase domain-like (MLKL) is a pseudokinase, best known for its role as the terminal effector of the necroptotic cell death pathway. MLKL-mediated necroptosis has long been linked to various age-related pathologies including neurodegeneration, atherosclerosis and male reproductive decline, however many of these attributions remain controversial. Here, we investigated the role of MLKL and necroptosis in the adult mouse testis: an organ divided into sperm-producing seminiferous tubules and the surrounding testosterone-producing interstitium. We find that sperm-producing cells within seminiferous tubules lack expression of key necroptotic mediators and thus are resistant to a pro-necroptotic challenge. By comparison, coordinated expression of the necroptotic pathway occurs in the testicular interstitium, rendering cells within this compartment, especially the lysozyme-positive macrophages, vulnerable to necroptotic cell death. We also uncover a non-necroptotic role for MLKL in regulating testosterone levels. Thus, MLKL serves two roles in the mouse testes – one involving the canonical response of macrophages to necroptotic insult, and the other a non-canonical function in male reproductive hormone control.
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spelling doaj-art-3e983790f4d740f6875bec76ced943af2025-08-20T02:22:16ZengNature Publishing GroupCell Death and Disease2041-48892024-11-01151111010.1038/s41419-024-07242-zMLKL deficiency elevates testosterone production in male mice independently of necroptotic functionsShene Chiou0Wayne Cawthorne1Thomas Soerianto2Vinzenz Hofferek3Komal M. Patel4Sarah E. Garnish5Emma C. Tovey Crutchfield6Cathrine Hall7Joanne M. Hildebrand8Malcolm J. McConville9Kate E. Lawlor10Edwin D. Hawkins11Andre L. Samson12James M. Murphy13Walter and Eliza Hall Institute of Medical ResearchWalter and Eliza Hall Institute of Medical ResearchDepartment of Biochemistry and Pharmacology, Bio21 Molecular Science and Biotechnology InstituteDepartment of Biochemistry and Pharmacology, Bio21 Molecular Science and Biotechnology InstituteWalter and Eliza Hall Institute of Medical ResearchWalter and Eliza Hall Institute of Medical ResearchWalter and Eliza Hall Institute of Medical ResearchWalter and Eliza Hall Institute of Medical ResearchWalter and Eliza Hall Institute of Medical ResearchDepartment of Biochemistry and Pharmacology, Bio21 Molecular Science and Biotechnology InstituteCentre for Innate Immunity and Infectious Diseases, Hudson Institute of Medical ResearchWalter and Eliza Hall Institute of Medical ResearchWalter and Eliza Hall Institute of Medical ResearchWalter and Eliza Hall Institute of Medical ResearchAbstract Mixed lineage kinase domain-like (MLKL) is a pseudokinase, best known for its role as the terminal effector of the necroptotic cell death pathway. MLKL-mediated necroptosis has long been linked to various age-related pathologies including neurodegeneration, atherosclerosis and male reproductive decline, however many of these attributions remain controversial. Here, we investigated the role of MLKL and necroptosis in the adult mouse testis: an organ divided into sperm-producing seminiferous tubules and the surrounding testosterone-producing interstitium. We find that sperm-producing cells within seminiferous tubules lack expression of key necroptotic mediators and thus are resistant to a pro-necroptotic challenge. By comparison, coordinated expression of the necroptotic pathway occurs in the testicular interstitium, rendering cells within this compartment, especially the lysozyme-positive macrophages, vulnerable to necroptotic cell death. We also uncover a non-necroptotic role for MLKL in regulating testosterone levels. Thus, MLKL serves two roles in the mouse testes – one involving the canonical response of macrophages to necroptotic insult, and the other a non-canonical function in male reproductive hormone control.https://doi.org/10.1038/s41419-024-07242-z
spellingShingle Shene Chiou
Wayne Cawthorne
Thomas Soerianto
Vinzenz Hofferek
Komal M. Patel
Sarah E. Garnish
Emma C. Tovey Crutchfield
Cathrine Hall
Joanne M. Hildebrand
Malcolm J. McConville
Kate E. Lawlor
Edwin D. Hawkins
Andre L. Samson
James M. Murphy
MLKL deficiency elevates testosterone production in male mice independently of necroptotic functions
Cell Death and Disease
title MLKL deficiency elevates testosterone production in male mice independently of necroptotic functions
title_full MLKL deficiency elevates testosterone production in male mice independently of necroptotic functions
title_fullStr MLKL deficiency elevates testosterone production in male mice independently of necroptotic functions
title_full_unstemmed MLKL deficiency elevates testosterone production in male mice independently of necroptotic functions
title_short MLKL deficiency elevates testosterone production in male mice independently of necroptotic functions
title_sort mlkl deficiency elevates testosterone production in male mice independently of necroptotic functions
url https://doi.org/10.1038/s41419-024-07242-z
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