Apocynin, a Selective NADPH Oxidase (Nox2) Inhibitor, Ameliorates Behavioural and Learning Deficits in the Fragile X Syndrome Mouse Model

<b>Background/Objectives:</b> Fragile X Syndrome (FXS) is associated with intellectual disability, hyperactivity, social anxiety and signs of autism. Hyperactivation of NADPH oxidase has been previously described in the brain of the male <i>Fmr1</i>-KO mouse. This work aims t...

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Main Authors: Yolanda de Diego-Otero, Rajaa El Bekay, Francisco García-Guirado, Lourdes Sánchez-Salido, Rosa María Giráldez-Pérez
Format: Article
Language:English
Published: MDPI AG 2024-12-01
Series:Biomedicines
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Online Access:https://www.mdpi.com/2227-9059/12/12/2887
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author Yolanda de Diego-Otero
Rajaa El Bekay
Francisco García-Guirado
Lourdes Sánchez-Salido
Rosa María Giráldez-Pérez
author_facet Yolanda de Diego-Otero
Rajaa El Bekay
Francisco García-Guirado
Lourdes Sánchez-Salido
Rosa María Giráldez-Pérez
author_sort Yolanda de Diego-Otero
collection DOAJ
description <b>Background/Objectives:</b> Fragile X Syndrome (FXS) is associated with intellectual disability, hyperactivity, social anxiety and signs of autism. Hyperactivation of NADPH oxidase has been previously described in the brain of the male <i>Fmr1</i>-KO mouse. This work aims to demonstrate the efficacy of Apocynin, a specific NADPH oxidase inhibitor, in treating Fragile X mouse hallmarks. <b>Methods:</b> Free radicals, lipid and protein oxidation markers and behavioural and learning paradigms were measured after chronic treatment with orally administered vehicle, 10 mg/kg/day or 30 mg/kg/day of Apocynin. <b>Results</b>: The results revealed a reduction in testis weight, an increase in peritoneal fat, and no variation in body weight after chronic treatment. Furthermore, a reduction in hyperactivity was detected in Apocynin-treated male Fmr1-KO mice. Additionally, the higher dose of 30 mg/kg/day also improves behaviour and learning in the male Fmr1-KO mice, normalising free radical production and oxidative parameters. Moreover, a reduction in phospho-EKR1 and P47-Phox protein signals was observed in specific brain areas. <b>Conclusions</b>: Thus, chronic treatment with Apocynin could lead to a new therapeutic option for the Fragile X Syndrome.
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spelling doaj-art-10c5560fcd1f4b68bdb8d88268e65cc12025-08-20T02:53:27ZengMDPI AGBiomedicines2227-90592024-12-011212288710.3390/biomedicines12122887Apocynin, a Selective NADPH Oxidase (Nox2) Inhibitor, Ameliorates Behavioural and Learning Deficits in the Fragile X Syndrome Mouse ModelYolanda de Diego-Otero0Rajaa El Bekay1Francisco García-Guirado2Lourdes Sánchez-Salido3Rosa María Giráldez-Pérez4Cellular Biology, Physiology and Immunology Department, University of Córdoba, 14014 Córdoba, SpainResearch Laboratory, Instituto de Investigación Biomédica de Málaga y Plataforma en Nanomedicina-IBIMA Plataforma BIO-NAND, Hospital Civil, 29009 Malaga, SpainResearch Laboratory, Instituto de Investigación Biomédica de Málaga y Plataforma en Nanomedicina-IBIMA Plataforma BIO-NAND, Hospital Civil, 29009 Malaga, SpainResearch Laboratory, Instituto de Investigación Biomédica de Málaga y Plataforma en Nanomedicina-IBIMA Plataforma BIO-NAND, Hospital Civil, 29009 Malaga, SpainCellular Biology, Physiology and Immunology Department, University of Córdoba, 14014 Córdoba, Spain<b>Background/Objectives:</b> Fragile X Syndrome (FXS) is associated with intellectual disability, hyperactivity, social anxiety and signs of autism. Hyperactivation of NADPH oxidase has been previously described in the brain of the male <i>Fmr1</i>-KO mouse. This work aims to demonstrate the efficacy of Apocynin, a specific NADPH oxidase inhibitor, in treating Fragile X mouse hallmarks. <b>Methods:</b> Free radicals, lipid and protein oxidation markers and behavioural and learning paradigms were measured after chronic treatment with orally administered vehicle, 10 mg/kg/day or 30 mg/kg/day of Apocynin. <b>Results</b>: The results revealed a reduction in testis weight, an increase in peritoneal fat, and no variation in body weight after chronic treatment. Furthermore, a reduction in hyperactivity was detected in Apocynin-treated male Fmr1-KO mice. Additionally, the higher dose of 30 mg/kg/day also improves behaviour and learning in the male Fmr1-KO mice, normalising free radical production and oxidative parameters. Moreover, a reduction in phospho-EKR1 and P47-Phox protein signals was observed in specific brain areas. <b>Conclusions</b>: Thus, chronic treatment with Apocynin could lead to a new therapeutic option for the Fragile X Syndrome.https://www.mdpi.com/2227-9059/12/12/2887fragile X syndromeApocyninNADPH-oxidasehyperactivitybehaviourlearning
spellingShingle Yolanda de Diego-Otero
Rajaa El Bekay
Francisco García-Guirado
Lourdes Sánchez-Salido
Rosa María Giráldez-Pérez
Apocynin, a Selective NADPH Oxidase (Nox2) Inhibitor, Ameliorates Behavioural and Learning Deficits in the Fragile X Syndrome Mouse Model
Biomedicines
fragile X syndrome
Apocynin
NADPH-oxidase
hyperactivity
behaviour
learning
title Apocynin, a Selective NADPH Oxidase (Nox2) Inhibitor, Ameliorates Behavioural and Learning Deficits in the Fragile X Syndrome Mouse Model
title_full Apocynin, a Selective NADPH Oxidase (Nox2) Inhibitor, Ameliorates Behavioural and Learning Deficits in the Fragile X Syndrome Mouse Model
title_fullStr Apocynin, a Selective NADPH Oxidase (Nox2) Inhibitor, Ameliorates Behavioural and Learning Deficits in the Fragile X Syndrome Mouse Model
title_full_unstemmed Apocynin, a Selective NADPH Oxidase (Nox2) Inhibitor, Ameliorates Behavioural and Learning Deficits in the Fragile X Syndrome Mouse Model
title_short Apocynin, a Selective NADPH Oxidase (Nox2) Inhibitor, Ameliorates Behavioural and Learning Deficits in the Fragile X Syndrome Mouse Model
title_sort apocynin a selective nadph oxidase nox2 inhibitor ameliorates behavioural and learning deficits in the fragile x syndrome mouse model
topic fragile X syndrome
Apocynin
NADPH-oxidase
hyperactivity
behaviour
learning
url https://www.mdpi.com/2227-9059/12/12/2887
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