New-Onset Type 1 Diabetes in a Child with Joubert Syndrome: A Rare Endocrine Complication

<b>Background and Clinical Significance:</b> Joubert syndrome (OMIM #213300) is a rare predominantly autosomal recessive inherited condition characterized by the classic cerebellar vermis hypoplasia and brainstem anomalies (also known as the “molar tooth sign”), hypotonia, and developmen...

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Main Authors: Yutaka Furuta, Erica T. Nelson, Rory J. Tinker, Angela R. Grochowsky
Format: Article
Language:English
Published: MDPI AG 2025-04-01
Series:Reports
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Online Access:https://www.mdpi.com/2571-841X/8/2/57
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author Yutaka Furuta
Erica T. Nelson
Rory J. Tinker
Angela R. Grochowsky
author_facet Yutaka Furuta
Erica T. Nelson
Rory J. Tinker
Angela R. Grochowsky
author_sort Yutaka Furuta
collection DOAJ
description <b>Background and Clinical Significance:</b> Joubert syndrome (OMIM #213300) is a rare predominantly autosomal recessive inherited condition characterized by the classic cerebellar vermis hypoplasia and brainstem anomalies (also known as the “molar tooth sign”), hypotonia, and developmental delays. Joubert syndrome is a ciliopathy that affects multiple systems including the central nervous system, eyes, kidneys, liver, respiratory, musculoskeletal system, cardiovascular system, and endocrine system. Endocrine abnormalities are not uncommon in Joubert syndrome, such as growth hormone deficiency, thyroid hormone deficiency, central diabetes insipidus, hypopituitarism, micropenis, and obesity. However, a new-onset type 1 diabetes in childhood is not common in Joubert syndrome. <b>Case Presentation:</b> Herein, we report a case of a 7-year-old male with a history of Joubert syndrome presenting with polydipsia, polyuria, weight loss, and hyperglycemia who was diagnosed with type 1 diabetes. <b>Conclusions:</b> While diabetes has been reported as a rare complication in Joubert syndrome, this is the first case report of Joubert syndrome to accentuate new-onset type 1 diabetes as an endocrine complication.
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spelling doaj-art-37ac8021493f44c9963cac932dd40bf22025-08-20T03:16:39ZengMDPI AGReports2571-841X2025-04-01825710.3390/reports8020057New-Onset Type 1 Diabetes in a Child with Joubert Syndrome: A Rare Endocrine ComplicationYutaka Furuta0Erica T. Nelson1Rory J. Tinker2Angela R. Grochowsky3Department of Pediatrics, Division of Medical Genetics and Genomic Medicine, Vanderbilt University Medical Center, Nashville, TN 37232, USADepartment of Pediatrics, Division of Medical Genetics and Genomic Medicine, Vanderbilt University Medical Center, Nashville, TN 37232, USADepartment of Pediatrics, Division of Medical Genetics and Genomic Medicine, Vanderbilt University Medical Center, Nashville, TN 37232, USADepartment of Pediatrics, Division of Medical Genetics and Genomic Medicine, Vanderbilt University Medical Center, Nashville, TN 37232, USA<b>Background and Clinical Significance:</b> Joubert syndrome (OMIM #213300) is a rare predominantly autosomal recessive inherited condition characterized by the classic cerebellar vermis hypoplasia and brainstem anomalies (also known as the “molar tooth sign”), hypotonia, and developmental delays. Joubert syndrome is a ciliopathy that affects multiple systems including the central nervous system, eyes, kidneys, liver, respiratory, musculoskeletal system, cardiovascular system, and endocrine system. Endocrine abnormalities are not uncommon in Joubert syndrome, such as growth hormone deficiency, thyroid hormone deficiency, central diabetes insipidus, hypopituitarism, micropenis, and obesity. However, a new-onset type 1 diabetes in childhood is not common in Joubert syndrome. <b>Case Presentation:</b> Herein, we report a case of a 7-year-old male with a history of Joubert syndrome presenting with polydipsia, polyuria, weight loss, and hyperglycemia who was diagnosed with type 1 diabetes. <b>Conclusions:</b> While diabetes has been reported as a rare complication in Joubert syndrome, this is the first case report of Joubert syndrome to accentuate new-onset type 1 diabetes as an endocrine complication.https://www.mdpi.com/2571-841X/8/2/57ciliopathyJoubert syndrometype 1 diabetes
spellingShingle Yutaka Furuta
Erica T. Nelson
Rory J. Tinker
Angela R. Grochowsky
New-Onset Type 1 Diabetes in a Child with Joubert Syndrome: A Rare Endocrine Complication
Reports
ciliopathy
Joubert syndrome
type 1 diabetes
title New-Onset Type 1 Diabetes in a Child with Joubert Syndrome: A Rare Endocrine Complication
title_full New-Onset Type 1 Diabetes in a Child with Joubert Syndrome: A Rare Endocrine Complication
title_fullStr New-Onset Type 1 Diabetes in a Child with Joubert Syndrome: A Rare Endocrine Complication
title_full_unstemmed New-Onset Type 1 Diabetes in a Child with Joubert Syndrome: A Rare Endocrine Complication
title_short New-Onset Type 1 Diabetes in a Child with Joubert Syndrome: A Rare Endocrine Complication
title_sort new onset type 1 diabetes in a child with joubert syndrome a rare endocrine complication
topic ciliopathy
Joubert syndrome
type 1 diabetes
url https://www.mdpi.com/2571-841X/8/2/57
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AT ericatnelson newonsettype1diabetesinachildwithjoubertsyndromearareendocrinecomplication
AT roryjtinker newonsettype1diabetesinachildwithjoubertsyndromearareendocrinecomplication
AT angelargrochowsky newonsettype1diabetesinachildwithjoubertsyndromearareendocrinecomplication