The Challenge of Prenatal Diagnostic Work-Up of Maternally Inherited X-Linked Opitz G/BBB: Case Report and Literature Review

Background. Prenatal diagnosis of Optiz G/BBB syndrome (OS) is challenging because the characteristic clinical features, such as facial and genitourinary anomalies, may be subtle at sonography and rather unspecific. Furthermore, molecular testing of the disease gene is not routinely performed, unles...

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Main Authors: Marialuigia Spinelli, Carmine Sica, Bruno Dallapiccola, Antonio Novelli, Letizia Di Meglio, Pasquale Martinelli
Format: Article
Language:English
Published: Wiley 2015-01-01
Series:Case Reports in Obstetrics and Gynecology
Online Access:http://dx.doi.org/10.1155/2015/830108
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author Marialuigia Spinelli
Carmine Sica
Bruno Dallapiccola
Antonio Novelli
Letizia Di Meglio
Pasquale Martinelli
author_facet Marialuigia Spinelli
Carmine Sica
Bruno Dallapiccola
Antonio Novelli
Letizia Di Meglio
Pasquale Martinelli
author_sort Marialuigia Spinelli
collection DOAJ
description Background. Prenatal diagnosis of Optiz G/BBB syndrome (OS) is challenging because the characteristic clinical features, such as facial and genitourinary anomalies, may be subtle at sonography and rather unspecific. Furthermore, molecular testing of the disease gene is not routinely performed, unless a specific diagnosis is suggested. Method. Both familial and ultrasound data were used to achieve the diagnosis of X-linked OS (XLOS), which was confirmed by molecular testing of MID1 gene (Xp22.3) at birth. Results. Sequencing of MID1 gene disclosed the nucleotide change c.1285 +1 G>T, previously associated with XLOS. Conclusions. This case illustrates current challenges of the prenatal diagnostic work-up of XLOS and exemplifies how clinical investigation, including family history, and accurate US foetal investigations can lead to the correct diagnosis.
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publishDate 2015-01-01
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series Case Reports in Obstetrics and Gynecology
spelling doaj-art-09ffdc6c368d45f082ef0df749ed1fe72025-08-20T03:55:27ZengWileyCase Reports in Obstetrics and Gynecology2090-66842090-66922015-01-01201510.1155/2015/830108830108The Challenge of Prenatal Diagnostic Work-Up of Maternally Inherited X-Linked Opitz G/BBB: Case Report and Literature ReviewMarialuigia Spinelli0Carmine Sica1Bruno Dallapiccola2Antonio Novelli3Letizia Di Meglio4Pasquale Martinelli5Department of Neurosciences, Reproductive Sciences and Odontostomatoloy, University of Naples Federico II, 80100 Naples, ItalyPrivate Prenatal Diagnostic Centre “Diagnostica ecografica Aniello Di Meglio s.r.l.”, 80100 Naples, ItalyDepartment of Medical Genetics, Bambino Gesù Children’s Hospital, IRCCS, 00146 Rome, ItalyDepartment of Medical Genetics, Bambino Gesù Children’s Hospital, IRCCS, 00146 Rome, ItalyPrivate Prenatal Diagnostic Centre “Diagnostica ecografica Aniello Di Meglio s.r.l.”, 80100 Naples, ItalyDepartment of Neurosciences, Reproductive Sciences and Odontostomatoloy, University of Naples Federico II, 80100 Naples, ItalyBackground. Prenatal diagnosis of Optiz G/BBB syndrome (OS) is challenging because the characteristic clinical features, such as facial and genitourinary anomalies, may be subtle at sonography and rather unspecific. Furthermore, molecular testing of the disease gene is not routinely performed, unless a specific diagnosis is suggested. Method. Both familial and ultrasound data were used to achieve the diagnosis of X-linked OS (XLOS), which was confirmed by molecular testing of MID1 gene (Xp22.3) at birth. Results. Sequencing of MID1 gene disclosed the nucleotide change c.1285 +1 G>T, previously associated with XLOS. Conclusions. This case illustrates current challenges of the prenatal diagnostic work-up of XLOS and exemplifies how clinical investigation, including family history, and accurate US foetal investigations can lead to the correct diagnosis.http://dx.doi.org/10.1155/2015/830108
spellingShingle Marialuigia Spinelli
Carmine Sica
Bruno Dallapiccola
Antonio Novelli
Letizia Di Meglio
Pasquale Martinelli
The Challenge of Prenatal Diagnostic Work-Up of Maternally Inherited X-Linked Opitz G/BBB: Case Report and Literature Review
Case Reports in Obstetrics and Gynecology
title The Challenge of Prenatal Diagnostic Work-Up of Maternally Inherited X-Linked Opitz G/BBB: Case Report and Literature Review
title_full The Challenge of Prenatal Diagnostic Work-Up of Maternally Inherited X-Linked Opitz G/BBB: Case Report and Literature Review
title_fullStr The Challenge of Prenatal Diagnostic Work-Up of Maternally Inherited X-Linked Opitz G/BBB: Case Report and Literature Review
title_full_unstemmed The Challenge of Prenatal Diagnostic Work-Up of Maternally Inherited X-Linked Opitz G/BBB: Case Report and Literature Review
title_short The Challenge of Prenatal Diagnostic Work-Up of Maternally Inherited X-Linked Opitz G/BBB: Case Report and Literature Review
title_sort challenge of prenatal diagnostic work up of maternally inherited x linked opitz g bbb case report and literature review
url http://dx.doi.org/10.1155/2015/830108
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