Oculodentodigital Dysplasia Presenting as Spastic Ataxic Syndrome in an Indian Patient

Spastic ataxic syndrome is a combination of cerebellar ataxia with spasticity and other pyramidal features. Common causes of spastic ataxic syndrome include spinocerebellar ataxia (SCA) 1, SCA2, autosomal recessive ataxia of Charlevoix–Saguenay, Friedreich ataxia, and hereditary spastic paraplegia t...

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Main Authors: Gosala RK Sarma, Abhinaya Varidireddy, GG Sharath, Sunitha P Kumaran
Format: Article
Language:English
Published: Wolters Kluwer Medknow Publications 2025-01-01
Series:Annals of Indian Academy of Neurology
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Online Access:https://journals.lww.com/10.4103/aian.aian_166_24
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author Gosala RK Sarma
Abhinaya Varidireddy
GG Sharath
Sunitha P Kumaran
author_facet Gosala RK Sarma
Abhinaya Varidireddy
GG Sharath
Sunitha P Kumaran
author_sort Gosala RK Sarma
collection DOAJ
description Spastic ataxic syndrome is a combination of cerebellar ataxia with spasticity and other pyramidal features. Common causes of spastic ataxic syndrome include spinocerebellar ataxia (SCA) 1, SCA2, autosomal recessive ataxia of Charlevoix–Saguenay, Friedreich ataxia, and hereditary spastic paraplegia type-7. We report a 32-year-old female who presented with unsteadiness of gait, incoordination, and tremulousness of both hands for 10 years with microphthalmia, microdontia, dental caries, and syndactyly. Magnetic resonance imaging of the brain showed T2 fluid-attenuated inversion recovery hyper intensities in periventricular and lobar white matter and internal capsule. Thus, we report a genetically confirmed oculodentodigital dysplasia (ODDD), an autosomal dominant disorder, in an Indian patient who presented with spastic ataxic syndrome, a rarity that has not been reported so far.
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1998-3549
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publishDate 2025-01-01
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series Annals of Indian Academy of Neurology
spelling doaj-art-14ced86cad234a2a9c1a2d19db6c85cf2025-08-20T03:02:06ZengWolters Kluwer Medknow PublicationsAnnals of Indian Academy of Neurology0972-23271998-35492025-01-0128111211510.4103/aian.aian_166_24Oculodentodigital Dysplasia Presenting as Spastic Ataxic Syndrome in an Indian PatientGosala RK SarmaAbhinaya VaridireddyGG SharathSunitha P KumaranSpastic ataxic syndrome is a combination of cerebellar ataxia with spasticity and other pyramidal features. Common causes of spastic ataxic syndrome include spinocerebellar ataxia (SCA) 1, SCA2, autosomal recessive ataxia of Charlevoix–Saguenay, Friedreich ataxia, and hereditary spastic paraplegia type-7. We report a 32-year-old female who presented with unsteadiness of gait, incoordination, and tremulousness of both hands for 10 years with microphthalmia, microdontia, dental caries, and syndactyly. Magnetic resonance imaging of the brain showed T2 fluid-attenuated inversion recovery hyper intensities in periventricular and lobar white matter and internal capsule. Thus, we report a genetically confirmed oculodentodigital dysplasia (ODDD), an autosomal dominant disorder, in an Indian patient who presented with spastic ataxic syndrome, a rarity that has not been reported so far.https://journals.lww.com/10.4103/aian.aian_166_24ataxiamicrodontiaoculodentodigital dysplasiaspastic ataxic syndromespasticitysyndactyly
spellingShingle Gosala RK Sarma
Abhinaya Varidireddy
GG Sharath
Sunitha P Kumaran
Oculodentodigital Dysplasia Presenting as Spastic Ataxic Syndrome in an Indian Patient
Annals of Indian Academy of Neurology
ataxia
microdontia
oculodentodigital dysplasia
spastic ataxic syndrome
spasticity
syndactyly
title Oculodentodigital Dysplasia Presenting as Spastic Ataxic Syndrome in an Indian Patient
title_full Oculodentodigital Dysplasia Presenting as Spastic Ataxic Syndrome in an Indian Patient
title_fullStr Oculodentodigital Dysplasia Presenting as Spastic Ataxic Syndrome in an Indian Patient
title_full_unstemmed Oculodentodigital Dysplasia Presenting as Spastic Ataxic Syndrome in an Indian Patient
title_short Oculodentodigital Dysplasia Presenting as Spastic Ataxic Syndrome in an Indian Patient
title_sort oculodentodigital dysplasia presenting as spastic ataxic syndrome in an indian patient
topic ataxia
microdontia
oculodentodigital dysplasia
spastic ataxic syndrome
spasticity
syndactyly
url https://journals.lww.com/10.4103/aian.aian_166_24
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AT ggsharath oculodentodigitaldysplasiapresentingasspasticataxicsyndromeinanindianpatient
AT sunithapkumaran oculodentodigitaldysplasiapresentingasspasticataxicsyndromeinanindianpatient