Dyskeratosis congenita: report of two cases with distinct clinical presentations

Dyskeratosis congenita (DC) is a rare, inheritable disorder characterized by a triad of abnormal skin pigmentation, nail dystrophy and mucosal leukoplakia. Inheritance is mainly X-linked recessive; however, autosomal dominant and recessive forms have also been reported. Here, we report two ca...

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Bibliographic Details
Main Authors: Fatma Elif Demirgüneş, Gonca Elçin, Sedef Sahin
Format: Article
Language:English
Published: Hacettepe University Institute of Child Health 2008-12-01
Series:The Turkish Journal of Pediatrics
Online Access:https://turkjpediatr.org/article/view/2500
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Summary:Dyskeratosis congenita (DC) is a rare, inheritable disorder characterized by a triad of abnormal skin pigmentation, nail dystrophy and mucosal leukoplakia. Inheritance is mainly X-linked recessive; however, autosomal dominant and recessive forms have also been reported. Here, we report two cases of DC with distinct clinical presentations together with different genetic screening results, which emphasize the quite heterogeneous clinical as well as genetic nature of DC.
ISSN:0041-4301
2791-6421