An Unusual Case of Mullerian Choristomas in the Lumbar Region Presented as Spinal Dysraphism

A choristoma is a benign growth of microscopically normal tissue that resembles a tumor and develops in an unusual place. Mullerian choristomas in connection with spinal dysraphism are incredibly uncommon; less than 10 cases have been reported in English literature. Here, we present a case of a 39-y...

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Main Authors: Yaminy Pradeep Ingale, Arpana Dharwadkar, Sushama Gurwale, Charusheela Gore
Format: Article
Language:English
Published: Wolters Kluwer Medknow Publications 2025-05-01
Series:Indian Spine Journal
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Online Access:https://doi.org/10.4103/isj.isj_67_24
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author Yaminy Pradeep Ingale
Arpana Dharwadkar
Sushama Gurwale
Charusheela Gore
author_facet Yaminy Pradeep Ingale
Arpana Dharwadkar
Sushama Gurwale
Charusheela Gore
author_sort Yaminy Pradeep Ingale
collection DOAJ
description A choristoma is a benign growth of microscopically normal tissue that resembles a tumor and develops in an unusual place. Mullerian choristomas in connection with spinal dysraphism are incredibly uncommon; less than 10 cases have been reported in English literature. Here, we present a case of a 39-year-old female who has had lower back swelling since birth, along with difficulty in walking and lower-limb pain for 8 months. A computed tomography scan and magnetic resonance imaging of the spine show spinal dysraphism–spina bifida at L3–L4 level with lipomeningocele. An excisional biopsy of the swelling was done and sent for histopathology. A biopsy shows the presence of ectopic endometrial and fallopian tissue along with fibro-fatty tissue, which is confirmed by immunohistochemistry. Smooth muscles, stromal cells, and epithelium had positive estrogen receptors, according to immunohistochemistry. In addition, the stromal cells demonstrated a cluster of differentiation 10 positivity, indicating Mullerian derivation and the epithelial cells were also positive for cytokeratin 7. From the results of immunohistochemistry and histopathology, we gave the diagnosis of Mullerian choristoma with lipomyelocele.
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publishDate 2025-05-01
publisher Wolters Kluwer Medknow Publications
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series Indian Spine Journal
spelling doaj-art-061fd36fbc524a32b325ea2324b4004e2025-08-20T02:36:42ZengWolters Kluwer Medknow PublicationsIndian Spine Journal2589-50792589-50872025-05-018216717110.4103/isj.isj_67_24An Unusual Case of Mullerian Choristomas in the Lumbar Region Presented as Spinal DysraphismYaminy Pradeep IngaleArpana DharwadkarSushama GurwaleCharusheela GoreA choristoma is a benign growth of microscopically normal tissue that resembles a tumor and develops in an unusual place. Mullerian choristomas in connection with spinal dysraphism are incredibly uncommon; less than 10 cases have been reported in English literature. Here, we present a case of a 39-year-old female who has had lower back swelling since birth, along with difficulty in walking and lower-limb pain for 8 months. A computed tomography scan and magnetic resonance imaging of the spine show spinal dysraphism–spina bifida at L3–L4 level with lipomeningocele. An excisional biopsy of the swelling was done and sent for histopathology. A biopsy shows the presence of ectopic endometrial and fallopian tissue along with fibro-fatty tissue, which is confirmed by immunohistochemistry. Smooth muscles, stromal cells, and epithelium had positive estrogen receptors, according to immunohistochemistry. In addition, the stromal cells demonstrated a cluster of differentiation 10 positivity, indicating Mullerian derivation and the epithelial cells were also positive for cytokeratin 7. From the results of immunohistochemistry and histopathology, we gave the diagnosis of Mullerian choristoma with lipomyelocele.https://doi.org/10.4103/isj.isj_67_24cytokeratin 7estrogen receptorsimmunohistochemistrymullerian choristomas
spellingShingle Yaminy Pradeep Ingale
Arpana Dharwadkar
Sushama Gurwale
Charusheela Gore
An Unusual Case of Mullerian Choristomas in the Lumbar Region Presented as Spinal Dysraphism
Indian Spine Journal
cytokeratin 7
estrogen receptors
immunohistochemistry
mullerian choristomas
title An Unusual Case of Mullerian Choristomas in the Lumbar Region Presented as Spinal Dysraphism
title_full An Unusual Case of Mullerian Choristomas in the Lumbar Region Presented as Spinal Dysraphism
title_fullStr An Unusual Case of Mullerian Choristomas in the Lumbar Region Presented as Spinal Dysraphism
title_full_unstemmed An Unusual Case of Mullerian Choristomas in the Lumbar Region Presented as Spinal Dysraphism
title_short An Unusual Case of Mullerian Choristomas in the Lumbar Region Presented as Spinal Dysraphism
title_sort unusual case of mullerian choristomas in the lumbar region presented as spinal dysraphism
topic cytokeratin 7
estrogen receptors
immunohistochemistry
mullerian choristomas
url https://doi.org/10.4103/isj.isj_67_24
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