CLINICAL CHARACTERISTICS OF RESPIRATORY INVOLVEMENT IN CHILDREN WITH CYSTIC FIBROSIS IN THE CHUVASH REPUBLIC

Cystic fibrosis is a common hereditary disease, characterized by multiple organ dysfunction, including early and severe involvement of respiratory system. The disease is caused by CFTR (cystic fibrosis transmembrane conductance regulator) gene mutation. Respiratory tract involvement is a main factor...

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Main Authors: O. I. Golubtsova, S. A. Krasovskiy, S. L. Kozhevnikova, N. I. Kapranov
Format: Article
Language:English
Published: "Paediatrician" Publishers LLC 2012-07-01
Series:Вопросы современной педиатрии
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Online Access:https://vsp.spr-journal.ru/jour/article/view/454
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author O. I. Golubtsova
S. A. Krasovskiy
S. L. Kozhevnikova
N. I. Kapranov
author_facet O. I. Golubtsova
S. A. Krasovskiy
S. L. Kozhevnikova
N. I. Kapranov
author_sort O. I. Golubtsova
collection DOAJ
description Cystic fibrosis is a common hereditary disease, characterized by multiple organ dysfunction, including early and severe involvement of respiratory system. The disease is caused by CFTR (cystic fibrosis transmembrane conductance regulator) gene mutation. Respiratory tract involvement is a main factor, predicting outcome, mortality, life quality and morbidity of patients. Genetic examination of Chuvash children demonstrated, that 53,5% of patients’ chromosomes are carriers of E92K mutation. According to genetic epidemiology of cystic fibrosis, Chuvash ethnic group is unique, as the prevalence of mutation E92K in it is almost twice higher than the most common and «severe» mutation in the world — F508del. The significant predominance of E92K determined the clinical presentation of cystic fibrosis in the examined group, because this mutation refers as «mild». The critical moment in treatment of this disorder is influence on sputum viscosity. Dornase alpha proved itself as an effective drug, which advantages among other agents, improving sputum rheological properties, are caused not only by unique mucolytic effect, but also anti-inflammatory and antibacterial actions.
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publishDate 2012-07-01
publisher "Paediatrician" Publishers LLC
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series Вопросы современной педиатрии
spelling doaj-art-39cca4f94a574c70abf09ebf685c76e12025-08-20T03:35:18Zeng"Paediatrician" Publishers LLCВопросы современной педиатрии1682-55271682-55352012-07-01114545910.15690/vsp.v11i4.359454CLINICAL CHARACTERISTICS OF RESPIRATORY INVOLVEMENT IN CHILDREN WITH CYSTIC FIBROSIS IN THE CHUVASH REPUBLICO. I. Golubtsova0S. A. Krasovskiy1S. L. Kozhevnikova2N. I. Kapranov3Chuvash State University name of I.N. Ulyanov, CheboksaryChuvash State University name of I.N. Ulyanov, CheboksaryChuvash State University name of I.N. Ulyanov, CheboksaryChuvash State University name of I.N. Ulyanov, CheboksaryCystic fibrosis is a common hereditary disease, characterized by multiple organ dysfunction, including early and severe involvement of respiratory system. The disease is caused by CFTR (cystic fibrosis transmembrane conductance regulator) gene mutation. Respiratory tract involvement is a main factor, predicting outcome, mortality, life quality and morbidity of patients. Genetic examination of Chuvash children demonstrated, that 53,5% of patients’ chromosomes are carriers of E92K mutation. According to genetic epidemiology of cystic fibrosis, Chuvash ethnic group is unique, as the prevalence of mutation E92K in it is almost twice higher than the most common and «severe» mutation in the world — F508del. The significant predominance of E92K determined the clinical presentation of cystic fibrosis in the examined group, because this mutation refers as «mild». The critical moment in treatment of this disorder is influence on sputum viscosity. Dornase alpha proved itself as an effective drug, which advantages among other agents, improving sputum rheological properties, are caused not only by unique mucolytic effect, but also anti-inflammatory and antibacterial actions.https://vsp.spr-journal.ru/jour/article/view/454cystic fibrosischildrenchronic nonspecific pulmonary diseasesmolecular genetic assay«mild» mutation e92k«severe» mutation f508 deldornase alpha
spellingShingle O. I. Golubtsova
S. A. Krasovskiy
S. L. Kozhevnikova
N. I. Kapranov
CLINICAL CHARACTERISTICS OF RESPIRATORY INVOLVEMENT IN CHILDREN WITH CYSTIC FIBROSIS IN THE CHUVASH REPUBLIC
Вопросы современной педиатрии
cystic fibrosis
children
chronic nonspecific pulmonary diseases
molecular genetic assay
«mild» mutation e92k
«severe» mutation f508 del
dornase alpha
title CLINICAL CHARACTERISTICS OF RESPIRATORY INVOLVEMENT IN CHILDREN WITH CYSTIC FIBROSIS IN THE CHUVASH REPUBLIC
title_full CLINICAL CHARACTERISTICS OF RESPIRATORY INVOLVEMENT IN CHILDREN WITH CYSTIC FIBROSIS IN THE CHUVASH REPUBLIC
title_fullStr CLINICAL CHARACTERISTICS OF RESPIRATORY INVOLVEMENT IN CHILDREN WITH CYSTIC FIBROSIS IN THE CHUVASH REPUBLIC
title_full_unstemmed CLINICAL CHARACTERISTICS OF RESPIRATORY INVOLVEMENT IN CHILDREN WITH CYSTIC FIBROSIS IN THE CHUVASH REPUBLIC
title_short CLINICAL CHARACTERISTICS OF RESPIRATORY INVOLVEMENT IN CHILDREN WITH CYSTIC FIBROSIS IN THE CHUVASH REPUBLIC
title_sort clinical characteristics of respiratory involvement in children with cystic fibrosis in the chuvash republic
topic cystic fibrosis
children
chronic nonspecific pulmonary diseases
molecular genetic assay
«mild» mutation e92k
«severe» mutation f508 del
dornase alpha
url https://vsp.spr-journal.ru/jour/article/view/454
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AT slkozhevnikova clinicalcharacteristicsofrespiratoryinvolvementinchildrenwithcysticfibrosisinthechuvashrepublic
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