Congenital Bladder and Urethral Agenesis: Two Case Reports and Management

Background. Agenesis of the bladder and urethra is a rare congenital anomaly, with a very few living cases reported in the literature so far. Case Presentation. We are reporting two female patients (3 and 6 years old) with bladder and urethral agenesis who presented with urinary incontinence. In bot...

Full description

Saved in:
Bibliographic Details
Main Authors: Salahaddin Delshad, Hadith Rastad, Parham Mardi
Format: Article
Language:English
Published: Wiley 2020-01-01
Series:Advances in Urology
Online Access:http://dx.doi.org/10.1155/2020/2782783
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1832560234958159872
author Salahaddin Delshad
Hadith Rastad
Parham Mardi
author_facet Salahaddin Delshad
Hadith Rastad
Parham Mardi
author_sort Salahaddin Delshad
collection DOAJ
description Background. Agenesis of the bladder and urethra is a rare congenital anomaly, with a very few living cases reported in the literature so far. Case Presentation. We are reporting two female patients (3 and 6 years old) with bladder and urethral agenesis who presented with urinary incontinence. In both patients, magnetic resonant imaging (MRI) revealed a case of bladder and urethral agenesis with normal ureters draining into the vagina. Patients underwent a neobladder and conduit creation surgery. The neobladder was constructed from the whole cecum and a part of the ascending colon, followed by an anastomose of the ureters into the neobladder in a nonrefluxing fashion; the appendix was used simultaneously as a continent catheterizable conduit. The two patients attained urinary continence postoperatively. Conclusion. We reported two cases of bladder agenesis, and for the first time, we have performed neobladder creation surgery using the cecum and ascending colon. One-year follow-up did not reveal any complications.
format Article
id doaj-art-3103324abf43444d8521a1d40bbdb418
institution Kabale University
issn 1687-6369
1687-6377
language English
publishDate 2020-01-01
publisher Wiley
record_format Article
series Advances in Urology
spelling doaj-art-3103324abf43444d8521a1d40bbdb4182025-02-03T01:27:58ZengWileyAdvances in Urology1687-63691687-63772020-01-01202010.1155/2020/27827832782783Congenital Bladder and Urethral Agenesis: Two Case Reports and ManagementSalahaddin Delshad0Hadith Rastad1Parham Mardi2Department of Pediatric Surgery, School of Medicine, Iran University of Medical Sciences, Tehran, IranNon-Communicable Diseases Research Center, Alborz University of Medical Sciences, Karaj, IranStudent Research Committee, Alborz University of Medical Sciences, Karaj, IranBackground. Agenesis of the bladder and urethra is a rare congenital anomaly, with a very few living cases reported in the literature so far. Case Presentation. We are reporting two female patients (3 and 6 years old) with bladder and urethral agenesis who presented with urinary incontinence. In both patients, magnetic resonant imaging (MRI) revealed a case of bladder and urethral agenesis with normal ureters draining into the vagina. Patients underwent a neobladder and conduit creation surgery. The neobladder was constructed from the whole cecum and a part of the ascending colon, followed by an anastomose of the ureters into the neobladder in a nonrefluxing fashion; the appendix was used simultaneously as a continent catheterizable conduit. The two patients attained urinary continence postoperatively. Conclusion. We reported two cases of bladder agenesis, and for the first time, we have performed neobladder creation surgery using the cecum and ascending colon. One-year follow-up did not reveal any complications.http://dx.doi.org/10.1155/2020/2782783
spellingShingle Salahaddin Delshad
Hadith Rastad
Parham Mardi
Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
Advances in Urology
title Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title_full Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title_fullStr Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title_full_unstemmed Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title_short Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title_sort congenital bladder and urethral agenesis two case reports and management
url http://dx.doi.org/10.1155/2020/2782783
work_keys_str_mv AT salahaddindelshad congenitalbladderandurethralagenesistwocasereportsandmanagement
AT hadithrastad congenitalbladderandurethralagenesistwocasereportsandmanagement
AT parhammardi congenitalbladderandurethralagenesistwocasereportsandmanagement