A Rare Hardware-related Complication after Deep Brain Stimulation: Two Cases of Twiddler’s Syndrome

Twiddler’s syndrome is an uncommon complication of deep brain stimulation, arising from the inadvertent rotation of the implanted pulse generator, which results in lead coiling, displacement, or fracture. This results in stimulation failure and symptom recurrence, often necessitating surgical revisi...

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Main Authors: Iroda Mammadinova, Seitzhan Aidarov, Nurtay Nurakay, Yerbol Makhambetov, Chingiz Nurimanov
Format: Article
Language:English
Published: National Scientific Medical Center 2025-03-01
Series:Ķazaķstannyṇ Klinikalyķ Medicinasy
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Online Access:https://www.clinmedkaz.org/download/a-rare-hardware-related-complication-after-deep-brain-stimulation-two-cases-of-twiddlers-syndrome-16165.pdf
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author Iroda Mammadinova
Seitzhan Aidarov
Nurtay Nurakay
Yerbol Makhambetov
Chingiz Nurimanov
author_facet Iroda Mammadinova
Seitzhan Aidarov
Nurtay Nurakay
Yerbol Makhambetov
Chingiz Nurimanov
author_sort Iroda Mammadinova
collection DOAJ
description Twiddler’s syndrome is an uncommon complication of deep brain stimulation, arising from the inadvertent rotation of the implanted pulse generator, which results in lead coiling, displacement, or fracture. This results in stimulation failure and symptom recurrence, often necessitating surgical revision. While well-documented in cardiac devices, Twiddler’s syndrome remains infrequent in operations. Early diagnosis through radiographic imaging and impedance abnormalities is crucial for prompt intervention. We report two cases of Twiddler’s syndrome in patients with movement disorders: a 73-year-old male with Parkinson’s disease and a 55-year-old female with multifocal dystonia, both of whom had bilateral deep brain stimulation with left-sided dual-channel implanted pulse generator. After years of effective symptom control, both patients presented with worsening motor symptoms. Device examination revealed abnormal impedance readings, and imaging confirmed extensive lead coiling. Surgical revision was performed, including lead replacement and implanted pulse generator repositioning under the pectoralis fascia. Both patients demonstrated significant symptom improvement postoperatively, with restored impedance levels and functional recovery. Twiddler’s syndrome is a rare but critical complication of deep brain stimulation, leading to hardware failure and clinical deterioration. Early diagnosis through imaging and impedance monitoring is essential. Preventive strategies, including secure implanted pulse generator fixation and careful pocket sizing, are key to minimizing risk and improving patient outcomes.
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spelling doaj-art-2fde8bc7f05849a2bf71280eaf3521312025-08-20T02:25:37ZengNational Scientific Medical CenterĶazaķstannyṇ Klinikalyķ Medicinasy1812-28922313-15192025-03-01222505310.23950/jcmk/16165A Rare Hardware-related Complication after Deep Brain Stimulation: Two Cases of Twiddler’s SyndromeIroda Mammadinova0Seitzhan Aidarov1Nurtay Nurakay2Yerbol Makhambetov3Chingiz Nurimanov4Department of Vascular and Functional Neurosurgery, National Centre for Neurosurgery, Astana, Kazakhstan Department of Vascular and Functional Neurosurgery, National Centre for Neurosurgery, Astana, Kazakhstan Department of Vascular and Functional Neurosurgery, National Centre for Neurosurgery, Astana, Kazakhstan Department of Vascular and Functional Neurosurgery, National Centre for Neurosurgery, Astana, Kazakhstan Department of Vascular and Functional Neurosurgery, National Centre for Neurosurgery, Astana, Kazakhstan Twiddler’s syndrome is an uncommon complication of deep brain stimulation, arising from the inadvertent rotation of the implanted pulse generator, which results in lead coiling, displacement, or fracture. This results in stimulation failure and symptom recurrence, often necessitating surgical revision. While well-documented in cardiac devices, Twiddler’s syndrome remains infrequent in operations. Early diagnosis through radiographic imaging and impedance abnormalities is crucial for prompt intervention. We report two cases of Twiddler’s syndrome in patients with movement disorders: a 73-year-old male with Parkinson’s disease and a 55-year-old female with multifocal dystonia, both of whom had bilateral deep brain stimulation with left-sided dual-channel implanted pulse generator. After years of effective symptom control, both patients presented with worsening motor symptoms. Device examination revealed abnormal impedance readings, and imaging confirmed extensive lead coiling. Surgical revision was performed, including lead replacement and implanted pulse generator repositioning under the pectoralis fascia. Both patients demonstrated significant symptom improvement postoperatively, with restored impedance levels and functional recovery. Twiddler’s syndrome is a rare but critical complication of deep brain stimulation, leading to hardware failure and clinical deterioration. Early diagnosis through imaging and impedance monitoring is essential. Preventive strategies, including secure implanted pulse generator fixation and careful pocket sizing, are key to minimizing risk and improving patient outcomes.https://www.clinmedkaz.org/download/a-rare-hardware-related-complication-after-deep-brain-stimulation-two-cases-of-twiddlers-syndrome-16165.pdfdeep brain stimulationmovement disordersTwiddler’s syndromehardware complicationsextension fracture.
spellingShingle Iroda Mammadinova
Seitzhan Aidarov
Nurtay Nurakay
Yerbol Makhambetov
Chingiz Nurimanov
A Rare Hardware-related Complication after Deep Brain Stimulation: Two Cases of Twiddler’s Syndrome
Ķazaķstannyṇ Klinikalyķ Medicinasy
deep brain stimulation
movement disorders
Twiddler’s syndrome
hardware complications
extension fracture.
title A Rare Hardware-related Complication after Deep Brain Stimulation: Two Cases of Twiddler’s Syndrome
title_full A Rare Hardware-related Complication after Deep Brain Stimulation: Two Cases of Twiddler’s Syndrome
title_fullStr A Rare Hardware-related Complication after Deep Brain Stimulation: Two Cases of Twiddler’s Syndrome
title_full_unstemmed A Rare Hardware-related Complication after Deep Brain Stimulation: Two Cases of Twiddler’s Syndrome
title_short A Rare Hardware-related Complication after Deep Brain Stimulation: Two Cases of Twiddler’s Syndrome
title_sort rare hardware related complication after deep brain stimulation two cases of twiddler s syndrome
topic deep brain stimulation
movement disorders
Twiddler’s syndrome
hardware complications
extension fracture.
url https://www.clinmedkaz.org/download/a-rare-hardware-related-complication-after-deep-brain-stimulation-two-cases-of-twiddlers-syndrome-16165.pdf
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