Gait characteristics in people with Friedreich ataxia: daily life versus clinic measures

IntroductionGait assessments in a clinical setting may not accurately reflect mobility in everyday life. To better understand gait during daily life, we compared measures that discriminated Friedreich ataxia (FRDA) from healthy control (HC) subjects in prescribed clinic tests and free, daily-life mo...

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Main Authors: Hannah L. Casey, Vrutangkumar V. Shah, Daniel Muzyka, James McNames, Mahmoud El-Gohary, Kristen Sowalsky, Delaram Safarpour, Patricia Carlson-Kuhta, Christian Rummey, Fay B. Horak, Christopher M. Gomez
Format: Article
Language:English
Published: Frontiers Media S.A. 2025-03-01
Series:Frontiers in Neurology
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Online Access:https://www.frontiersin.org/articles/10.3389/fneur.2025.1544453/full
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author Hannah L. Casey
Vrutangkumar V. Shah
Vrutangkumar V. Shah
Daniel Muzyka
James McNames
James McNames
Mahmoud El-Gohary
Kristen Sowalsky
Delaram Safarpour
Patricia Carlson-Kuhta
Christian Rummey
Fay B. Horak
Fay B. Horak
Christopher M. Gomez
author_facet Hannah L. Casey
Vrutangkumar V. Shah
Vrutangkumar V. Shah
Daniel Muzyka
James McNames
James McNames
Mahmoud El-Gohary
Kristen Sowalsky
Delaram Safarpour
Patricia Carlson-Kuhta
Christian Rummey
Fay B. Horak
Fay B. Horak
Christopher M. Gomez
author_sort Hannah L. Casey
collection DOAJ
description IntroductionGait assessments in a clinical setting may not accurately reflect mobility in everyday life. To better understand gait during daily life, we compared measures that discriminated Friedreich ataxia (FRDA) from healthy control (HC) subjects in prescribed clinic tests and free, daily-life monitoring.MethodsWe recruited 9 people with FRDA (median age: 20, IQR [12, 48] years). A comparative healthy control (HC) subject cohort of 9 was sampled using propensity matching on age (median age: 18 [13, 22] years). Subjects wore 3 inertial sensors (one each foot and lower back) in the laboratory during a 2-min walk at a natural pace, followed by 7 days of daily life. For daily life analysis, a total of 99,216 strides across 1,008 h of recording were included. Mann–Whitney U test and area under the curve (AUC) compared gait differences between FRDA and HC when assessed in the laboratory and daily life. Pairwise Wilcoxon tests also compared if participants exhibited different metric values between the two environments.ResultsThe FRDA group exhibited lower levels of daily activity. Measures that best discriminated gait characteristics of FRDA from HC differed between environments. Variation in elevation of the feet at midswing best discriminated in-clinic (Clinic AUC = 1, Home AUC = 0.69), whereas slow gait speed performed best in daily life (Home AUC = 1, Clinic AUC = 0.64). Of the 17 measures tested, 11 had an AUC > 0.8 in-clinic and 8 had an AUC >0.8 at home. Variability of swing time (Clinic AUC = 0.97, Home AUC = 0.94) and double-support time (Clinic AUC = 0.94, Home AUC = 0.94) were the most sensitive and specific for FRDA in both environments.ConclusionDigital gait characteristics from inertial sensors are sensitive and specific for FRDA in both environments. However, different gait measures were more sensitive and specific during free-living versus prescribed gait, suggesting that in-clinic gait does not reflect daily life gait.
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spelling doaj-art-0e1189ed8e1a48fcae0ac96150635caa2025-08-20T02:56:03ZengFrontiers Media S.A.Frontiers in Neurology1664-22952025-03-011610.3389/fneur.2025.15444531544453Gait characteristics in people with Friedreich ataxia: daily life versus clinic measuresHannah L. Casey0Vrutangkumar V. Shah1Vrutangkumar V. Shah2Daniel Muzyka3James McNames4James McNames5Mahmoud El-Gohary6Kristen Sowalsky7Delaram Safarpour8Patricia Carlson-Kuhta9Christian Rummey10Fay B. Horak11Fay B. Horak12Christopher M. Gomez13Department of Neurology, The University of Chicago, Chicago, IL, United StatesAPDM Wearable Technologies - A Clario Company, Portland, OR, United StatesDepartment of Neurology, Oregon Health & Science University, Portland, OR, United StatesAPDM Wearable Technologies - A Clario Company, Portland, OR, United StatesAPDM Wearable Technologies - A Clario Company, Portland, OR, United StatesDepartment of Electrical and Computer Engineering, Portland State University, Portland, OR, United StatesAPDM Wearable Technologies - A Clario Company, Portland, OR, United StatesAPDM Wearable Technologies - A Clario Company, Portland, OR, United StatesDepartment of Neurology, Oregon Health & Science University, Portland, OR, United StatesDepartment of Neurology, Oregon Health & Science University, Portland, OR, United StatesClinical Data Science GmbH, Basel, SwitzerlandAPDM Wearable Technologies - A Clario Company, Portland, OR, United StatesDepartment of Neurology, Oregon Health & Science University, Portland, OR, United StatesDepartment of Neurology, The University of Chicago, Chicago, IL, United StatesIntroductionGait assessments in a clinical setting may not accurately reflect mobility in everyday life. To better understand gait during daily life, we compared measures that discriminated Friedreich ataxia (FRDA) from healthy control (HC) subjects in prescribed clinic tests and free, daily-life monitoring.MethodsWe recruited 9 people with FRDA (median age: 20, IQR [12, 48] years). A comparative healthy control (HC) subject cohort of 9 was sampled using propensity matching on age (median age: 18 [13, 22] years). Subjects wore 3 inertial sensors (one each foot and lower back) in the laboratory during a 2-min walk at a natural pace, followed by 7 days of daily life. For daily life analysis, a total of 99,216 strides across 1,008 h of recording were included. Mann–Whitney U test and area under the curve (AUC) compared gait differences between FRDA and HC when assessed in the laboratory and daily life. Pairwise Wilcoxon tests also compared if participants exhibited different metric values between the two environments.ResultsThe FRDA group exhibited lower levels of daily activity. Measures that best discriminated gait characteristics of FRDA from HC differed between environments. Variation in elevation of the feet at midswing best discriminated in-clinic (Clinic AUC = 1, Home AUC = 0.69), whereas slow gait speed performed best in daily life (Home AUC = 1, Clinic AUC = 0.64). Of the 17 measures tested, 11 had an AUC > 0.8 in-clinic and 8 had an AUC >0.8 at home. Variability of swing time (Clinic AUC = 0.97, Home AUC = 0.94) and double-support time (Clinic AUC = 0.94, Home AUC = 0.94) were the most sensitive and specific for FRDA in both environments.ConclusionDigital gait characteristics from inertial sensors are sensitive and specific for FRDA in both environments. However, different gait measures were more sensitive and specific during free-living versus prescribed gait, suggesting that in-clinic gait does not reflect daily life gait.https://www.frontiersin.org/articles/10.3389/fneur.2025.1544453/fullgaitfree-livingFriedreich’s ataxiawearable inertial sensorsdigital biomarkerclinical trials
spellingShingle Hannah L. Casey
Vrutangkumar V. Shah
Vrutangkumar V. Shah
Daniel Muzyka
James McNames
James McNames
Mahmoud El-Gohary
Kristen Sowalsky
Delaram Safarpour
Patricia Carlson-Kuhta
Christian Rummey
Fay B. Horak
Fay B. Horak
Christopher M. Gomez
Gait characteristics in people with Friedreich ataxia: daily life versus clinic measures
Frontiers in Neurology
gait
free-living
Friedreich’s ataxia
wearable inertial sensors
digital biomarker
clinical trials
title Gait characteristics in people with Friedreich ataxia: daily life versus clinic measures
title_full Gait characteristics in people with Friedreich ataxia: daily life versus clinic measures
title_fullStr Gait characteristics in people with Friedreich ataxia: daily life versus clinic measures
title_full_unstemmed Gait characteristics in people with Friedreich ataxia: daily life versus clinic measures
title_short Gait characteristics in people with Friedreich ataxia: daily life versus clinic measures
title_sort gait characteristics in people with friedreich ataxia daily life versus clinic measures
topic gait
free-living
Friedreich’s ataxia
wearable inertial sensors
digital biomarker
clinical trials
url https://www.frontiersin.org/articles/10.3389/fneur.2025.1544453/full
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