Use of external control arms in immune-mediated inflammatory diseases: a systematic review

Objectives External control arms (ECAs) provide useful comparisons in clinical trials when randomised control arms are limited or not feasible. We conducted a systematic review to summarise applications of ECAs in trials of immune-mediated inflammatory diseases (IMIDs).Design Systematic review with...

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Main Authors: Brian G Feagan, Vipul Jairath, Claire E Parker, Christopher Ma, Siddharth Singh, John K MacDonald, Joshua Chang, Alexa Zayadi, Robert Edge, Blue Neustifter, Guowei Zhong
Format: Article
Language:English
Published: BMJ Publishing Group 2023-12-01
Series:BMJ Open
Online Access:https://bmjopen.bmj.com/content/13/12/e076677.full
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author Brian G Feagan
Vipul Jairath
Claire E Parker
Christopher Ma
Siddharth Singh
John K MacDonald
Joshua Chang
Alexa Zayadi
Robert Edge
Blue Neustifter
Guowei Zhong
author_facet Brian G Feagan
Vipul Jairath
Claire E Parker
Christopher Ma
Siddharth Singh
John K MacDonald
Joshua Chang
Alexa Zayadi
Robert Edge
Blue Neustifter
Guowei Zhong
author_sort Brian G Feagan
collection DOAJ
description Objectives External control arms (ECAs) provide useful comparisons in clinical trials when randomised control arms are limited or not feasible. We conducted a systematic review to summarise applications of ECAs in trials of immune-mediated inflammatory diseases (IMIDs).Design Systematic review with an appraisal of ECA source quality rated across five domains (data collection, study populations, outcome definitions, reliability and comprehensiveness of the dataset, and other potential limitations) as high, low or unclear quality.Data sources Embase, Medline and Cochrane Central Register of Controlled Trial were searched through to 12 September 2023.Eligibility criteria Eligible studies were single-arm or randomised controlled trials (RCTs) of inflammatory bowel disease, pouchitis, rheumatoid arthritis, juvenile idiopathic arthritis, ankylosing spondylitis, psoriatic arthritis, psoriasis and atopic dermatitis in which an ECA was used as the comparator.Data extraction and synthesis Two authors independently screened the search results in duplicate. The characteristics of included studies, external data source(s), outcomes and statistical methods were recorded, and the quality of the ECA data source was assessed by two independent authors.Results Forty-three studies met the inclusion criteria (inflammatory bowel disease: 16, pouchitis: 1, rheumatoid arthritis: 12, juvenile idiopathic arthritis: 1, ankylosing spondylitis: 5, psoriasis: 3, multiple indications: 4). The majority of these trials were single-arm (33/43) and enrolled adult patients (34/43). All included studies used a historical control rather than a contemporaneous ECA. In RCTs, ECAs were most often derived from the placebo arm of another RCT (6/10). In single-arm trials, historical case series were the most common ECA source (19/33). Most studies (31/43) did not employ a statistical approach to generate the ECA from historical data.Conclusions Standardised ECA methodology and reporting conventions are lacking for IMIDs trials. The establishment of ECA reporting guidelines may enhance the rigour and transparency of future research.
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spelling doaj-art-2fb6c4875b4541eaba967cfd101aff512025-08-20T03:10:56ZengBMJ Publishing GroupBMJ Open2044-60552023-12-01131210.1136/bmjopen-2023-076677Use of external control arms in immune-mediated inflammatory diseases: a systematic reviewBrian G Feagan0Vipul Jairath1Claire E Parker2Christopher Ma3Siddharth Singh4John K MacDonald5Joshua Chang6Alexa Zayadi7Robert Edge8Blue Neustifter9Guowei Zhong102 Alimentiv Inc, London, Ontario, CanadaDepartment of Epidemiology and Biostatistics, Western University, London, Ontario, CanadaAlimentiv Inc, London, Ontario, Canada18 Division of Gastroenterology and Hepatology, Cumming School of Medicine, University of Calgary, Calgary, Alberta, Canada1 Division of Gastroenterology, Department of Medicine, University of California San Diego, La Jolla, California, USAAlimentiv Inc, London, Ontario, CanadaAlimentiv Inc, London, Ontario, CanadaAlimentiv Inc, London, Ontario, CanadaAlimentiv Inc, London, Ontario, CanadaAlimentiv Inc, London, Ontario, CanadaAlimentiv Inc, London, Ontario, CanadaObjectives External control arms (ECAs) provide useful comparisons in clinical trials when randomised control arms are limited or not feasible. We conducted a systematic review to summarise applications of ECAs in trials of immune-mediated inflammatory diseases (IMIDs).Design Systematic review with an appraisal of ECA source quality rated across five domains (data collection, study populations, outcome definitions, reliability and comprehensiveness of the dataset, and other potential limitations) as high, low or unclear quality.Data sources Embase, Medline and Cochrane Central Register of Controlled Trial were searched through to 12 September 2023.Eligibility criteria Eligible studies were single-arm or randomised controlled trials (RCTs) of inflammatory bowel disease, pouchitis, rheumatoid arthritis, juvenile idiopathic arthritis, ankylosing spondylitis, psoriatic arthritis, psoriasis and atopic dermatitis in which an ECA was used as the comparator.Data extraction and synthesis Two authors independently screened the search results in duplicate. The characteristics of included studies, external data source(s), outcomes and statistical methods were recorded, and the quality of the ECA data source was assessed by two independent authors.Results Forty-three studies met the inclusion criteria (inflammatory bowel disease: 16, pouchitis: 1, rheumatoid arthritis: 12, juvenile idiopathic arthritis: 1, ankylosing spondylitis: 5, psoriasis: 3, multiple indications: 4). The majority of these trials were single-arm (33/43) and enrolled adult patients (34/43). All included studies used a historical control rather than a contemporaneous ECA. In RCTs, ECAs were most often derived from the placebo arm of another RCT (6/10). In single-arm trials, historical case series were the most common ECA source (19/33). Most studies (31/43) did not employ a statistical approach to generate the ECA from historical data.Conclusions Standardised ECA methodology and reporting conventions are lacking for IMIDs trials. The establishment of ECA reporting guidelines may enhance the rigour and transparency of future research.https://bmjopen.bmj.com/content/13/12/e076677.full
spellingShingle Brian G Feagan
Vipul Jairath
Claire E Parker
Christopher Ma
Siddharth Singh
John K MacDonald
Joshua Chang
Alexa Zayadi
Robert Edge
Blue Neustifter
Guowei Zhong
Use of external control arms in immune-mediated inflammatory diseases: a systematic review
BMJ Open
title Use of external control arms in immune-mediated inflammatory diseases: a systematic review
title_full Use of external control arms in immune-mediated inflammatory diseases: a systematic review
title_fullStr Use of external control arms in immune-mediated inflammatory diseases: a systematic review
title_full_unstemmed Use of external control arms in immune-mediated inflammatory diseases: a systematic review
title_short Use of external control arms in immune-mediated inflammatory diseases: a systematic review
title_sort use of external control arms in immune mediated inflammatory diseases a systematic review
url https://bmjopen.bmj.com/content/13/12/e076677.full
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