Difficulties of Management of Multiple Synchronous Bone Tumors in Li-Fraumeni Syndrome

Li-Fraumeni syndrome is a rare inherited disease characterized by the early onset of multiple primary malignant tumors. Sarcomas account for more than 30% of all malignant tumors occurring at pediatric age. Furthermore, it was shown that the rates of second cancer were higher in childhood cancer sur...

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Main Authors: Marine Huby, Laurence Brugières, Eric Mascard, Nathalie Gaspar, Stéphanie Pannier, Jean-Charles Aurégan
Format: Article
Language:English
Published: Wiley 2019-01-01
Series:Case Reports in Orthopedics
Online Access:http://dx.doi.org/10.1155/2019/8732089
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author Marine Huby
Laurence Brugières
Eric Mascard
Nathalie Gaspar
Stéphanie Pannier
Jean-Charles Aurégan
author_facet Marine Huby
Laurence Brugières
Eric Mascard
Nathalie Gaspar
Stéphanie Pannier
Jean-Charles Aurégan
author_sort Marine Huby
collection DOAJ
description Li-Fraumeni syndrome is a rare inherited disease characterized by the early onset of multiple primary malignant tumors. Sarcomas account for more than 30% of all malignant tumors occurring at pediatric age. Furthermore, it was shown that the rates of second cancer were higher in childhood cancer survivors. We report the case of a patient with Li-Fraumeni syndrome who was referred to us with three synchronous skeletal tumors. This unique situation led to difficulties for the medical team regarding the diagnosis of malignancy and the surgical treatment to propose. The discovery of multiple lesions in the extension assessment underlines the usefulness of whole-body imaging for the follow-up of patients with germline TP53 mutations. Most recent guidelines now recommend annual whole-body MRI for screening for cancer patients carrying germline TP53. With this report, we aim to share our experience with this rare situation in order to improve care about these specific cases.
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institution Kabale University
issn 2090-6749
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publishDate 2019-01-01
publisher Wiley
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series Case Reports in Orthopedics
spelling doaj-art-2f3eb36719734812a4109c731ea72d962025-08-20T03:55:16ZengWileyCase Reports in Orthopedics2090-67492090-67572019-01-01201910.1155/2019/87320898732089Difficulties of Management of Multiple Synchronous Bone Tumors in Li-Fraumeni SyndromeMarine Huby0Laurence Brugières1Eric Mascard2Nathalie Gaspar3Stéphanie Pannier4Jean-Charles Aurégan5Department of Pediatric Orthopedics, Necker-Enfants Malades Hospital, AP-HP, University Paris Descartes, 149 Rue de Sèvres, 75014 Paris, FranceDepartment of Pediatric and Adolescents Oncology, Gustave Roussy Cancer Campus, Paris Saclay-University, 114 Rue Édouard Vaillant, 94800 Villejuif, FranceDepartment of Pediatric Orthopedics, Necker-Enfants Malades Hospital, AP-HP, University Paris Descartes, 149 Rue de Sèvres, 75014 Paris, FranceDepartment of Pediatric and Adolescents Oncology, Gustave Roussy Cancer Campus, Paris Saclay-University, 114 Rue Édouard Vaillant, 94800 Villejuif, FranceDepartment of Pediatric Orthopedics, Necker-Enfants Malades Hospital, AP-HP, University Paris Descartes, 149 Rue de Sèvres, 75014 Paris, FranceDepartment of Pediatric Orthopedics, Necker-Enfants Malades Hospital, AP-HP, University Paris Descartes, 149 Rue de Sèvres, 75014 Paris, FranceLi-Fraumeni syndrome is a rare inherited disease characterized by the early onset of multiple primary malignant tumors. Sarcomas account for more than 30% of all malignant tumors occurring at pediatric age. Furthermore, it was shown that the rates of second cancer were higher in childhood cancer survivors. We report the case of a patient with Li-Fraumeni syndrome who was referred to us with three synchronous skeletal tumors. This unique situation led to difficulties for the medical team regarding the diagnosis of malignancy and the surgical treatment to propose. The discovery of multiple lesions in the extension assessment underlines the usefulness of whole-body imaging for the follow-up of patients with germline TP53 mutations. Most recent guidelines now recommend annual whole-body MRI for screening for cancer patients carrying germline TP53. With this report, we aim to share our experience with this rare situation in order to improve care about these specific cases.http://dx.doi.org/10.1155/2019/8732089
spellingShingle Marine Huby
Laurence Brugières
Eric Mascard
Nathalie Gaspar
Stéphanie Pannier
Jean-Charles Aurégan
Difficulties of Management of Multiple Synchronous Bone Tumors in Li-Fraumeni Syndrome
Case Reports in Orthopedics
title Difficulties of Management of Multiple Synchronous Bone Tumors in Li-Fraumeni Syndrome
title_full Difficulties of Management of Multiple Synchronous Bone Tumors in Li-Fraumeni Syndrome
title_fullStr Difficulties of Management of Multiple Synchronous Bone Tumors in Li-Fraumeni Syndrome
title_full_unstemmed Difficulties of Management of Multiple Synchronous Bone Tumors in Li-Fraumeni Syndrome
title_short Difficulties of Management of Multiple Synchronous Bone Tumors in Li-Fraumeni Syndrome
title_sort difficulties of management of multiple synchronous bone tumors in li fraumeni syndrome
url http://dx.doi.org/10.1155/2019/8732089
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