Teprotumumab and sensorineural hearing loss: a propensity score-matched retrospective cohort study

Teprotumumab, a monoclonal antibody that antagonizes the insulin-like growth factor 1 receptor, is the first medication within the United States to receive Food and Drug Administration (FDA) approval for thyroid eye disease (TED). The FDA recently issued a warning regarding otologic complications, s...

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Main Authors: Maxim John Levy Barnett, Justin Lam, Mikaela Nikkola Jara-Tantoco, Carlo Casipit, Sarah Eidbo, Catherine Anastasopoulou
Format: Article
Language:English
Published: Bioscientifica 2025-07-01
Series:Endocrine Connections
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Online Access:https://ec.bioscientifica.com/view/journals/ec/14/7/EC-25-0293.xml
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author Maxim John Levy Barnett
Justin Lam
Mikaela Nikkola Jara-Tantoco
Carlo Casipit
Sarah Eidbo
Catherine Anastasopoulou
author_facet Maxim John Levy Barnett
Justin Lam
Mikaela Nikkola Jara-Tantoco
Carlo Casipit
Sarah Eidbo
Catherine Anastasopoulou
author_sort Maxim John Levy Barnett
collection DOAJ
description Teprotumumab, a monoclonal antibody that antagonizes the insulin-like growth factor 1 receptor, is the first medication within the United States to receive Food and Drug Administration (FDA) approval for thyroid eye disease (TED). The FDA recently issued a warning regarding otologic complications, such as hearing loss. We aimed to study the association between teprotumumab and sensorineural hearing loss in thyrotoxic patients with TED. A real-world retrospective cohort study was performed through the TriNetX Collaborative Network (globally de-identified database) over a 5-year period. Inclusion criteria were patients at least 18 years of age with a diagnosis of Graves’ disease and TED, and were stratified into two cohorts: those treated with teprotumumab and those who were not. Propensity score-matching was performed for an even balance among cohorts (adjusting for age, sex, race, ethnicity, comorbidities, medications, smoking, and laboratory values), providing 532 patients per cohort. We identified a significantly higher risk difference of sensorineural hearing loss in patients treated with teprotumumab compared to those without exposure (risk difference 8.415%, 95% CI 4.954–11.876; 12.222 versus 3.808%), with a near three-fold increased relative risk for acquiring sensorineural hearing loss (risk ratio 3.21, 95% CI 1.936–5.323, P < 0.0001) over a 5-year period. Although the mechanism of teprotumumab-induced hearing loss remains unknown, and there is a lack of data to identify patients at risk (or those more likely to recover), our study confirms a higher risk for sensorineural hearing loss, which patients and providers alike must be aware of. Further studies providing prospective data are required to confirm such findings.
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spelling doaj-art-25ccf1e1afaf46e99edf176ca964089f2025-08-20T03:44:28ZengBioscientificaEndocrine Connections2049-36142025-07-0114710.1530/EC-25-02931Teprotumumab and sensorineural hearing loss: a propensity score-matched retrospective cohort studyMaxim John Levy Barnett0Justin Lam1Mikaela Nikkola Jara-Tantoco2Carlo Casipit3Sarah Eidbo4Catherine Anastasopoulou5Jefferson-Einstein Hospital, Internal Medicine, Philadelphia, Pennsylvania, USAJefferson-Einstein Hospital, Internal Medicine, Philadelphia, Pennsylvania, USAJefferson-Einstein Hospital, Internal Medicine, Philadelphia, Pennsylvania, USAJefferson-Einstein Hospital, Internal Medicine, Philadelphia, Pennsylvania, USAJefferson-Einstein Hospital, Internal Medicine, Philadelphia, Pennsylvania, USAJefferson-Einstein Hospital, Endocrinology, Diabetes & Metabolism, Philadelphia, Pennsylvania, USATeprotumumab, a monoclonal antibody that antagonizes the insulin-like growth factor 1 receptor, is the first medication within the United States to receive Food and Drug Administration (FDA) approval for thyroid eye disease (TED). The FDA recently issued a warning regarding otologic complications, such as hearing loss. We aimed to study the association between teprotumumab and sensorineural hearing loss in thyrotoxic patients with TED. A real-world retrospective cohort study was performed through the TriNetX Collaborative Network (globally de-identified database) over a 5-year period. Inclusion criteria were patients at least 18 years of age with a diagnosis of Graves’ disease and TED, and were stratified into two cohorts: those treated with teprotumumab and those who were not. Propensity score-matching was performed for an even balance among cohorts (adjusting for age, sex, race, ethnicity, comorbidities, medications, smoking, and laboratory values), providing 532 patients per cohort. We identified a significantly higher risk difference of sensorineural hearing loss in patients treated with teprotumumab compared to those without exposure (risk difference 8.415%, 95% CI 4.954–11.876; 12.222 versus 3.808%), with a near three-fold increased relative risk for acquiring sensorineural hearing loss (risk ratio 3.21, 95% CI 1.936–5.323, P < 0.0001) over a 5-year period. Although the mechanism of teprotumumab-induced hearing loss remains unknown, and there is a lack of data to identify patients at risk (or those more likely to recover), our study confirms a higher risk for sensorineural hearing loss, which patients and providers alike must be aware of. Further studies providing prospective data are required to confirm such findings.https://ec.bioscientifica.com/view/journals/ec/14/7/EC-25-0293.xmlteprotumumabsensorineural hearing lossthyroid eye diseasegraves’ ophthalmopathy
spellingShingle Maxim John Levy Barnett
Justin Lam
Mikaela Nikkola Jara-Tantoco
Carlo Casipit
Sarah Eidbo
Catherine Anastasopoulou
Teprotumumab and sensorineural hearing loss: a propensity score-matched retrospective cohort study
Endocrine Connections
teprotumumab
sensorineural hearing loss
thyroid eye disease
graves’ ophthalmopathy
title Teprotumumab and sensorineural hearing loss: a propensity score-matched retrospective cohort study
title_full Teprotumumab and sensorineural hearing loss: a propensity score-matched retrospective cohort study
title_fullStr Teprotumumab and sensorineural hearing loss: a propensity score-matched retrospective cohort study
title_full_unstemmed Teprotumumab and sensorineural hearing loss: a propensity score-matched retrospective cohort study
title_short Teprotumumab and sensorineural hearing loss: a propensity score-matched retrospective cohort study
title_sort teprotumumab and sensorineural hearing loss a propensity score matched retrospective cohort study
topic teprotumumab
sensorineural hearing loss
thyroid eye disease
graves’ ophthalmopathy
url https://ec.bioscientifica.com/view/journals/ec/14/7/EC-25-0293.xml
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