Paired box 6 gene delivery preserves beta cells and improves islet transplantation efficacy

Abstract Loss of pancreatic beta cells is the central feature of all forms of diabetes. Current therapies fail to halt the declined beta cell mass. Thus, strategies to preserve beta cells are imperatively needed. In this study, we identified paired box 6 (PAX6) as a critical regulator of beta cell s...

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Main Authors: Wing Yan So, Yilie Liao, Wai Nam Liu, Guy A Rutter, Weiping Han
Format: Article
Language:English
Published: Springer Nature 2023-11-01
Series:EMBO Molecular Medicine
Subjects:
Online Access:https://doi.org/10.15252/emmm.202317928
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author Wing Yan So
Yilie Liao
Wai Nam Liu
Guy A Rutter
Weiping Han
author_facet Wing Yan So
Yilie Liao
Wai Nam Liu
Guy A Rutter
Weiping Han
author_sort Wing Yan So
collection DOAJ
description Abstract Loss of pancreatic beta cells is the central feature of all forms of diabetes. Current therapies fail to halt the declined beta cell mass. Thus, strategies to preserve beta cells are imperatively needed. In this study, we identified paired box 6 (PAX6) as a critical regulator of beta cell survival. Under diabetic conditions, the human beta cell line EndoC‐βH1, db/db mouse and human islets displayed dampened insulin and incretin signalings and reduced beta cell survival, which were alleviated by PAX6 overexpression. Adeno‐associated virus (AAV)‐mediated PAX6 overexpression in beta cells of streptozotocin‐induced diabetic mice and db/db mice led to a sustained maintenance of glucose homeostasis. AAV‐PAX6 transduction in human islets reduced islet graft loss and improved glycemic control after transplantation into immunodeficient diabetic mice. Our study highlights a previously unappreciated role for PAX6 in beta cell survival and raises the possibility that ex vivo PAX6 gene transfer into islets prior to transplantation might enhance islet graft function and transplantation outcome.
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publishDate 2023-11-01
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spelling doaj-art-135e3d13ea6e412ba77f578d5de7bd632025-08-20T03:06:00ZengSpringer NatureEMBO Molecular Medicine1757-46761757-46842023-11-01151212010.15252/emmm.202317928Paired box 6 gene delivery preserves beta cells and improves islet transplantation efficacyWing Yan So0Yilie Liao1Wai Nam Liu2Guy A Rutter3Weiping Han4Institute of Molecular and Cell Biology (IMCB), Agency for Science, Technology and Research (A*STAR)Institute of Molecular and Cell Biology (IMCB), Agency for Science, Technology and Research (A*STAR)Institute of Molecular and Cell Biology (IMCB), Agency for Science, Technology and Research (A*STAR)Centre de Recherche du CHUM, Faculté de Médicine, Université de MontréalInstitute of Molecular and Cell Biology (IMCB), Agency for Science, Technology and Research (A*STAR)Abstract Loss of pancreatic beta cells is the central feature of all forms of diabetes. Current therapies fail to halt the declined beta cell mass. Thus, strategies to preserve beta cells are imperatively needed. In this study, we identified paired box 6 (PAX6) as a critical regulator of beta cell survival. Under diabetic conditions, the human beta cell line EndoC‐βH1, db/db mouse and human islets displayed dampened insulin and incretin signalings and reduced beta cell survival, which were alleviated by PAX6 overexpression. Adeno‐associated virus (AAV)‐mediated PAX6 overexpression in beta cells of streptozotocin‐induced diabetic mice and db/db mice led to a sustained maintenance of glucose homeostasis. AAV‐PAX6 transduction in human islets reduced islet graft loss and improved glycemic control after transplantation into immunodeficient diabetic mice. Our study highlights a previously unappreciated role for PAX6 in beta cell survival and raises the possibility that ex vivo PAX6 gene transfer into islets prior to transplantation might enhance islet graft function and transplantation outcome.https://doi.org/10.15252/emmm.202317928AAVbeta cellsdiabetesislet transplantPAX6
spellingShingle Wing Yan So
Yilie Liao
Wai Nam Liu
Guy A Rutter
Weiping Han
Paired box 6 gene delivery preserves beta cells and improves islet transplantation efficacy
EMBO Molecular Medicine
AAV
beta cells
diabetes
islet transplant
PAX6
title Paired box 6 gene delivery preserves beta cells and improves islet transplantation efficacy
title_full Paired box 6 gene delivery preserves beta cells and improves islet transplantation efficacy
title_fullStr Paired box 6 gene delivery preserves beta cells and improves islet transplantation efficacy
title_full_unstemmed Paired box 6 gene delivery preserves beta cells and improves islet transplantation efficacy
title_short Paired box 6 gene delivery preserves beta cells and improves islet transplantation efficacy
title_sort paired box 6 gene delivery preserves beta cells and improves islet transplantation efficacy
topic AAV
beta cells
diabetes
islet transplant
PAX6
url https://doi.org/10.15252/emmm.202317928
work_keys_str_mv AT wingyanso pairedbox6genedeliverypreservesbetacellsandimprovesislettransplantationefficacy
AT yilieliao pairedbox6genedeliverypreservesbetacellsandimprovesislettransplantationefficacy
AT wainamliu pairedbox6genedeliverypreservesbetacellsandimprovesislettransplantationefficacy
AT guyarutter pairedbox6genedeliverypreservesbetacellsandimprovesislettransplantationefficacy
AT weipinghan pairedbox6genedeliverypreservesbetacellsandimprovesislettransplantationefficacy