Congenital pulmonary airway malformation type 2 associated with intralobar pulmonary sequestration in an adult patient: a case report

Congenital pulmonary airway malformation (CPAM) and pulmonary sequestration (PS) are among the most common congenital lung malformations and their association is extremely rare. In exceptional cases, patients with CPAM remain asymptomatic until adulthood. We report the case of a 30-year-old man who...

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Main Authors: Asma Knaz, Soumaya Boujneh, Bechir ben Radhia, Marwa Krifa, Iteb BenLimem, Wafa Benzarti, Ahmed Abdelghani
Format: Article
Language:English
Published: Taylor & Francis Group 2025-12-01
Series:Future Science OA
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Online Access:https://www.tandfonline.com/doi/10.1080/20565623.2025.2527473
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author Asma Knaz
Soumaya Boujneh
Bechir ben Radhia
Marwa Krifa
Iteb BenLimem
Wafa Benzarti
Ahmed Abdelghani
author_facet Asma Knaz
Soumaya Boujneh
Bechir ben Radhia
Marwa Krifa
Iteb BenLimem
Wafa Benzarti
Ahmed Abdelghani
author_sort Asma Knaz
collection DOAJ
description Congenital pulmonary airway malformation (CPAM) and pulmonary sequestration (PS) are among the most common congenital lung malformations and their association is extremely rare. In exceptional cases, patients with CPAM remain asymptomatic until adulthood. We report the case of a 30-year-old man who was hospitalized in our pneumology department for fever, cough and chest pain. Radiological and histological findings confirmed the coexistence of CPAM and PS. The patient underwent surgical resection and recovered well. This is one of the few reported cases in the literature that describe the uncommon association of CPAM and PS with an infrequent diagnosis in adulthood. Clinicians should consider congenital malformations in the differential diagnosis of recurrent respiratory infections, particularly when they affect the same pulmonary lobe.
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series Future Science OA
spelling doaj-art-345a4e6a6331472989dfe3561028f6b62025-08-20T03:28:41ZengTaylor & Francis GroupFuture Science OA2056-56232025-12-0111110.1080/20565623.2025.2527473Congenital pulmonary airway malformation type 2 associated with intralobar pulmonary sequestration in an adult patient: a case reportAsma Knaz0Soumaya Boujneh1Bechir ben Radhia2Marwa Krifa3Iteb BenLimem4Wafa Benzarti5Ahmed Abdelghani6Pneumology Department, Farhat Hached Hospital, Sousse, TunisiaPneumology Department, Farhat Hached Hospital, Sousse, TunisiaThoracic and Cardiovascular Surgery Department, Sahloul Hospital, Sousse, TunisiaPathology Laboratory, Sahloul Hospital, Sousse, TunisiaPneumology Department, Farhat Hached Hospital, Sousse, TunisiaPneumology Department, Farhat Hached Hospital, Sousse, TunisiaPneumology Department, Farhat Hached Hospital, Sousse, TunisiaCongenital pulmonary airway malformation (CPAM) and pulmonary sequestration (PS) are among the most common congenital lung malformations and their association is extremely rare. In exceptional cases, patients with CPAM remain asymptomatic until adulthood. We report the case of a 30-year-old man who was hospitalized in our pneumology department for fever, cough and chest pain. Radiological and histological findings confirmed the coexistence of CPAM and PS. The patient underwent surgical resection and recovered well. This is one of the few reported cases in the literature that describe the uncommon association of CPAM and PS with an infrequent diagnosis in adulthood. Clinicians should consider congenital malformations in the differential diagnosis of recurrent respiratory infections, particularly when they affect the same pulmonary lobe.https://www.tandfonline.com/doi/10.1080/20565623.2025.2527473Airway malformationlung sequestrationcongenital lung malformationscase reportpulmonary abnormalitieshybrid lesion
spellingShingle Asma Knaz
Soumaya Boujneh
Bechir ben Radhia
Marwa Krifa
Iteb BenLimem
Wafa Benzarti
Ahmed Abdelghani
Congenital pulmonary airway malformation type 2 associated with intralobar pulmonary sequestration in an adult patient: a case report
Future Science OA
Airway malformation
lung sequestration
congenital lung malformations
case report
pulmonary abnormalities
hybrid lesion
title Congenital pulmonary airway malformation type 2 associated with intralobar pulmonary sequestration in an adult patient: a case report
title_full Congenital pulmonary airway malformation type 2 associated with intralobar pulmonary sequestration in an adult patient: a case report
title_fullStr Congenital pulmonary airway malformation type 2 associated with intralobar pulmonary sequestration in an adult patient: a case report
title_full_unstemmed Congenital pulmonary airway malformation type 2 associated with intralobar pulmonary sequestration in an adult patient: a case report
title_short Congenital pulmonary airway malformation type 2 associated with intralobar pulmonary sequestration in an adult patient: a case report
title_sort congenital pulmonary airway malformation type 2 associated with intralobar pulmonary sequestration in an adult patient a case report
topic Airway malformation
lung sequestration
congenital lung malformations
case report
pulmonary abnormalities
hybrid lesion
url https://www.tandfonline.com/doi/10.1080/20565623.2025.2527473
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