Cellular Signaling and Production of Galactose-Deficient IgA1 in IgA Nephropathy, an Autoimmune Disease

Immunoglobulin A (IgA) nephropathy (IgAN), the leading cause of primary glomerulonephritis, is characterized by IgA1-containing immunodeposits in the glomeruli. IgAN is a chronic disease, with up to 40% of patients progressing to end-stage renal disease, with no disease-specific treatment. Multiple...

Full description

Saved in:
Bibliographic Details
Main Authors: Colin Reily, Hiroyuki Ueda, Zhi-Qiang Huang, Jiri Mestecky, Bruce A. Julian, Christopher D. Willey, Jan Novak
Format: Article
Language:English
Published: Wiley 2014-01-01
Series:Journal of Immunology Research
Online Access:http://dx.doi.org/10.1155/2014/197548
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1849687023106916352
author Colin Reily
Hiroyuki Ueda
Zhi-Qiang Huang
Jiri Mestecky
Bruce A. Julian
Christopher D. Willey
Jan Novak
author_facet Colin Reily
Hiroyuki Ueda
Zhi-Qiang Huang
Jiri Mestecky
Bruce A. Julian
Christopher D. Willey
Jan Novak
author_sort Colin Reily
collection DOAJ
description Immunoglobulin A (IgA) nephropathy (IgAN), the leading cause of primary glomerulonephritis, is characterized by IgA1-containing immunodeposits in the glomeruli. IgAN is a chronic disease, with up to 40% of patients progressing to end-stage renal disease, with no disease-specific treatment. Multiple studies of the origin of the glomerular immunodeposits have linked elevated circulating levels of aberrantly glycosylated IgA1 (galactose-deficient in some O-glycans; Gd-IgA1) with formation of nephritogenic Gd-IgA1-containing immune complexes. Gd-IgA1 is recognized as an autoantigen in susceptible individuals by anti-glycan autoantibodies, resulting in immune complexes that may ultimately deposit in the kidney and induce glomerular injury. Genetic studies have revealed that an elevated level of Gd-IgA1 in the circulation of IgAN patients is a hereditable trait. Moreover, recent genome-wide association studies have identified several immunity-related loci that associated with IgAN. Production of Gd-IgA1 by IgA1-secreting cells of IgAN patients has been attributed to abnormal expression and activity of several key glycosyltransferases. Substantial evidence is emerging that abnormal signaling in IgA1-producing cells is related to the production of Gd-IgA1. As Gd-IgA1 is the key autoantigen in IgAN, understanding the genetic, biochemical, and environmental aspects of the abnormal signaling in IgA1-producing cells will provide insight into possible targets for future disease-specific therapy.
format Article
id doaj-art-018477dfc6d8451d87d2bf7e11f83da2
institution DOAJ
issn 2314-8861
2314-7156
language English
publishDate 2014-01-01
publisher Wiley
record_format Article
series Journal of Immunology Research
spelling doaj-art-018477dfc6d8451d87d2bf7e11f83da22025-08-20T03:22:28ZengWileyJournal of Immunology Research2314-88612314-71562014-01-01201410.1155/2014/197548197548Cellular Signaling and Production of Galactose-Deficient IgA1 in IgA Nephropathy, an Autoimmune DiseaseColin Reily0Hiroyuki Ueda1Zhi-Qiang Huang2Jiri Mestecky3Bruce A. Julian4Christopher D. Willey5Jan Novak6Department of Microbiology, University of Alabama at Birmingham, 845 19th Street South, BBRB 762, Birmingham, AL 35294, USADepartment of Microbiology, University of Alabama at Birmingham, 845 19th Street South, BBRB 762, Birmingham, AL 35294, USADepartment of Microbiology, University of Alabama at Birmingham, 845 19th Street South, BBRB 762, Birmingham, AL 35294, USADepartment of Microbiology, University of Alabama at Birmingham, 845 19th Street South, BBRB 762, Birmingham, AL 35294, USADepartment of Microbiology, University of Alabama at Birmingham, 845 19th Street South, BBRB 762, Birmingham, AL 35294, USADepartment of Radiation Oncology, University of Alabama at Birmingham, 845 19th Street South, Birmingham, AL 35294, USADepartment of Microbiology, University of Alabama at Birmingham, 845 19th Street South, BBRB 762, Birmingham, AL 35294, USAImmunoglobulin A (IgA) nephropathy (IgAN), the leading cause of primary glomerulonephritis, is characterized by IgA1-containing immunodeposits in the glomeruli. IgAN is a chronic disease, with up to 40% of patients progressing to end-stage renal disease, with no disease-specific treatment. Multiple studies of the origin of the glomerular immunodeposits have linked elevated circulating levels of aberrantly glycosylated IgA1 (galactose-deficient in some O-glycans; Gd-IgA1) with formation of nephritogenic Gd-IgA1-containing immune complexes. Gd-IgA1 is recognized as an autoantigen in susceptible individuals by anti-glycan autoantibodies, resulting in immune complexes that may ultimately deposit in the kidney and induce glomerular injury. Genetic studies have revealed that an elevated level of Gd-IgA1 in the circulation of IgAN patients is a hereditable trait. Moreover, recent genome-wide association studies have identified several immunity-related loci that associated with IgAN. Production of Gd-IgA1 by IgA1-secreting cells of IgAN patients has been attributed to abnormal expression and activity of several key glycosyltransferases. Substantial evidence is emerging that abnormal signaling in IgA1-producing cells is related to the production of Gd-IgA1. As Gd-IgA1 is the key autoantigen in IgAN, understanding the genetic, biochemical, and environmental aspects of the abnormal signaling in IgA1-producing cells will provide insight into possible targets for future disease-specific therapy.http://dx.doi.org/10.1155/2014/197548
spellingShingle Colin Reily
Hiroyuki Ueda
Zhi-Qiang Huang
Jiri Mestecky
Bruce A. Julian
Christopher D. Willey
Jan Novak
Cellular Signaling and Production of Galactose-Deficient IgA1 in IgA Nephropathy, an Autoimmune Disease
Journal of Immunology Research
title Cellular Signaling and Production of Galactose-Deficient IgA1 in IgA Nephropathy, an Autoimmune Disease
title_full Cellular Signaling and Production of Galactose-Deficient IgA1 in IgA Nephropathy, an Autoimmune Disease
title_fullStr Cellular Signaling and Production of Galactose-Deficient IgA1 in IgA Nephropathy, an Autoimmune Disease
title_full_unstemmed Cellular Signaling and Production of Galactose-Deficient IgA1 in IgA Nephropathy, an Autoimmune Disease
title_short Cellular Signaling and Production of Galactose-Deficient IgA1 in IgA Nephropathy, an Autoimmune Disease
title_sort cellular signaling and production of galactose deficient iga1 in iga nephropathy an autoimmune disease
url http://dx.doi.org/10.1155/2014/197548
work_keys_str_mv AT colinreily cellularsignalingandproductionofgalactosedeficientiga1iniganephropathyanautoimmunedisease
AT hiroyukiueda cellularsignalingandproductionofgalactosedeficientiga1iniganephropathyanautoimmunedisease
AT zhiqianghuang cellularsignalingandproductionofgalactosedeficientiga1iniganephropathyanautoimmunedisease
AT jirimestecky cellularsignalingandproductionofgalactosedeficientiga1iniganephropathyanautoimmunedisease
AT bruceajulian cellularsignalingandproductionofgalactosedeficientiga1iniganephropathyanautoimmunedisease
AT christopherdwilley cellularsignalingandproductionofgalactosedeficientiga1iniganephropathyanautoimmunedisease
AT jannovak cellularsignalingandproductionofgalactosedeficientiga1iniganephropathyanautoimmunedisease