The N-degron pathway mediates the autophagic degradation of cytosolic mitochondrial DNA during sterile innate immune responses

Summary: The human body reacts to tissue damage by generating damage-associated molecular patterns (DAMPs) that activate sterile immune responses. To date, little is known about how DAMPs are removed to avoid excessive immune responses. Here, we show that proteasomal dysfunction induces the release...

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Main Authors: Chan Hoon Jung, Yoon Jee Lee, Eun Hye Cho, Gee Eun Lee, Sung Tae Kim, Ki Sa Sung, Daeho Kim, Dong Hyun Kim, Yeon Sung Son, Jin-Hyun Ahn, Dohyun Han, Yong Tae Kwon
Format: Article
Language:English
Published: Elsevier 2025-01-01
Series:Cell Reports
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Online Access:http://www.sciencedirect.com/science/article/pii/S2211124724014451
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author Chan Hoon Jung
Yoon Jee Lee
Eun Hye Cho
Gee Eun Lee
Sung Tae Kim
Ki Sa Sung
Daeho Kim
Dong Hyun Kim
Yeon Sung Son
Jin-Hyun Ahn
Dohyun Han
Yong Tae Kwon
author_facet Chan Hoon Jung
Yoon Jee Lee
Eun Hye Cho
Gee Eun Lee
Sung Tae Kim
Ki Sa Sung
Daeho Kim
Dong Hyun Kim
Yeon Sung Son
Jin-Hyun Ahn
Dohyun Han
Yong Tae Kwon
author_sort Chan Hoon Jung
collection DOAJ
description Summary: The human body reacts to tissue damage by generating damage-associated molecular patterns (DAMPs) that activate sterile immune responses. To date, little is known about how DAMPs are removed to avoid excessive immune responses. Here, we show that proteasomal dysfunction induces the release of mitochondrial DNA (mtDNA) as a DAMP that activates the cyclic GMP-AMP synthase (cGAS)-stimulator of interferon gene (STING) pathway and is subsequently degraded through the N-degron pathway. In the resolution phase of sterile immune responses, DNA-dependent protein kinase (DNA-PK) senses cytosolic mtDNA and activates N-terminal (Nt-) arginylation by ATE1 R-transferases. The substrates of Nt-arginylation include the molecular chaperone BiP/GRP78 retrotranslocated from the endoplasmic reticulum (ER). R-BiP, the Nt-arginylated species of BiP, is associated with cytosolic mtDNA to accelerate its targeting to autophagic membranes for lysosomal degradation. Thus, cytosolic mtDNA activates the N-degron pathway to facilitate its own degradation and form a negative feedback loop, by which the cell can turn off sterile immune responses at the right time.
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spelling doaj-art-352d7fb146d04df3b5e2fe3ec2d3130c2025-08-20T01:59:48ZengElsevierCell Reports2211-12472025-01-0144111509410.1016/j.celrep.2024.115094The N-degron pathway mediates the autophagic degradation of cytosolic mitochondrial DNA during sterile innate immune responsesChan Hoon Jung0Yoon Jee Lee1Eun Hye Cho2Gee Eun Lee3Sung Tae Kim4Ki Sa Sung5Daeho Kim6Dong Hyun Kim7Yeon Sung Son8Jin-Hyun Ahn9Dohyun Han10Yong Tae Kwon11Cellular Degradation Biology Center and Department of Biomedical Sciences, College of Medicine, Seoul National University, Seoul 03080, Republic of KoreaCellular Degradation Biology Center and Department of Biomedical Sciences, College of Medicine, Seoul National University, Seoul 03080, Republic of KoreaCellular Degradation Biology Center and Department of Biomedical Sciences, College of Medicine, Seoul National University, Seoul 03080, Republic of KoreaCellular Degradation Biology Center and Department of Biomedical Sciences, College of Medicine, Seoul National University, Seoul 03080, Republic of KoreaRegeners, Inc., BVC 112, 125 Gwahak-ro, Yuseong-gu, Daejeon, Republic of KoreaDepartment of Pharmacological Sciences, Icahn School of Medicine at Mount Sinai, New York, NY 10029, USADepartment of Biochemistry, Case Western Reserve University, Cleveland, OH 44106, USACancer Metastasis Brach, Division of Cancer Biology, National Cancer Center, Goyang-si Gyeonggi-do 10408, Republic of KoreaCellular Degradation Biology Center and Department of Biomedical Sciences, College of Medicine, Seoul National University, Seoul 03080, Republic of Korea; Neuroscience Research Institute, Medical Research Center, College of Medicine, Seoul National University, Seoul 03080, Republic of KoreaDepartment of Microbiology, Sungkyunkwan University School of Medicine, Suwon 16419, Republic of KoreaDepartment of Transdisciplinary Medicine, Seoul National University Hospital, Seoul 03082, Republic of Korea; Department of Medicine, College of Medicine, Seoul National University, Seoul 03080, Republic of Korea; Corresponding authorCellular Degradation Biology Center and Department of Biomedical Sciences, College of Medicine, Seoul National University, Seoul 03080, Republic of Korea; Convergence Research Center for Dementia, Seoul National University Medical Research Center, Seoul 110-799, Republic of Korea; AUTOTAC Bio, Inc., Changkkyunggung-ro 254, Jongno-gu, Seoul 03077, Republic of Korea; Ischemic/Hypoxic Disease Institute, College of Medicine, Seoul National University, Seoul 110-799, Republic of Korea; Corresponding authorSummary: The human body reacts to tissue damage by generating damage-associated molecular patterns (DAMPs) that activate sterile immune responses. To date, little is known about how DAMPs are removed to avoid excessive immune responses. Here, we show that proteasomal dysfunction induces the release of mitochondrial DNA (mtDNA) as a DAMP that activates the cyclic GMP-AMP synthase (cGAS)-stimulator of interferon gene (STING) pathway and is subsequently degraded through the N-degron pathway. In the resolution phase of sterile immune responses, DNA-dependent protein kinase (DNA-PK) senses cytosolic mtDNA and activates N-terminal (Nt-) arginylation by ATE1 R-transferases. The substrates of Nt-arginylation include the molecular chaperone BiP/GRP78 retrotranslocated from the endoplasmic reticulum (ER). R-BiP, the Nt-arginylated species of BiP, is associated with cytosolic mtDNA to accelerate its targeting to autophagic membranes for lysosomal degradation. Thus, cytosolic mtDNA activates the N-degron pathway to facilitate its own degradation and form a negative feedback loop, by which the cell can turn off sterile immune responses at the right time.http://www.sciencedirect.com/science/article/pii/S2211124724014451CP: Immunology
spellingShingle Chan Hoon Jung
Yoon Jee Lee
Eun Hye Cho
Gee Eun Lee
Sung Tae Kim
Ki Sa Sung
Daeho Kim
Dong Hyun Kim
Yeon Sung Son
Jin-Hyun Ahn
Dohyun Han
Yong Tae Kwon
The N-degron pathway mediates the autophagic degradation of cytosolic mitochondrial DNA during sterile innate immune responses
Cell Reports
CP: Immunology
title The N-degron pathway mediates the autophagic degradation of cytosolic mitochondrial DNA during sterile innate immune responses
title_full The N-degron pathway mediates the autophagic degradation of cytosolic mitochondrial DNA during sterile innate immune responses
title_fullStr The N-degron pathway mediates the autophagic degradation of cytosolic mitochondrial DNA during sterile innate immune responses
title_full_unstemmed The N-degron pathway mediates the autophagic degradation of cytosolic mitochondrial DNA during sterile innate immune responses
title_short The N-degron pathway mediates the autophagic degradation of cytosolic mitochondrial DNA during sterile innate immune responses
title_sort n degron pathway mediates the autophagic degradation of cytosolic mitochondrial dna during sterile innate immune responses
topic CP: Immunology
url http://www.sciencedirect.com/science/article/pii/S2211124724014451
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