Autoreactive Antibodies Associated with Castleman Disease Triad

The Castleman triad has been described in a select few patients presenting with a retroperitoneal mass, mucocutaneous pemphigus vulgaris, and bronchiolitis obliterans. Here, we describe the Castleman triad in a 19-year-old male with unicentric hyaline vascular type Castleman disease (HV-CD). This pa...

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Main Authors: Jacqueline A. Turner, Ali Hakimi, Hannah Lee, Jeffrey T. Schowinsky, Jeffrey M. Sippel, Bradford J. Siegele, Raul M. Torres, William A. Robinson
Format: Article
Language:English
Published: Wiley 2024-01-01
Series:Case Reports in Immunology
Online Access:http://dx.doi.org/10.1155/2024/9382107
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author Jacqueline A. Turner
Ali Hakimi
Hannah Lee
Jeffrey T. Schowinsky
Jeffrey M. Sippel
Bradford J. Siegele
Raul M. Torres
William A. Robinson
author_facet Jacqueline A. Turner
Ali Hakimi
Hannah Lee
Jeffrey T. Schowinsky
Jeffrey M. Sippel
Bradford J. Siegele
Raul M. Torres
William A. Robinson
author_sort Jacqueline A. Turner
collection DOAJ
description The Castleman triad has been described in a select few patients presenting with a retroperitoneal mass, mucocutaneous pemphigus vulgaris, and bronchiolitis obliterans. Here, we describe the Castleman triad in a 19-year-old male with unicentric hyaline vascular type Castleman disease (HV-CD). This patient presented with an array of positive antibodies, including anti-cyclic citrullinated peptide, anti-double-stranded DNA, and Sjogren’s IgG. Interestingly, the patient’s rheumatologic symptoms resolved after tumor resection, while his antibody profile remained relatively unchanged. HV-CD, with a triad presentation, was thought to be from a paraneoplastic syndrome secondary to an underlying lymphoproliferative disorder. The findings presented here identify multiple autoantibodies potentially contributing to this patient’s presentation with HV-CD.
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series Case Reports in Immunology
spelling doaj-art-1e69e9c95320442ea9383cccec73152c2025-08-20T02:03:47ZengWileyCase Reports in Immunology2090-66172024-01-01202410.1155/2024/9382107Autoreactive Antibodies Associated with Castleman Disease TriadJacqueline A. Turner0Ali Hakimi1Hannah Lee2Jeffrey T. Schowinsky3Jeffrey M. Sippel4Bradford J. Siegele5Raul M. Torres6William A. Robinson7Division of Medical OncologyUniversity of Colorado Anschutz School of MedicineDivision of Hematology and OncologyDepartment of PathologyDivision of PulmonologyDepartment of PathologyDepartment of Immunology and MicrobiologyDivision of Medical OncologyThe Castleman triad has been described in a select few patients presenting with a retroperitoneal mass, mucocutaneous pemphigus vulgaris, and bronchiolitis obliterans. Here, we describe the Castleman triad in a 19-year-old male with unicentric hyaline vascular type Castleman disease (HV-CD). This patient presented with an array of positive antibodies, including anti-cyclic citrullinated peptide, anti-double-stranded DNA, and Sjogren’s IgG. Interestingly, the patient’s rheumatologic symptoms resolved after tumor resection, while his antibody profile remained relatively unchanged. HV-CD, with a triad presentation, was thought to be from a paraneoplastic syndrome secondary to an underlying lymphoproliferative disorder. The findings presented here identify multiple autoantibodies potentially contributing to this patient’s presentation with HV-CD.http://dx.doi.org/10.1155/2024/9382107
spellingShingle Jacqueline A. Turner
Ali Hakimi
Hannah Lee
Jeffrey T. Schowinsky
Jeffrey M. Sippel
Bradford J. Siegele
Raul M. Torres
William A. Robinson
Autoreactive Antibodies Associated with Castleman Disease Triad
Case Reports in Immunology
title Autoreactive Antibodies Associated with Castleman Disease Triad
title_full Autoreactive Antibodies Associated with Castleman Disease Triad
title_fullStr Autoreactive Antibodies Associated with Castleman Disease Triad
title_full_unstemmed Autoreactive Antibodies Associated with Castleman Disease Triad
title_short Autoreactive Antibodies Associated with Castleman Disease Triad
title_sort autoreactive antibodies associated with castleman disease triad
url http://dx.doi.org/10.1155/2024/9382107
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AT jeffreymsippel autoreactiveantibodiesassociatedwithcastlemandiseasetriad
AT bradfordjsiegele autoreactiveantibodiesassociatedwithcastlemandiseasetriad
AT raulmtorres autoreactiveantibodiesassociatedwithcastlemandiseasetriad
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