Activity-dependent synapse elimination requires caspase-3 activation

During brain development, synapses are initially formed in excess and are later eliminated in an activity-dependent manner. Weak synapses are preferentially removed, but the mechanism linking neuronal activity to synapse removal is unclear. Here, we show that, in the developing mouse visual pathway,...

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Main Authors: Zhou Yu, Andrian Gutu, Namsoo Kim, Erin K O'Shea
Format: Article
Language:English
Published: eLife Sciences Publications Ltd 2025-06-01
Series:eLife
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Online Access:https://elifesciences.org/articles/101779
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author Zhou Yu
Andrian Gutu
Namsoo Kim
Erin K O'Shea
author_facet Zhou Yu
Andrian Gutu
Namsoo Kim
Erin K O'Shea
author_sort Zhou Yu
collection DOAJ
description During brain development, synapses are initially formed in excess and are later eliminated in an activity-dependent manner. Weak synapses are preferentially removed, but the mechanism linking neuronal activity to synapse removal is unclear. Here, we show that, in the developing mouse visual pathway, inhibiting synaptic transmission induces postsynaptic activation of caspase-3. Caspase-3 deficiency results in defects in synapse elimination driven by both spontaneous and experience-dependent neural activity. Notably, caspase-3 deficiency blocks activity-dependent synapse elimination, as evidenced by reduced engulfment of inactive synapses by microglia. Furthermore, in a mouse model of Alzheimer’s disease, caspase-3 deficiency protects against synapse loss induced by amyloid-β deposition. Our results reveal caspase-3 activation as a key step in activity-dependent synapse elimination during development and synapse loss in neurodegeneration.
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spelling doaj-art-3ac6b62f8586482f99bb5c3a2ced47772025-08-20T02:23:27ZengeLife Sciences Publications LtdeLife2050-084X2025-06-011310.7554/eLife.101779Activity-dependent synapse elimination requires caspase-3 activationZhou Yu0https://orcid.org/0000-0003-3213-4583Andrian Gutu1https://orcid.org/0000-0002-5804-1978Namsoo Kim2Erin K O'Shea3https://orcid.org/0000-0002-2649-1018Janelia Research Campus, Howard Hughes Medical Institute, Ashburn, United StatesJanelia Research Campus, Howard Hughes Medical Institute, Ashburn, United StatesJanelia Research Campus, Howard Hughes Medical Institute, Ashburn, United StatesJanelia Research Campus, Howard Hughes Medical Institute, Ashburn, United StatesDuring brain development, synapses are initially formed in excess and are later eliminated in an activity-dependent manner. Weak synapses are preferentially removed, but the mechanism linking neuronal activity to synapse removal is unclear. Here, we show that, in the developing mouse visual pathway, inhibiting synaptic transmission induces postsynaptic activation of caspase-3. Caspase-3 deficiency results in defects in synapse elimination driven by both spontaneous and experience-dependent neural activity. Notably, caspase-3 deficiency blocks activity-dependent synapse elimination, as evidenced by reduced engulfment of inactive synapses by microglia. Furthermore, in a mouse model of Alzheimer’s disease, caspase-3 deficiency protects against synapse loss induced by amyloid-β deposition. Our results reveal caspase-3 activation as a key step in activity-dependent synapse elimination during development and synapse loss in neurodegeneration.https://elifesciences.org/articles/101779synapse eliminationsynaptic activitycaspase-3microglia
spellingShingle Zhou Yu
Andrian Gutu
Namsoo Kim
Erin K O'Shea
Activity-dependent synapse elimination requires caspase-3 activation
eLife
synapse elimination
synaptic activity
caspase-3
microglia
title Activity-dependent synapse elimination requires caspase-3 activation
title_full Activity-dependent synapse elimination requires caspase-3 activation
title_fullStr Activity-dependent synapse elimination requires caspase-3 activation
title_full_unstemmed Activity-dependent synapse elimination requires caspase-3 activation
title_short Activity-dependent synapse elimination requires caspase-3 activation
title_sort activity dependent synapse elimination requires caspase 3 activation
topic synapse elimination
synaptic activity
caspase-3
microglia
url https://elifesciences.org/articles/101779
work_keys_str_mv AT zhouyu activitydependentsynapseeliminationrequirescaspase3activation
AT andriangutu activitydependentsynapseeliminationrequirescaspase3activation
AT namsookim activitydependentsynapseeliminationrequirescaspase3activation
AT erinkoshea activitydependentsynapseeliminationrequirescaspase3activation